Literature DB >> 21113739

Gaucher disease with foamy transformed macrophages and erythrophagocytic activity.

Maciej Machaczka1, Monika Klimkowska, Sofie Regenthal, Hans Hägglund.   

Abstract

Foamy transformation of macrophages is typically seen in lysosomal storage disorders in patients with Niemann-Pick disease, but foamy Gaucher cells (GC) were previously reported only once, in the autopsy report. Although the majority of stored glucocerebroside in GC is of erythrocyte origin, apparent erythrophagocytosis by GC in bone marrow is an unusual finding. Here, we describe the case of an adult non-Jewish Caucasian male with a heterozygous Gaucher disease type 1 (mutations c.1226A>G and c.1448T>C in the GBA1 gene) who presented with atypical morphology of GC on bone marrow examination. Approximately 15% of his GC showed a notable erythrophagocytic activity or unusual appearance of foamy transformed macrophages with a great number of vacuoles and erythrocyte rests in the cytoplasm. This report highlights the fact that morphological examination of cells and tissue specimens is very helpful in the diagnosis of a storage disorder but that confirmatory testing for specific diseases should always follow. Moreover, it is now clear that Gaucher disease should be a part of the differential diagnosis of foamy transformed macrophages.

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Year:  2010        PMID: 21113739     DOI: 10.1007/s10545-010-9241-0

Source DB:  PubMed          Journal:  J Inherit Metab Dis        ISSN: 0141-8955            Impact factor:   4.982


  6 in total

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Authors:  Asaf Bitton; Joan Etzell; James P Grenert; Endi Wang
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5.  Hepatosplenomegalic lipidosis: what unless Gaucher? Adult cholesteryl ester storage disease (CESD) with anemia, mesenteric lipodystrophy, increased plasma chitotriosidase activity and a homozygous lysosomal acid lipase -1 exon 8 splice junction mutation.

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Journal:  Am J Med       Date:  1967-06       Impact factor: 4.965

  6 in total
  15 in total

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3.  Gaucher iPSC-derived macrophages produce elevated levels of inflammatory mediators and serve as a new platform for therapeutic development.

Authors:  Leelamma M Panicker; Diana Miller; Ola Awad; Vivek Bose; Yu Lun; Tea Soon Park; Elias T Zambidis; Judi A Sgambato; Ricardo A Feldman
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7.  Lysosomal storage and impaired autophagy lead to inflammasome activation in Gaucher macrophages.

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8.  An Engineered sgsh Mutant Zebrafish Recapitulates Molecular and Behavioural Pathobiology of Sanfilippo Syndrome A/MPS IIIA.

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9.  Impact of imiglucerase supply shortage on clinical and laboratory parameters in Norrbottnian patients with Gaucher disease type 3.

Authors:  Maciej Machaczka; Cecilia Kämpe Björkvall; Joanna Wieremiejczyk; Martin Paucar Arce; Kristina Myhr-Eriksson; Monika Klimkowska; Hans Hägglund; Per Svenningsson
Journal:  Arch Immunol Ther Exp (Warsz)       Date:  2014-09-10       Impact factor: 4.291

10.  The appearance of newly identified intraocular lesions in Gaucher disease type 3 despite long-term glucocerebrosidase replacement therapy.

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Journal:  Ups J Med Sci       Date:  2016-04-11       Impact factor: 2.384

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