| Literature DB >> 19779134 |
Stavros Bashiardes1, Ludmila Kousoulidou, Hans van Bokhoven, Hans-Hilger Ropers, Jamel Chelly, Claude Moraine, Arjan P M de Brouwer, Hilde Van Esch, Guy Froyen, Philippos C Patsalis.
Abstract
Recent studies and advances in high-density oligonucleotide arrays have shown that microdeletions and microduplications occur at a high frequency in the human genome, causing various genetic conditions including mental retardation. Thus far little is known about the pathways leading to this disease, and implementation of microarrays is hampered by their increasing cost and complexity, underlining the need for new diagnostic tools. The aim of this study was to introduce a new targeted platform called "chromosome X exon-specific array" and to apply this new platform to screening of 20 families (including one blind positive control) with suspected X-linked mental retardation, to identify new causative X-linked mental retardation genes. The new microarray contains of 21,939 oligonucleotides covering 92.9% of all exons of all genes on chromosome X. Patient screening resulted in successful identification of the blind positive control included in the sample of 20 families, and one of the remaining 19 families was found to carry a 1.78-kilobase deletion involving all exons of pseudogene BRAF2. The BRAF2 deletion segregated in the family and was not found in 200 normal male samples, and no copy number variations are reported in this region. Further studies and focused investigation of X-linked disorders have the potential to reveal the molecular basis of human genetic pathological conditions that are caused by copy-number changes in chromosome X genes.Entities:
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Year: 2009 PMID: 19779134 PMCID: PMC2765755 DOI: 10.2353/jmoldx.2009.090086
Source DB: PubMed Journal: J Mol Diagn ISSN: 1525-1578 Impact factor: 5.568