Literature DB >> 19697114

Multiple sulfatase deficiency: clinical report and description of two novel mutations in a Brazilian patient.

Osvaldo Alfonso Artigalás1, Luiz Roberto da Silva, Maira Burin, Gregory M Pastores, Bai Zeng, Nívea Macedo, Ida Vanessa Doederlein Schwartz.   

Abstract

Multiple Sulfatase Deficiency (MSD) is a rare autosomal recessive disease in which the activities of all sulfatases are reduced; its estimated prevalence is 1:1.4 million births. The disease is caused by mutations in SUMF1, which encodes an enzyme involved in the post-translational modification of sulfatases. The MSD phenotype is a combination of the clinical features found in diseases resulting from a deficiency of the individual sulfatases; i.e., mucopolysaccharidosis II, IIIA, IIID, IVA and VI, metachromatic leukodystrophy, X-linked ichthyosis, and the X-linked recessive form of chondrodysplasia punctata. We describe herein the first case of a Brazilian patient with MSD. The case was initially diagnosed as having mucopolysaccharidosis (MPS), due to skeletal alterations, coarse facial features, and urinary excretion of dermatan sulfate and heparan sulfate. Later, after a detailed biochemical investigation, the diagnosis of MSD was established. The analysis of the SUMF1 showed the patient was a compound heterozygote for two novel mutations (p.R349G and p.F244S). This case illustrates the challenges in the diagnosis of a disease considered rare, such as MSD. We point out that the availability of therapy for certain MPS disorders necessitates correct disease assignment, and the need to exclude the likelihood of MSD.

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Year:  2009        PMID: 19697114     DOI: 10.1007/s11011-009-9151-8

Source DB:  PubMed          Journal:  Metab Brain Dis        ISSN: 0885-7490            Impact factor:   3.584


  11 in total

1.  Saudi variant of multiple sulfatase deficiency.

Authors:  A al Aqeel; P T Ozand; J Brismar; G G Gascon; G Brismar; M Nester; N Sakati
Journal:  J Child Neurol       Date:  1992-04       Impact factor: 1.987

2.  Molecular characterization of the human Calpha-formylglycine-generating enzyme.

Authors:  Andrea Preusser-Kunze; Malaiyalam Mariappan; Bernhard Schmidt; Santosh Lakshmi Gande; Kudzai Mutenda; Dirk Wenzel; Kurt von Figura; Thomas Dierks
Journal:  J Biol Chem       Date:  2005-01-18       Impact factor: 5.157

3.  Pitfalls in the diagnosis of multiple sulfatase deficiency.

Authors:  G M Mancini; O P van Diggelen; J G Huijmans; H Stroink; R F de Coo
Journal:  Neuropediatrics       Date:  2001-02       Impact factor: 1.947

4.  Molecular basis for multiple sulfatase deficiency and mechanism for formylglycine generation of the human formylglycine-generating enzyme.

Authors:  Thomas Dierks; Achim Dickmanns; Andrea Preusser-Kunze; Bernhard Schmidt; Malaiyalam Mariappan; Kurt von Figura; Ralf Ficner; Markus Georg Rudolph
Journal:  Cell       Date:  2005-05-20       Impact factor: 41.582

5.  Molecular analysis of SUMF1 mutations: stability and residual activity of mutant formylglycine-generating enzyme determine disease severity in multiple sulfatase deficiency.

Authors:  Lars Schlotawa; Robert Steinfeld; Kurt von Figura; Thomas Dierks; Jutta Gärtner
Journal:  Hum Mutat       Date:  2008-01       Impact factor: 4.878

6.  Multiple sulfatase deficiency is caused by mutations in the gene encoding the human C(alpha)-formylglycine generating enzyme.

Authors:  Thomas Dierks; Bernhard Schmidt; Ljudmila V Borissenko; Jianhe Peng; Andrea Preusser; Malaiyalam Mariappan; Kurt von Figura
Journal:  Cell       Date:  2003-05-16       Impact factor: 41.582

7.  Multiple sulfatase deficiency in a Turkish family resulting from a novel mutation.

Authors:  Uluç Yiş; Stefano Pepe; Semra Hiz Kurul; Andrea Ballabio; Maria Pia Cosma; Eray Dirik
Journal:  Brain Dev       Date:  2008-05       Impact factor: 1.961

8.  Prevalence of lysosomal storage disorders.

Authors:  P J Meikle; J J Hopwood; A E Clague; W F Carey
Journal:  JAMA       Date:  1999-01-20       Impact factor: 56.272

Review 9.  The sulfatase gene family.

Authors:  G Parenti; G Meroni; A Ballabio
Journal:  Curr Opin Genet Dev       Date:  1997-06       Impact factor: 5.578

10.  Molecular and functional analysis of SUMF1 mutations in multiple sulfatase deficiency.

Authors:  Maria Pia Cosma; Stefano Pepe; Giancarlo Parenti; Carmine Settembre; Ida Annunziata; Richard Wade-Martins; Carmela Di Domenico; Paola Di Natale; Anuj Mankad; Barbara Cox; Graziella Uziel; Grazia M S Mancini; Enrico Zammarchi; Maria Alice Donati; Wim J Kleijer; Mirella Filocamo; Romeo Carrozzo; Massimo Carella; Andrea Ballabio
Journal:  Hum Mutat       Date:  2004-06       Impact factor: 4.878

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  2 in total

1.  SUMF1 mutations affecting stability and activity of formylglycine generating enzyme predict clinical outcome in multiple sulfatase deficiency.

Authors:  Lars Schlotawa; Eva Charlotte Ennemann; Karthikeyan Radhakrishnan; Bernhard Schmidt; Anupam Chakrapani; Hans-Jürgen Christen; Hugo Moser; Beat Steinmann; Thomas Dierks; Jutta Gärtner
Journal:  Eur J Hum Genet       Date:  2011-01-12       Impact factor: 4.246

2.  Late infantile form of multiple sulfatase deficiency.

Authors:  Nami Mohammadian Khonsari; Benyamin Hakak-Zargar; Tessa Voth; Shahab Noorian
Journal:  Endocrinol Diabetes Metab Case Rep       Date:  2020-09-23
  2 in total

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