Literature DB >> 20812055

Digital clubbing in primary intestinal lymphangiectasia: a case report.

Christian J Wiedermann1, Michael Kob, Stefano Benvenuti, Rodolfo Carella, Lucio Lucchin, Lucia Piazzi, Fausto Chilovi, Guido Mazzoleni.   

Abstract

Primary intestinal lymphangiectasia (PIL), also known as Waldmann's disease, is a rare disorder characterized by dilated intestinal lacteals resulting in lymph leakage into the small bowel lumen and responsible for protein-losing enteropathy leading to lymphopenia, hypoalbuminemia and hypogammaglobulinemia. The symptoms usually start in early infancy. We report a case of secondary hyperparathyroidism, osteopenia, monoclonal gammopathy and digital clubbing in a 57-year-old patient with a 12-year history of discontinuous diarrhea. Malabsorption with inability to gain weight, and finally weight loss and formation of leg edema were associated with protein-losing enteropathy. A low-fat diet associated with medium-chain triglyceride supplementation was clinically effective as medical management in reducing diarrhea and leg edema, and promoting weight gain. Double-balloon enteroscopy and small bowel biopsy histopathology confirmed dilated intestinal lacteals. Digital clubbing associated with primary intestinal lymphangiectasia which may causally be related to chronic platelet excess has not been reported before.

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Year:  2010        PMID: 20812055     DOI: 10.1007/s10354-010-0815-0

Source DB:  PubMed          Journal:  Wien Med Wochenschr        ISSN: 0043-5341


  27 in total

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6.  Megakaryocytes and platelet clumps as the cause of finger clubbing.

Authors:  C J Dickinson; J F Martin
Journal:  Lancet       Date:  1987-12-19       Impact factor: 79.321

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Review 9.  Budesonide for Crohn's disease.

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Journal:  Expert Opin Drug Metab Toxicol       Date:  2009-08       Impact factor: 4.481

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Journal:  Arch Surg       Date:  1986-05
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  2 in total

Review 1.  Primary intestinal lymphangiectasia: Minireview.

Authors:  Sachin B Ingle; Chitra R Hinge Ingle
Journal:  World J Clin Cases       Date:  2014-10-16       Impact factor: 1.337

Review 2.  Primary intestinal lymphangiectasia in an adult patient: A case report and review of literature.

Authors:  Rudolf Huber; Georg Semmler; Alexander Mayr; Felix Offner; Christian Datz
Journal:  World J Gastroenterol       Date:  2020-12-08       Impact factor: 5.742

  2 in total

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