Literature DB >> 20859665

Primary immunodeficiencies: a 27-year review at a tertiary paediatric hospital in Cape Town, South Africa.

Reené Naidoo1, Lisa Ungerer, Margaret Cooper, Sandra Pienaar, Brian S Eley.   

Abstract

INTRODUCTION: The epidemiology of primary immunodeficiencies (PID) is not well documented in Africa. The objective of this study was to describe the spectrum of PID at a tertiary paediatric centre in South Africa.
METHODS: A retrospective study was conducted on 168 patients diagnosed with PID from 1983 to 2009.
RESULTS: Over the study period, antibody deficiencies predominated (51%) followed by well-defined syndromes (24%). Common variable immunodeficiency was the commonest antibody deficiency. The mean age of diagnosis was 51 months overall but decreased significantly to 35 months over the last 9 years. Recurrent infections were the most common presenting complaint (74%). The overall mortality rate was 25% while combined immunodeficiencies accounted for 40% of the deaths.
CONCLUSIONS: The spectrum of PID in South Africa was similar to international trends. The declining mean age of diagnosis indicated improved recognition of PID. Future research should focus on identifying children with PID more effectively.

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Year:  2010        PMID: 20859665     DOI: 10.1007/s10875-010-9465-7

Source DB:  PubMed          Journal:  J Clin Immunol        ISSN: 0271-9142            Impact factor:   8.317


  19 in total

1.  [Primary immunodeficiency in Tunisia: study of 152 cases].

Authors:  M Bejaoui; M R Barbouche; A Sassi; B Larguche; N Miladi; A Bouguerra; K Dellagi
Journal:  Arch Pediatr       Date:  1997-09       Impact factor: 1.180

2.  The French national registry of primary immunodeficiency diseases.

Authors: 
Journal:  Clin Immunol       Date:  2010-05       Impact factor: 3.969

3.  Primary immunodeficiency diseases at Red Cross War Memorial Children's Hospital.

Authors:  B S Eley; J Hughes; M Cooper; S Pienaar; D W Beatty
Journal:  S Afr Med J       Date:  1997-12

4.  Diagnostic criteria for primary immunodeficiencies. Representing PAGID (Pan-American Group for Immunodeficiency) and ESID (European Society for Immunodeficiencies).

Authors:  M E Conley; L D Notarangelo; A Etzioni
Journal:  Clin Immunol       Date:  1999-12       Impact factor: 3.969

5.  Primary immunodeficiencies: 2009 update.

Authors:  Luigi D Notarangelo; Alain Fischer; Raif S Geha; Jean-Laurent Casanova; Helen Chapel; Mary Ellen Conley; Charlotte Cunningham-Rundles; Amos Etzioni; Lennart Hammartröm; Shigeaki Nonoyama; Hans D Ochs; Jennifer Puck; Chaim Roifman; Reinhard Seger; Josiah Wedgwood
Journal:  J Allergy Clin Immunol       Date:  2009-12       Impact factor: 10.793

6.  From genotype to phenotype. Further studies measuring the impact of a Physician Education and Public Awareness Campaign on early diagnosis and management of primary immunodeficiencies.

Authors:  Fred Modell; Diana Puente; Vicki Modell
Journal:  Immunol Res       Date:  2009       Impact factor: 2.829

7.  Incidence and temporal trends of primary immunodeficiency: a population-based cohort study.

Authors:  Avni Y Joshi; Vivek N Iyer; John B Hagan; Jennifer L St Sauver; Thomas G Boyce
Journal:  Mayo Clin Proc       Date:  2009       Impact factor: 7.616

8.  Primary immunodeficiency diseases in Australia and New Zealand.

Authors:  Philippa Kirkpatrick; Sean Riminton
Journal:  J Clin Immunol       Date:  2007-06-22       Impact factor: 8.317

9.  Primary immunodeficiency diseases in Egyptian children: a single-center study.

Authors:  Shereen M Reda; Hanaa M Afifi; Mai M Amine
Journal:  J Clin Immunol       Date:  2008-11-11       Impact factor: 8.317

10.  Frequency and clinical manifestations of patients with primary immunodeficiency disorders in Iran: update from the Iranian Primary Immunodeficiency Registry.

