Literature DB >> 21117861

The York Platelet Syndrome: a third case.

James G White1, Meral Gunay-Aygun.   

Abstract

Our present study has described a third patient with the York Platelet Syndrome (YPS). The condition consists of a mitochondrial myopathy associated with unique platelet pathology. Their mitochondrial myopathy has not been completely delineated and will be the subject of further study. Platelet pathology in the new patient is essentially identical to that described in the first two patients. Thin sections of her thrombocytes reveal a normal complement of α and δ granules (dense bodies) in some, a decreased number in others and complete absence in a few. The unique pathological feature is the presence of giant organelles, including an intensely electron dense, huge body, the opaque organelle (OO) and a multilayered large body, the target organelle. In addition platelets from the new patient contain large masses and coils of smooth endoplasmic reticulum present infrequently in platelets of the first two patients. The giant opaque and target organelles appear to develop in rough and smooth endoplasmic reticulum of the parent megakaryocyte and mature in the dense tubular system of circulating platelets. The relationship of the unique platelet pathology and mitochondrial myopathy has not been defined.

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Year:  2010        PMID: 21117861      PMCID: PMC3501964          DOI: 10.3109/09537104.2010.524323

Source DB:  PubMed          Journal:  Platelets        ISSN: 0953-7104            Impact factor:   3.862


  9 in total

1.  Giant electron-dense chains, clusters and granules in megakaryocytes and platelets with normal dense bodies: an inherited thrombocytopenic disorder I. Megakaryocytes.

Authors:  James G White
Journal:  Platelets       Date:  2003-02       Impact factor: 3.862

2.  Reliability of absent platelet dense bodies as a diagnostic criterion for Hermansky-Pudlak syndrome.

Authors:  C J Witkop; M Krumwiede; H Sedano; J G White
Journal:  Am J Hematol       Date:  1987-12       Impact factor: 10.047

Review 3.  Ultrastructure of human bone marrow cell maturation.

Authors:  J Breton-Gorius; F Reyes
Journal:  Int Rev Cytol       Date:  1976

4.  Interaction of membrane systems in blood platelets.

Authors:  J G White
Journal:  Am J Pathol       Date:  1972-02       Impact factor: 4.307

5.  Cytochemical localization of lysosomal enzymes in rat megakaryocytes and platelets.

Authors:  M E Bentfeld; D F Bainton
Journal:  J Clin Invest       Date:  1975-12       Impact factor: 14.808

6.  Further studies of the secretory pathway in thrombin-stimulated human platelets.

Authors:  J G White; M Krumwiede
Journal:  Blood       Date:  1987-04       Impact factor: 22.113

7.  Electron-dense chains and clusters in platelets from patients with storage pool-deficiency disorders.

Authors:  J G White
Journal:  J Thromb Haemost       Date:  2003-01       Impact factor: 5.824

8.  Giant electron dense chains, clusters and granules in megakaryocytes and platelets with normal dense bodies: an inherited thrombocytopenic disorder III. Platelet analytical electron microscopy.

Authors:  James G White; Gilbert G Ahlstrand
Journal:  Platelets       Date:  2003-08       Impact factor: 3.862

9.  Giant electron-dense chains, clusters and granules in megakaryocytes and platelets with normal dense bodies: an inherited thrombocytopenic disorder.

Authors:  James G White
Journal:  Platelets       Date:  2003-03       Impact factor: 3.862

  9 in total
  2 in total

1.  York platelet syndrome is a CRAC channelopathy due to gain-of-function mutations in STIM1.

Authors:  Thomas Markello; Dong Chen; Justin Y Kwan; Iren Horkayne-Szakaly; Alan Morrison; Olga Simakova; Irina Maric; Jay Lozier; Andrew R Cullinane; Tatjana Kilo; Lynn Meister; Kourosh Pakzad; William Bone; Sanjay Chainani; Elizabeth Lee; Amanda Links; Cornelius Boerkoel; Roxanne Fischer; Camilo Toro; James G White; William A Gahl; Meral Gunay-Aygun
Journal:  Mol Genet Metab       Date:  2014-12-24       Impact factor: 4.797

2.  Myopathy in the York Platelet Syndrome: An Underrecognized Complication.

Authors:  Joy Roman; Michael I Palmer; Cheryl A Palmer; Nicholas E Johnson; Russell J Butterfield
Journal:  Case Rep Pathol       Date:  2018-08-12
  2 in total

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