Literature DB >> 1961718

Identification of the second common Jewish Gaucher disease mutation makes possible population-based screening for the heterozygous state.

E Beutler1, T Gelbart, W Kuhl, J Sorge, C West.   

Abstract

Gaucher disease is an autosomal recessive glycolipid storage disease characterized by a deficiency of glucocerebrosidase. The disease is most common in persons of Ashkenazi Jewish ancestry and the most common mutation, accounting for about 75% of the mutant alleles in this population, is known to be an A----G substitution at cDNA nucleotide (nt) 1226. Screening for this disease has not been possible because nearly 25% of the mutant alleles had not been identified, but linkage analysis led to the suggestion that most of these could be accounted for by a single mutation. We now report the discovery of this mutation. The insertion of a single nucleotide, a second guanine at cDNA nt 84 (the 84GG mutation), has been detected in the 5' coding region of the glucocerebrosidase gene. The amount of mRNA produced is shown to be normal but since the frameshift produced early termination, no translation product is seen. This finding is consistent with the virtual absence of antigen found in patients carrying this mutation. The 84GG mutation accounts for most of the previously unidentified Gaucher disease mutations in Jewish patients. The common Jewish mutation at nt 1226, the 84GG mutation, and the less-common mutation at nt 1448 accounted for 95% of all of the Gaucher disease-producing alleles in 71 Jewish patients. This now makes it possible to screen for heterozygotes on a DNA level with a relatively low risk of missing couples at risk for producing infants with Gaucher disease.

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Year:  1991        PMID: 1961718      PMCID: PMC52965          DOI: 10.1073/pnas.88.23.10544

Source DB:  PubMed          Journal:  Proc Natl Acad Sci U S A        ISSN: 0027-8424            Impact factor:   11.205


  25 in total

1.  Genetic heterogeneity in type 1 Gaucher disease: multiple genotypes in Ashkenazic and non-Ashkenazic individuals.

Authors:  S Tsuji; B M Martin; J A Barranger; B K Stubblefield; M E LaMarca; E I Ginns
Journal:  Proc Natl Acad Sci U S A       Date:  1988-04       Impact factor: 11.205

2.  An improved method for prenatal diagnosis of genetic diseases by analysis of amplified DNA sequences. Application to hemophilia A.

Authors:  S C Kogan; M Doherty; J Gitschier
Journal:  N Engl J Med       Date:  1987-10-15       Impact factor: 91.245

3.  Molecular cloning and nucleotide sequence of human glucocerebrosidase cDNA.

Authors:  J Sorge; C West; B Westwood; E Beutler
Journal:  Proc Natl Acad Sci U S A       Date:  1985-11       Impact factor: 11.205

4.  Detection of the defect of Gaucher's disease and its carrier state in peripheral-blood leucocytes.

Authors:  E Beutler; W Kuhl
Journal:  Lancet       Date:  1970-03-21       Impact factor: 79.321

5.  The human glucocerebrosidase gene and pseudogene: structure and evolution.

Authors:  M Horowitz; S Wilder; Z Horowitz; O Reiner; T Gelbart; E Beutler
Journal:  Genomics       Date:  1989-01       Impact factor: 5.736

6.  A glucocerebrosidase fusion gene in Gaucher disease. Implications for the molecular anatomy, pathogenesis, and diagnosis of this disorder.

Authors:  A Zimran; J Sorge; E Gross; M Kubitz; C West; E Beutler
Journal:  J Clin Invest       Date:  1990-01       Impact factor: 14.808

7.  The human glucocerebrosidase gene has two functional ATG initiator codons.

Authors:  J A Sorge; C West; W Kuhl; L Treger; E Beutler
Journal:  Am J Hum Genet       Date:  1987-12       Impact factor: 11.025

8.  Gaucher disease type 1: cloning and characterization of a cDNA encoding acid beta-glucosidase from an Ashkenazi Jewish patient.

Authors:  P N Graves; G A Grabowski; R Eisner; P Palese; F I Smith
Journal:  DNA       Date:  1988-10

9.  A mutation in the human glucocerebrosidase gene in neuronopathic Gaucher's disease.

Authors:  S Tsuji; P V Choudary; B M Martin; B K Stubblefield; J A Mayor; J A Barranger; E I Ginns
Journal:  N Engl J Med       Date:  1987-03-05       Impact factor: 91.245

10.  Heterogeneity in type I Gaucher disease demonstrated by restriction mapping of the gene.

Authors:  J Sorge; T Gelbart; C West; B Westwood; E Beutler
Journal:  Proc Natl Acad Sci U S A       Date:  1985-08       Impact factor: 11.205

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  25 in total

1.  Glucosidase acid beta gene mutations in Egyptian children with Gaucher disease and relation to disease phenotypes.

Authors:  Zakarya El-Morsy; Mohamed T Khashaba; Othman El-Sayed Soliman; Sohier Yahia; Dina Abd El-Hady
Journal:  World J Pediatr       Date:  2011-06-01       Impact factor: 2.764

2.  Linkage and association.

Authors:  U Langenbeck
Journal:  J Inherit Metab Dis       Date:  1995       Impact factor: 4.982

3.  Characteristics of gene mutations among 32 unrelated Japanese Gaucher disease patients: absence of the common Jewish 84GG and 1226G mutations.

Authors:  H Ida; K Iwasawa; H Kawame; O M Rennert; K Maekawa; Y Eto
Journal:  Hum Genet       Date:  1995-06       Impact factor: 4.132

4.  Role of pH in determining the cell-type-specific residual activity of glucocerebrosidase in type 1 Gaucher disease.

Authors:  S van Weely; M van den Berg; J A Barranger; M C Sa Miranda; J M Tager; J M Aerts
Journal:  J Clin Invest       Date:  1993-03       Impact factor: 14.808

5.  Gaucher's disease in the United Kingdom: screening non-Jewish patients for the two common mutations.

Authors:  A J Walley; M L Barth; I Ellis; A H Fensom; A Harris
Journal:  J Med Genet       Date:  1993-04       Impact factor: 6.318

Review 6.  Gaucher disease as a paradigm of current issues regarding single gene mutations of humans.

Authors:  E Beutler
Journal:  Proc Natl Acad Sci U S A       Date:  1993-06-15       Impact factor: 11.205

7.  Clinical and molecular characteristics of Japanese Gaucher disease.

Authors:  Y Eto; H Ida
Journal:  Neurochem Res       Date:  1999-02       Impact factor: 3.996

8.  Prevalence of nine mutations among Jewish and non-Jewish Gaucher disease patients.

Authors:  M Horowitz; G Tzuri; N Eyal; A Berebi; E H Kolodny; R O Brady; N W Barton; A Abrahamov; A Zimran
Journal:  Am J Hum Genet       Date:  1993-10       Impact factor: 11.025

9.  Phenotypic and genotypic heterogeneity in gaucher disease: Implications for genetic counseling.

Authors:  E Sidransky; E I Ginns
Journal:  J Genet Couns       Date:  1994-03       Impact factor: 2.537

10.  False-positive results using a Gaucher diagnostic kit--RecTL and N370S.

Authors:  Jae Hyuk Choi; Arash Velayati; Barbara K Stubblefield; Avi Orr-Urtreger; Ziv Gan-Or; Nahid Tayebi; Ellen Sidransky
Journal:  Mol Genet Metab       Date:  2010-01-04       Impact factor: 4.797

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