Literature DB >> 19546057

Pituitary macroadenoma in a patient with POEMS syndrome in conjunction with Castleman disease: first report of a case and review of related literature.

Carolina Bruno1, James D Fleck, Melissa K Cavaghan.   

Abstract

OBJECTIVE: To describe the first reported case of a patient with POEMS syndrome (polyneuropathy, organomegaly, endocrinopathy, monoclonal gammopathy, and skin changes) in conjunction with the endocrinologic manifestation of panhypopituitarism due to a large clinically nonfunctioning pituitary adenoma.
METHODS: We present the clinical, laboratory, and radiologic details of the case and review the relevant updated literature.
RESULTS: A 48-year-old man with hypopituitarism and progressive polyneuropathy presented to an outside hospital with confusion and diaphoresis. He also had diffuse lymphadenopathy, monoclonal gammopathy, and skin lesions consistent with a diagnosis of POEMS syndrome. Cytopathologic study of a lymph node showed findings consistent with Castleman disease. A large suprasellar mass was found to be the cause of the hypopituitarism.
CONCLUSION: POEMS syndrome is a rare paraneoplastic condition, commonly associated with Castleman disease, that manifests with progressive distal polyneuropathy and a monoclonal plasma cell disorder, often accompanied by endocrinopathy, organomegaly, skin changes, sclerotic bone lesions, ascites, erythrocytosis, and thrombocytosis. Our current patient had all 5 classic features of POEMS syndrome along with some diagnostic elements of Castleman disease, sclerotic bone lesions, and thrombocytosis. To our knowledge, this is the first known reported case of a patient whose endocrinologic manifestation of POEMS syndrome was panhypopituitarism attributable to a large clinically nonfunctioning pituitary adenoma.

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Year:  2010        PMID: 19546057     DOI: 10.4158/EP09027.CRR

Source DB:  PubMed          Journal:  Endocr Pract        ISSN: 1530-891X            Impact factor:   3.443


  3 in total

1.  Multicentric Castleman's disease in a Ghanaian adult.

Authors:  Y A Dei-Adomakoh; C Segbefia; I Ekem; A Taylor
Journal:  Ghana Med J       Date:  2013-06

Review 2.  Castleman Disease: A Rare Condition with Endocrine Manifestations.

Authors:  Carmen E Cervantes; Ricardo Correa
Journal:  Cureus       Date:  2015-11-17

3.  Multicentric Castleman's disease: "A rare entity that mimics malignancy".

Authors:  Vishak K Acharya; Santosh Rai; Sachin Shirgavi; Radha R Pai; R Anand
Journal:  Lung India       Date:  2016 Nov-Dec
  3 in total

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