Literature DB >> 20532525

[Genetics of neuronal ceroidlipofuscinoses. Aspects of genetic counseling].

M N Preising1, B Lorenz.   

Abstract

Neuronal ceroid lipofuscinoses are autosomal recessive inherited disorders of neuronal cells. Neuronal ceroid lipofuscinoses belong to the lysosomal storage disorders and are characterized by accumulation of protein-lipid complexes in the lysosomal compartments of all somatic cells. This debris causes degenerative activities in the nervous system, especially in the cerebrum, the cerebellum and the afferent and efferent cranial nerves. With one exception of adult onset the disorder causes the loss of receptive, cognitive and control function in the first decade of life and an early death by the age of 20. Currently 10 loci are known which correlate to 8 genes. The genotype related phenotype and the correlated prognosis depend on the underlying gene and type of mutation. The genotype phenotype correlation is hampered by a lack of knowledge on the function of the mutant gene products. In this review we summarize the known genetic data on neuronal ceroid lipofuscinoses and comment on therapeutic approaches.

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Mesh:

Year:  2010        PMID: 20532525     DOI: 10.1007/s00347-009-2107-x

Source DB:  PubMed          Journal:  Ophthalmologe        ISSN: 0941-293X            Impact factor:   1.059


  10 in total

1.  Homogeneous polymerase chain reaction nucleobase quenching assay to detect the 1-kbp deletion in CLN3 that causes Batten disease.

Authors:  Paul G Rothberg; Denia Ramirez-Montealegre; Sharon D Frazier; David A Pearce
Journal:  J Mol Diagn       Date:  2004-08       Impact factor: 5.568

Review 2.  Diagnosis of the neuronal ceroid lipofuscinoses: an update.

Authors:  Ruth E Williams; Laura Aberg; Taina Autti; Hans H Goebel; Alfried Kohlschütter; Tuula Lönnqvist
Journal:  Biochim Biophys Acta       Date:  2006-07-12

Review 3.  Correlations between genotype, ultrastructural morphology and clinical phenotype in the neuronal ceroid lipofuscinoses.

Authors:  Sara E Mole; Ruth E Williams; Hans H Goebel
Journal:  Neurogenetics       Date:  2005-09-28       Impact factor: 2.660

4.  Cathepsin D deficiency is associated with a human neurodegenerative disorder.

Authors:  Robert Steinfeld; Konstanze Reinhardt; Kathrin Schreiber; Merle Hillebrand; Ralph Kraetzner; Wolfgang Bruck; Paul Saftig; Jutta Gartner
Journal:  Am J Hum Genet       Date:  2006-03-29       Impact factor: 11.025

Review 5.  Functional biology of the neuronal ceroid lipofuscinoses (NCL) proteins.

Authors:  Aija Kyttälä; Ulla Lahtinen; Thomas Braulke; Sandra L Hofmann
Journal:  Biochim Biophys Acta       Date:  2006-06-03

Review 6.  Molecular genetics of the NCLs -- status and perspectives.

Authors:  Eija Siintola; Anna-Elina Lehesjoki; Sara E Mole
Journal:  Biochim Biophys Acta       Date:  2006-05-27

7.  Cathepsin D deficiency underlies congenital human neuronal ceroid-lipofuscinosis.

Authors:  Eija Siintola; Sanna Partanen; Petter Strömme; Aleksi Haapanen; Matti Haltia; Jan Maehlen; Anna-Elina Lehesjoki; Jaana Tyynelä
Journal:  Brain       Date:  2006-05-02       Impact factor: 13.501

8.  Mutations in the palmitoyl-protein thioesterase gene (PPT; CLN1) causing juvenile neuronal ceroid lipofuscinosis with granular osmiophilic deposits.

Authors:  H M Mitchison; S L Hofmann; C H Becerra; P B Munroe; B D Lake; Y J Crow; J B Stephenson; R E Williams; I L Hofman; P E Taschner; J J Martin; M Philippart; E Andermann; F Andermann; S E Mole; R M Gardiner; A M O'Rawe
Journal:  Hum Mol Genet       Date:  1998-02       Impact factor: 6.150

Review 9.  Neuronal ceroid lipofuscinoses.

Authors:  Anu Jalanko; Thomas Braulke
Journal:  Biochim Biophys Acta       Date:  2008-11-24

Review 10.  Neuronal ceroid-lipofuscinoses in childhood.

Authors:  P Santavuori
Journal:  Brain Dev       Date:  1988       Impact factor: 1.961

  10 in total
  2 in total

Review 1.  Review and update on the molecular basis of Leber congenital amaurosis.

Authors:  Oscar Francisco Chacon-Camacho; Juan Carlos Zenteno
Journal:  World J Clin Cases       Date:  2015-02-16       Impact factor: 1.337

2.  [Neurological alterations and intellectual deficits with sudden visual loss in a 7-year-old boy].

Authors:  A Gotz-Wieckowska; M Pawlak; J Siwiec-Proscinska; M Seget
Journal:  Ophthalmologe       Date:  2013-05       Impact factor: 1.059

  2 in total

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