Literature DB >> 20462663

Acral lesions in tuberous sclerosis complex: insights into pathogenesis.

Capt Shelley L Aldrich1, Chien-Hui Hong, Leslie Groves, Cara Olsen, Joel Moss, Thomas N Darling.   

Abstract

BACKGROUND: Patients with tuberous sclerosis complex (TSC) are predisposed to developing ungual fibromas and other acral lesions.
OBJECTIVE: We sought to determine the numbers, types, and locations of acral skin lesions in TSC.
METHODS: We examined and photographed 76 adult women with TSC.
RESULTS: The age of the patients ranged from 20 to 69 years, with a mean age of 39 +/- 11 years. Ungual fibromas were observed in 61 of 76 patients (80%). Periungual fibromas were more common than subungual fibromas, were more common on the feet than the hands, and showed the greatest frequency on the fifth toe. Longitudinal grooves in the nails occurred with or without a visible fibroma. Longitudinal short red streaks--lesions that we term "red comets"--were observed in 22 patients (29%). Longitudinal leukonychia was observed in 14 patients (18%). One patient had isolated digital overgrowth and one patient had pachydermodactyly. LIMITATIONS: No men or children were included in this study.
CONCLUSIONS: Examination of patients for skin lesions of TSC could be improved by including inspection for longitudinal nail grooves, red comets, longitudinal leukonychia, and splinter hemorrhages in addition to ungual fibromas. The anatomic distribution of TSC ungual fibromas is not random and appears consistent with trauma-promoted tumor formation. Copyright 2009 American Academy of Dermatology, Inc. Published by Mosby, Inc. All rights reserved.

Entities:  

Mesh:

Year:  2010        PMID: 20462663      PMCID: PMC2947366          DOI: 10.1016/j.jaad.2009.08.042

Source DB:  PubMed          Journal:  J Am Acad Dermatol        ISSN: 0190-9622            Impact factor:   11.527


  33 in total

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2.  Subungual splinter hemorrhages: a clinical window to inhibition of vascular endothelial growth factor receptors?

Authors:  Caroline Robert; Sandrine Faivre; Eric Raymond; Jean-Pierre Armand; Bernard Escudier
Journal:  Ann Intern Med       Date:  2005-08-16       Impact factor: 25.391

3.  Tuberous sclerosis. Special reference to the microscopic alterations in the cutaneous hamartomas.

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Journal:  Br J Dermatol       Date:  1996-07       Impact factor: 9.302

5.  The significance of a single periungual fibroma: report of seven cases.

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Journal:  Arch Dermatol       Date:  1995-12

6.  Subungual glomus tumor: clinical manifestations and outcome of surgical treatment.

Authors:  Sang Eun Moon; Jong Hyun Won; Oh Sang Kwon; Jeong Aee Kim
Journal:  J Dermatol       Date:  2004-12       Impact factor: 4.005

Review 7.  Clinical and molecular insights into lymphangioleiomyomatosis.

Authors:  Wendy K Steagall; Angelo M Taveira-DaSilva; Joel Moss
Journal:  Sarcoidosis Vasc Diffuse Lung Dis       Date:  2005-12       Impact factor: 0.670

8.  Skin lesions in children with tuberous sclerosis complex: their prevalence, natural course, and diagnostic significance.

Authors:  S Jóźwiak; R A Schwartz; C K Janniger; R Michałowicz; J Chmielik
Journal:  Int J Dermatol       Date:  1998-12       Impact factor: 2.736

Review 9.  Tuberous sclerosis complex consensus conference: revised clinical diagnostic criteria.

Authors:  E S Roach; M R Gomez; H Northrup
Journal:  J Child Neurol       Date:  1998-12       Impact factor: 1.987

10.  MCP-1 overexpressed in tuberous sclerosis lesions acts as a paracrine factor for tumor development.

Authors:  Shaowei Li; Fumiko Takeuchi; Ji-an Wang; Christopher Fuller; Gustavo Pacheco-Rodriguez; Joel Moss; Thomas N Darling
Journal:  J Exp Med       Date:  2005-08-29       Impact factor: 14.307

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  10 in total

1.  Tuberous sclerosis complex diagnostic criteria update: recommendations of the 2012 Iinternational Tuberous Sclerosis Complex Consensus Conference.

Authors:  Hope Northrup; Darcy A Krueger
Journal:  Pediatr Neurol       Date:  2013-10       Impact factor: 3.372

2.  Histologic variants of periungual fibromas in tuberous sclerosis complex.

Authors:  Deqin Ma; Thomas Darling; Joel Moss; Chyi-Chia Richard Lee
Journal:  J Am Acad Dermatol       Date:  2011-02       Impact factor: 11.527

3.  Recognition of tuberous sclerosis in adult women: delayed presentation with life-threatening consequences.

Authors:  Diane Seibert; Chien-Hui Hong; Fumiko Takeuchi; Cara Olsen; Olonda Hathaway; Joel Moss; Thomas N Darling
Journal:  Ann Intern Med       Date:  2011-06-21       Impact factor: 25.391

4.  Symptomatic Periungual Fibroma of the Hand.

Authors:  Camelia Qian Ying Tang; Audrey Qi Xin Chia; Sreedharan Sechachalam
Journal:  J Hand Microsurg       Date:  2020-04-13

5.  Tuberous sclerosis and its rare association with macrodactyly and fibrous hamartomas.

Authors:  Y S Lim; M S Mak; P C Mohan
Journal:  Skeletal Radiol       Date:  2017-06-03       Impact factor: 2.199

6.  Onychogryphosis in tuberous sclerosis complex: an unusual feature.

Authors:  Xiang-Chun Han; Li-Qiang Zheng; Tie-Gang Zheng
Journal:  An Bras Dermatol       Date:  2016 Sep-Oct       Impact factor: 1.896

7.  Trends in the prevalence of tuberous sclerosis complex manifestations: an epidemiological study of 166 Japanese patients.

Authors:  Mari Wataya-Kaneda; Mari Tanaka; Toshimitsu Hamasaki; Ichiro Katayama
Journal:  PLoS One       Date:  2013-05-17       Impact factor: 3.240

8.  Miliary fibromas in tuberous sclerosis complex.

Authors:  A M Cartron; D Buccine; A M Treichel; C R Lee; J Moss; T N Darling
Journal:  J Eur Acad Dermatol Venereol       Date:  2021-02-23       Impact factor: 9.228

9.  Nipple Angiofibromas with Loss of TSC2 Are Associated with Tuberous Sclerosis Complex.

Authors:  Neera Nathan; Magdalena E Tyburczy; Lana Hamieh; Ji-An Wang; G Thomas Brown; Chyi-Chia Richard Lee; David J Kwiatkowski; Joel Moss; Thomas N Darling
Journal:  J Invest Dermatol       Date:  2015-12-10       Impact factor: 8.551

Review 10.  Leukonychia: What Can White Nails Tell Us?

Authors:  Matilde Iorizzo; Michela Starace; Marcel C Pasch
Journal:  Am J Clin Dermatol       Date:  2022-02-02       Impact factor: 7.403

  10 in total

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