Literature DB >> 21262074

Novel frameshift mutation in Troponin C ( TNNC1) associated with hypertrophic cardiomyopathy and sudden death.

Wendy K Chung1, Carrie Kitner, Barry J Maron.   

Abstract

UNLABELLED: PurposeHypertrophic cardiomyopathy is the most common cause of sudden death in young people, including trained athletes, and is caused by mutations in genes encoding proteins of the cardiac sarcomere. Mutations in the Troponin C gene (TNNC1) are a rare genetic cause of hypertrophic cardiomyopathy. We describe a novel type of mutation (c.363dupG) in Troponin C, a rare form of hypertrophic cardiomyopathy.
METHODS: A family in which a 19-year-old asymptomatic male died of sudden cardiac death due to hypertrophic cardiomyopathy was genetically studied by sequencing 17 genes associated with hypertrophic cardiomyopathy or its phenocopies.
RESULTS: A c.363dupG mutation in Troponin C was identified, and tested across the family.
CONCLUSIONS: We report the first frameshift mutation (c.363dupG or p.Gln122AlafsX30) in Troponin C causing hypertrophic cardiomyopathy (and sudden cardiac death) in a 19-year-old male, and have demonstrated that the mutation segregates with hypertrophic cardiomyopathy within the family.

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Year:  2011        PMID: 21262074     DOI: 10.1017/S1047951110001927

Source DB:  PubMed          Journal:  Cardiol Young        ISSN: 1047-9511            Impact factor:   1.093


  12 in total

1.  Myosin Rod Hypophosphorylation and CB Kinetics in Papillary Muscles from a TnC-A8V KI Mouse Model.

Authors:  Masataka Kawai; Jamie R Johnston; Tarek Karam; Li Wang; Rakesh K Singh; Jose R Pinto
Journal:  Biophys J       Date:  2017-04-25       Impact factor: 4.033

2.  A mutation in TNNC1-encoded cardiac troponin C, TNNC1-A31S, predisposes to hypertrophic cardiomyopathy and ventricular fibrillation.

Authors:  Michelle S Parvatiyar; Andrew P Landstrom; Cicero Figueiredo-Freitas; James D Potter; Michael J Ackerman; Jose Renato Pinto
Journal:  J Biol Chem       Date:  2012-07-18       Impact factor: 5.157

3.  Beyond the cardiac myofilament: hypertrophic cardiomyopathy- associated mutations in genes that encode calcium-handling proteins.

Authors:  A P Landstrom; M J Ackerman
Journal:  Curr Mol Med       Date:  2012-06       Impact factor: 2.222

4.  Enhanced troponin I binding explains the functional changes produced by the hypertrophic cardiomyopathy mutation A8V of cardiac troponin C.

Authors:  Henry G Zot; Javier E Hasbun; Clara A Michell; Maicon Landim-Vieira; Jose R Pinto
Journal:  Arch Biochem Biophys       Date:  2016-03-11       Impact factor: 4.013

5.  In Vivo Analysis of Troponin C Knock-In (A8V) Mice: Evidence that TNNC1 Is a Hypertrophic Cardiomyopathy Susceptibility Gene.

Authors:  Adriano S Martins; Michelle S Parvatiyar; Han-Zhong Feng; J Martijn Bos; David Gonzalez-Martinez; Milica Vukmirovic; Rajdeep S Turna; Marcos A Sanchez-Gonzalez; Crystal-Dawn Badger; Diego A R Zorio; Rakesh K Singh; Yingcai Wang; J-P Jin; Michael J Ackerman; Jose R Pinto
Journal:  Circ Cardiovasc Genet       Date:  2015-08-24

Review 6.  Structure and function of cardiac troponin C (TNNC1): Implications for heart failure, cardiomyopathies, and troponin modulating drugs.

Authors:  Monica X Li; Peter M Hwang
Journal:  Gene       Date:  2015-07-29       Impact factor: 3.688

7.  Fluorescent Protein-Based Ca2+ Sensor Reveals Global, Divalent Cation-Dependent Conformational Changes in Cardiac Troponin C.

Authors:  Myriam A Badr; Jose R Pinto; Michael W Davidson; P Bryant Chase
Journal:  PLoS One       Date:  2016-10-13       Impact factor: 3.240

8.  Cardiomyopathy-Related Mutations in Cardiac Troponin C, L29Q and G159D, Have Divergent Effects on Rat Cardiac Myofiber Contractile Dynamics.

Authors:  Sampath K Gollapudi; Murali Chandra
Journal:  Biochem Res Int       Date:  2012-09-12

9.  The structural and functional effects of the familial hypertrophic cardiomyopathy-linked cardiac troponin C mutation, L29Q.

Authors:  Ian M Robertson; Ivanka Sevrieva; Monica X Li; Malcolm Irving; Yin-Biao Sun; Brian D Sykes
Journal:  J Mol Cell Cardiol       Date:  2015-09-01       Impact factor: 5.000

10.  A comprehensive guide to genetic variants and post-translational modifications of cardiac troponin C.

Authors:  Tyler R Reinoso; Maicon Landim-Vieira; Yun Shi; Jamie R Johnston; P Bryant Chase; Michelle S Parvatiyar; Andrew P Landstrom; Jose R Pinto; Hanna J Tadros
Journal:  J Muscle Res Cell Motil       Date:  2020-11-11       Impact factor: 3.352

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