Literature DB >> 20970936

Somatic mosaicism for Y120X mutation in the MECP2 gene causes atypical Rett syndrome in a male.

Juan I Pieras1, Beatriz Muñoz-Cabello, Salud Borrego, Irene Marcos, Javier Sanchez, Marcos Madruga, Guillermo Antiñolo.   

Abstract

Rett Syndrome (RS; MIM_312750) is a severe and progressive neurodevelopmental disorder affecting principally females. Mutations in X-Linked MECP2 gene (methyl CpG-binding protein 2; MIM_300005) have been reported as being the major cause of RS. Mutations in this gene have been described as cause of wide spectrum of neurological disorders and mental retardation in males. In some cases, mutations in MECP2 in males produce clinical picture similar to RS. Here we report the identification of the novel truncating mutation Y120X in a 4-year-old child with atypical RS phenotype. Chromosome analysis showed a normal karyotype, and blood DNA and tissue DNA analysis reveal a mosaic for the mutation. Patient's mother DNA analysis showed that this is a de novo mutation, that has never been described before in any female or male case of RS.
Copyright © 2010 The Japanese Society of Child Neurology. Published by Elsevier B.V. All rights reserved.

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Year:  2010        PMID: 20970936     DOI: 10.1016/j.braindev.2010.09.012

Source DB:  PubMed          Journal:  Brain Dev        ISSN: 0387-7604            Impact factor:   1.961


  11 in total

Review 1.  Brief report: systematic review of Rett syndrome in males.

Authors:  Brian Reichow; Annie George-Puskar; Tara Lutz; Isaac C Smith; Fred R Volkmar
Journal:  J Autism Dev Disord       Date:  2015-10

Review 2.  Somatic mutation, genomic variation, and neurological disease.

Authors:  Annapurna Poduri; Gilad D Evrony; Xuyu Cai; Christopher A Walsh
Journal:  Science       Date:  2013-07-05       Impact factor: 47.728

Review 3.  Hypothesis: somatic mosaicism and Parkinson disease.

Authors:  Han-Joon Kim; Beom S Jeon
Journal:  Exp Neurobiol       Date:  2014-12-12       Impact factor: 3.261

Review 4.  NGS Technologies as a Turning Point in Rare Disease Research , Diagnosis and Treatment.

Authors:  Ana Fernandez-Marmiesse; Sofia Gouveia; Maria L Couce
Journal:  Curr Med Chem       Date:  2018-01-30       Impact factor: 4.530

5.  Genomic mosaicism in paternal sperm and multiple parental tissues in a Dravet syndrome cohort.

Authors:  Xiaoxu Yang; Aijie Liu; Xiaojing Xu; Xiaoling Yang; Qi Zeng; Adam Yongxin Ye; Zhe Yu; Sheng Wang; August Yue Huang; Xiru Wu; Qixi Wu; Liping Wei; Yuehua Zhang
Journal:  Sci Rep       Date:  2017-11-15       Impact factor: 4.379

6.  De novo mosaic MECP2 mutation in a female with Rett syndrome.

Authors:  Angelos Alexandrou; Ioannis Papaevripidou; Ioanna Maria Alexandrou; Athina Theodosiou; Paola Evangelidou; Ludmila Kousoulidou; George Tanteles; Violetta Christophidou-Anastasiadou; Carolina Sismani
Journal:  Clin Case Rep       Date:  2019-01-15

7.  Genomic mosaicism in the pathogenesis and inheritance of a Rett syndrome cohort.

Authors:  Qingping Zhang; Xiaoxu Yang; Jiaping Wang; Jiarui Li; Qixi Wu; Yongxin Wen; Ying Zhao; Xiaoying Zhang; He Yao; Xiru Wu; Shujie Yu; Liping Wei; Xinhua Bao
Journal:  Genet Med       Date:  2018-11-08       Impact factor: 8.822

8.  Exploring the biological role of postzygotic and germinal de novo mutations in ASD.

Authors:  A Alonso-Gonzalez; M Calaza; J Amigo; J González-Peñas; R Martínez-Regueiro; M Fernández-Prieto; M Parellada; C Arango; Cristina Rodriguez-Fontenla; A Carracedo
Journal:  Sci Rep       Date:  2021-01-11       Impact factor: 4.379

9.  A rare case of a male child with post-zygotic de novo mosaic variant c.538C > T in MECP2 gene: a case report of Rett syndrome.

Authors:  Frenny Sheth; Harsh Sheth; Jhanvi Shah; Harsh Patel; Deepika Jain
Journal:  BMC Neurol       Date:  2021-12-02       Impact factor: 2.474

Review 10.  De novo Mutations (DNMs) in Autism Spectrum Disorder (ASD): Pathway and Network Analysis.

Authors:  Aitana Alonso-Gonzalez; Cristina Rodriguez-Fontenla; Angel Carracedo
Journal:  Front Genet       Date:  2018-09-21       Impact factor: 4.599

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