Literature DB >> 19700862

Detection of combined genomic variants in a Jordanian family with familial non-autoimmune hyperthyroidism.

Said I Ismail1, Ismail S Mahmoud, Mahmoud Al-Ardah, Amid Abdelnour, Nidal A Younes.   

Abstract

Five patients, four brothers and their paternal aunt, presented with a history of overt hyperthyroidism and goiter. Hyperthyroidism in this family was remarkable for its poor response to carbimazole (30-50 mg/d). The thyroid ultrasound showed a diffusely enlarged gland in all the affected members, and thyroid stimulating antibodies (TSAB) were negative. Screening for germline mutations in thyroid stimulating hormone (TSH) receptor (TSHR) gene was performed by direct sequencing of genomic DNA extracted from peripheral blood leukocytes of all family members. The sequence analysis of all TSHR gene exons and intron borders revealed two genomic variants. The first was a single nucleotide polymorphism (SNP) within exon seven (Asn187Asn), whereas the other was located in intron seven (IVS7+68TG). All affected members, two asymptomatic brothers with sub-clinical hyperthyroidism, and their father were heterozygous for those two genomic variants. Anti-thyroid drug treatment for several months successfully relieved symptoms in one subject, whereas the remaining patients required total thyroidectomy to control their disease. This is the first Jordanian family with familial non-autoimmune hyperthyroidism, with mutations affecting the TSHR gene.

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Year:  2009        PMID: 19700862     DOI: 10.1007/s12041-009-0032-z

Source DB:  PubMed          Journal:  J Genet        ISSN: 0022-1333            Impact factor:   1.166


  34 in total

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2.  A novel intronic mutation in the DDP1 gene in a family with X-linked dystonia-deafness syndrome.

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3.  Novel thyrotropin receptor germline mutation (Ile568Val) in a Saxonian family with hereditary nonautoimmune hyperthyroidism.

Authors:  Maren Claus; Jacqueline Maier; Ralf Paschke; Christoph Kujat; Michael Stumvoll; Dagmar Führer
Journal:  Thyroid       Date:  2005-09       Impact factor: 6.568

4.  Novel TSHR germline mutation (Met463Val) masquerading as Graves' disease in a large Welsh kindred with hyperthyroidism.

Authors:  D Fuhrer; J Warner; M Sequeira; R Paschke; J Gregory; M Ludgate
Journal:  Thyroid       Date:  2000-12       Impact factor: 6.568

5.  A novel intronic mutation of the TAZ ( G4.5) gene in a patient with Barth syndrome: creation of a 5' splice donor site with variant GC consensus and elongation of the upstream exon.

Authors:  O Sakamoto; T Ohura; Y Katsushima; I Fujiwara; E Ogawa; S Miyabayashi; K Iinuma
Journal:  Hum Genet       Date:  2001-10-13       Impact factor: 4.132

6.  A family with a novel TSH receptor activating germline mutation (p.Ala485Val).

Authors:  Sema Akcurin; Doga Turkkahraman; Carolyn Tysoe; Sian Ellard; Anne De Leener; Gilbert Vassart; Sabine Costagliola
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7.  Functional splicing assay shows a pathogenic intronic mutation in neurofibromatosis type 1 (NF1) due to intronic sequence exonization.

Authors:  M Raponi; M Upadhyaya; D Baralle
Journal:  Hum Mutat       Date:  2006-03       Impact factor: 4.878

8.  A novel TSHR gene mutation (Ile691Phe) in a Chinese family causing autosomal dominant non-autoimmune hyperthyroidism.

Authors:  Zheng Liu; Yuanming Sun; Qingming Dong; Mingliang He; Christopher H K Cheng; Feiyue Fan
Journal:  J Hum Genet       Date:  2008-02-29       Impact factor: 3.172

Review 9.  Premature birth and low birth weight associated with nonautoimmune hyperthyroidism due to an activating thyrotropin receptor gene mutation.

Authors:  Bijay Vaidya; Viv Campbell; John H Tripp; Gill Spyer; Andrew T Hattersley; Sian Ellard
Journal:  Clin Endocrinol (Oxf)       Date:  2004-06       Impact factor: 3.478

Review 10.  Genomic variants in exons and introns: identifying the splicing spoilers.

Authors:  Franco Pagani; Francisco E Baralle
Journal:  Nat Rev Genet       Date:  2004-05       Impact factor: 53.242

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  2 in total

1.  Lack of association between autonomously functioning thyroid nodules and germline polymorphisms of the thyrotropin receptor and Gαs genes in a mild to moderate iodine-deficient Caucasian population.

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Journal:  J Endocrinol Invest       Date:  2014-05-01       Impact factor: 4.256

2.  Characteristics of thyrotoxicosis among thyroid patients and their quality of life in a teaching hospital in Jordan: A cross-sectional study.

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Journal:  Pharm Pract (Granada)       Date:  2022-01-17
  2 in total

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