| Literature DB >> 20132077 |
U Holzer1, A van Royen-Kerkhof, P van der Torre, J Kuemmerle-Deschner, C Well, R Handgretinger, I Mueller, N Wulffraat.
Abstract
Juvenile dermatomyositis (JDM) is a chronic inflammatory disorder of unknown aetiology that affects muscle and skin. We report on two patients with severe progressive JDM who developed contractures and were wheelchair dependent despite therapy including methotrexate (MTX), steroids, immunoglobulins, cyclosporin A, and rituximab. On account of the refractory disease, autologous stem cell transplantation (ASCT) was performed using a CD3/CD19-depleted graft after immunoablative conditioning with fludarabine, cyclophosphamide, and anti-thymocyte globulin. This induced a dramatic improvement and sustained remission of the disease in both patients. We demonstrate that ASCT is a therapeutic option with low toxicity for patients with severe, refractory JDM.Entities:
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Year: 2010 PMID: 20132077 DOI: 10.3109/03009740903096622
Source DB: PubMed Journal: Scand J Rheumatol ISSN: 0300-9742 Impact factor: 3.641