Authors:  Nima Rezaei; Asghar Aghamohammadi; Mostafa Moin; Zahra Pourpak; Masoud Movahedi; Mohammad Gharagozlou; Lida Atarod; Bahram Mirsaeid Ghazi; Anna Isaeian; Maryam Mahmoudi; Kamran Abolmaali; Davoud Mansouri; Saba Arshi; Naser Javaher Tarash; Roya Sherkat; Hedayat Akbari; Reza Amin; Abdolvahab Alborzi; Sara Kashef; Reza Farid; Iraj Mohammadzadeh; Mehrnaz Sadeghi Shabestari; Mohammad Nabavi; Abolhassan Farhoudi
Journal:  J Clin Immunol       Date:  2006-10-06       Impact factor: 8.542

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  10 in total

1.  Primary Immunodeficiency Diseases in Saudi Arabia: a Tertiary Care Hospital Experience over a Period of Three Years (2010-2013).

Authors:  Bandar Al-Saud; Hamoud Al-Mousa; Sulaiman Al Gazlan; Abdulaziz Al-Ghonaium; Rand Arnaout; Amal Al-Seraihy; Sahar Elshorbagi; Nazeema Elsayed; Jawad Afzal; Hasan Al-Dhekri; Saleh Al-Muhsen
Journal:  J Clin Immunol       Date:  2015-09-22       Impact factor: 8.317

2.  Primary immunodeficiency diseases in children: 15 year experience in a tertiary care medical center in Qatar.

Authors:  Mohammad S Ehlayel; Abdulbari Bener; Mohammad Abu Laban
Journal:  J Clin Immunol       Date:  2012-10-03       Impact factor: 8.317

Review 3.  Report of the Tunisian Registry of Primary Immunodeficiencies: 25-Years of Experience (1988-2012).

Authors:  Fethi Mellouli; Imen Ben Mustapha; Monia Ben Khaled; Habib Besbes; Monia Ouederni; Najla Mekki; Meriem Ben Ali; Beya Larguèche; Mongia Hachicha; Tahar Sfar; Neji Gueddiche; Siheme Barsaoui; Azza Sammoud; Khadija Boussetta; Saida Ben Becher; Ahmed Meherzi; Najoua Guandoura; Lamia Boughammoura; Abdelaziz Harbi; Fethi Amri; Fethi Bayoudh; Najla Ben Jaballah; Neji Tebib; Asma Bouaziz; Abdelmajid Mahfoudh; Hajer Aloulou; Lamia Ben Mansour; Imen Chabchoub; Raoudha Boussoffara; Jalel Chemli; Jihène Bouguila; Saida Hassayoun; Saber Hammami; Zakia Habboul; Agnès Hamzaoui; Jamel Ammar; Mohamed-Ridha Barbouche; Mohamed Bejaoui
Journal:  J Clin Immunol       Date:  2015-10-13       Impact factor: 8.317

4.  Primary Immunodeficiency Diseases in Oman: 10-Year Experience in a Tertiary Care Hospital.

Authors:  Salem Al-Tamemi; Shafiq Ur Rehman Naseem; Nabila Al-Siyabi; Ibtisam El-Nour; Abdulhakim Al-Rawas; David Dennison
Journal:  J Clin Immunol       Date:  2016-10-03       Impact factor: 8.317

5.  The prevalences [correction] and patient characteristics of primary immunodeficiency diseases in Turkey--two centers study.

Authors:  Sara S Kilic; Mustafa Ozel; Demet Hafizoglu; Neslihan Edeer Karaca; Guzide Aksu; Necil Kutukculer
Journal:  J Clin Immunol       Date:  2012-09-15       Impact factor: 8.317

6.  Hereditary Deficiency of the Second Component of Complement: Early Diagnosis and 21-Year Follow-Up of a Family.

Authors:  Rosa Maria Dellepiane; Lucia Augusta Baselli; Marco Cazzaniga; Vassilios Lougaris; Paolo Macor; Mara Giordano; Roberta Gualtierotti; Massimo Cugno
Journal:  Medicina (Kaunas)       Date:  2020-03-10       Impact factor: 2.430

Review 7.  Infection in the Developing Brain: The Role of Unique Systemic Immune Vulnerabilities.

