Literature DB >> 19768759

Evolution of the phenotype in a family with an LMNA gene mutation presenting with isolated cardiac involvement.

Nicola Carboni1, Maurizio Porcu, Marco Mura, Eleonora Cocco, Giovanni Marrosu, Maria A Maioli, Elisabetta Solla, Stefania Tranquilli, Pierpaolo Orrù, Maria G Marrosu.   

Abstract

The aim of this study is to report the evolution of a phenotype in members of a single family carrying the heterozygous exon 1 c.178 C/G, p.Arg 60 Gly LMNA gene mutation. All mutated family members underwent neurological and cardiological assessments for a period ranging from 10 to 20 years. At onset, 4 affected adult members presented a phenotype that required pacemaker implantation. Three subjects underwent cardiac transplantation leading to long-term survival in 2 of them. One of the 3 longest surviving relatives manifested late lipodystrophy, and the other 2 had lipodystrophy, insulin-resistant diabetes, and distal peripheral neuropathy. The findings demonstrate that the exon 1 c.178 C/G, p.Arg 60 Gly LMNA gene mutation is associated with a novel phenotype featuring cardiac involvement followed by late lipodystrophy, diabetes, and peripheral axonal neuropathy.

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Year:  2010        PMID: 19768759     DOI: 10.1002/mus.21443

Source DB:  PubMed          Journal:  Muscle Nerve        ISSN: 0148-639X            Impact factor:   3.217


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  7 in total

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