Literature DB >> 20055781

Neonatal liver failure and haemophagocytic lymphohistiocytosis caused by a new perforin mutation.

O Danhaive1, M Caniglia1, R Devito1, F Piersigilli1, C Corchia1, C Auriti1.   

Abstract

UNLABELLED: Acute liver failure is a rare heterogeneous syndrome in neonates. We report of a newborn with haemophagocytic lymphohistiocytosis presenting as acute liver failure. Pancytopenia and multi-organ failure occurred later in the course. He carried two mutations of the perforin gene (PRF-1), one of which not previously described, causing a complete loss of perforin expression and natural killer cell function.
CONCLUSION: Perforin expression and function should be promptly assessed in neonatal/infantile acute liver failure, as haemophagocytic lymphohistiocytosis requires specific treatment and represents a contra-indication to liver transplant.

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Year:  2009        PMID: 20055781     DOI: 10.1111/j.1651-2227.2009.01647.x

Source DB:  PubMed          Journal:  Acta Paediatr        ISSN: 0803-5253            Impact factor:   2.299


  4 in total

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4.  Late-onset hemophagocytic lymphohistiocytosis with neurological presentation.

Authors:  Sarah Benezech; Thierry Walzer; Emily Charrier; Damien Heidelberg; Geneviève De Saint-Basile; Yves Bertrand; Alexandre Belot
Journal:  Clin Case Rep       Date:  2017-09-12
  4 in total

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