Authors:  Gabriela Singh; Elizabeth W Tucker; Ursula K Rohlwink
Journal:  Front Neurol       Date:  2022-01-24       Impact factor: 4.003

8.  Inborn Errors of Immunity in Algerian Children and Adults: A Single-Center Experience Over a Period of 13 Years (2008-2021).

Authors:  Brahim Belaid; Lydia Lamara Mahammed; Ouardia Drali; Aida Mohand Oussaid; Nabila Souad Touri; Souhila Melzi; Abdelhak Dehimi; Lylia Meriem Berkani; Fatma Merah; Zineb Larab; Ines Allam; Ouarda Khemici; Sonya Yasmine Kirane; Mounia Boutaba; Reda Belbouab; Hadjira Bekkakcha; Assia Guedouar; Abdelhakim Chelali; Brahim Baamara; Djamila Noui; Hadda Baaziz; Radia Rezak; Sidi Mohamed Azzouz; Malika Aichaoui; Assia Moktefi; Redha Mohamed Benhatchi; Meriem Oussalah; Naila Benaissa; Amel Laredj; Assia Bouchetara; Abdelkader Adria; Brahim Habireche; Noureddine Tounsi; Fella Dahmoun; Rabah Touati; Hamza Boucenna; Fadila Bouferoua; Lynda Sekfali; Nadjet Bouhafs; Rawda Aboura; Sakina Kherra; Yacine Inouri; Saadeddine Dib; Nawel Medouri; Noureddine Khelfaoui; Aicha Redjedal; Amara Zelaci; Samah Yahiaoui; Sihem Medjadj; Tahar Khelifi Touhami; Ahmed Kadi; Fouzia Amireche; Imane Frada; Shahrazed Houasnia; Karima Benarab; Chahynez Boubidi; Yacine Ferhani; Hayet Benalioua; Samia Sokhal; Nadia Benamar; Samira Aggoune; Karima Hadji; Asma Bellouti; Hakim Rahmoune; Nada Boutrid; Kamelia Okka; Assia Ammour; Houssem Saadoune; Malika Amroun; Hayet Belhadj; Amina Ghanem; Hanane Abbaz; Sana Boudrioua; Besma Zebiche; Assia Ayad; Zahra Hamadache; Nassima Ouaras; Nassima Achour; Nadira Bouchair; Houda Boudiaf; Dahila Bekkat-Berkani; Hachemi Maouche; Zahir Bouzrar; Lynda Aissat; Ouardia Ibsaine; Belkacem Bioud; Leila Kedji; Djazia Dahlouk; Manoubia Bensmina; Abdelkarim Radoui; Mimouna Bessahraoui; Nadia Bensaadi; Azzeddine Mekki; Zoulikha Zeroual; Koon-Wing Chan; Daniel Leung; Amar Tebaibia; Soraya Ayoub; Dalila Mekideche; Merzak Gharnaout; Jean Laurent Casanova; Anne Puel; Yu Lung Lau; Nacira Cherif; Samir Ladj; Leila Smati; Rachida Boukari; Nafissa Benhalla; Reda Djidjik
Journal:  Front Immunol       Date:  2022-04-21       Impact factor: 8.786

9.  Invasive meningococcal disease in three siblings with hereditary deficiency of the 8(th) component of complement: evidence for the importance of an early diagnosis.

Authors:  Rosa Maria Dellepiane; Laura Dell'Era; Paola Pavesi; Paolo Macor; Mara Giordano; Luca De Maso; Maria Cristina Pietrogrande; Massimo Cugno
Journal:  Orphanet J Rare Dis       Date:  2016-05-17       Impact factor: 4.123

10.  A First Case Report of DiGeorge Syndrome from Ethiopia Highlights Challenges in Identifying and Treating Children with Primary T-Cell Deficiencies in Low Resource Settings.

Authors:  Tinsae Alemayehu; Solomie Jebessa Deribessa
Journal:  Case Reports Immunol       Date:  2020-02-26
  10 in total

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