Literature DB >> 19434689

Gorham-Stout Syndrome with chylothorax: successful remission by interferon alpha-2b.

Mehmet Kose1, Sevgi Pekcan, Deniz Dogru, Canan Akyuz, Ugur Ozcelik, Yasemin Ozsurekci, Bora Gulhan, Metin Demircin, Nural Kiper.   

Abstract

Gorham-Stout syndrome is a rare disease and most often recognized in children and young adults. Chylothorax is a serious complication of Gorham-Stout syndrome. The treatment of either Gorham-Stout syndrome or chylothorax is still a dilemma. We described a 9-year-old girl with Gorham-Stout syndrome and chylothorax who was admitted to our hospital because of dyspnea, orthopnea, and bone pain, and treated with interferon alpha-2b.

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Year:  2009        PMID: 19434689     DOI: 10.1002/ppul.20849

Source DB:  PubMed          Journal:  Pediatr Pulmonol        ISSN: 1099-0496


  19 in total

1.  Intraosseous CSF fistula in a patient with Gorham disease resulting in intracranial hypotension.

Authors:  F Adler; N Gupta; C P Hess; C F Dowd; W P Dillon
Journal:  AJNR Am J Neuroradiol       Date:  2011-06-09       Impact factor: 3.825

2.  Thoracic osteotomy for Gorham-Stout disease of the spine: a case report and literature review.

Authors:  C Maillot; T Cloche; J-C Le Huec
Journal:  Eur Spine J       Date:  2014-10-21       Impact factor: 3.134

3.  Gorham-Stout syndrome of the pelvic girdle treated by radiation therapy: a case report.

Authors:  Reinhard Heyd; Daniela Rabeneck; Oliver Dörnenburg; Nikolaos Tselis; Nikolaos Zamboglou
Journal:  Strahlenther Onkol       Date:  2011-01-18       Impact factor: 3.621

Review 4.  Novel molecular pathways in Gorham disease: implications for treatment.

Authors:  Jeroen Hagendoorn; Torunn I Yock; Inne H M Borel Rinkes; Timothy P Padera; David H Ebb
Journal:  Pediatr Blood Cancer       Date:  2013-11-08       Impact factor: 3.167

5.  Retrospective French nationwide survey of childhood aggressive vascular anomalies of bone, 1988-2009.

Authors:  Sébastien Héritier; Martine Le Merrer; Francis Jaubert; Michèle Bigorre; Marion Gillibert-Yvert; Benoit de Courtivron; Makram Ziade; Yves Bertrand; Christian Carrie; Pascal Chastagner; Cécile Bost-Bru; Jean-Claude Léonard; Marie Ouache; Liliane Boccon-Gibod; Pierre Mary; Jacques de Blic; Isabelle Pin; Daniel Wendling; Yann Revillon; Véronique Houdoin; Véronique Forin; Hubert Ducou Lepointe; Jane Languepin; Jeanne Wagnon; Ralph Epaud; Brigitte Fauroux; Jean Donadieu
Journal:  Orphanet J Rare Dis       Date:  2010-02-03       Impact factor: 4.123

6.  Japanese clinical practice guidelines for vascular anomalies 2017.

Authors:  Hidefumi Mimura; Sadanori Akita; Akihiro Fujino; Masatoshi Jinnin; Mine Ozaki; Keigo Osuga; Hiroki Nakaoka; Eiichi Morii; Akira Kuramochi; Yoko Aoki; Yasunori Arai; Noriko Aramaki; Masanori Inoue; Yuki Iwashina; Tadashi Iwanaka; Shigeru Ueno; Akihiro Umezawa; Michio Ozeki; Junko Ochi; Yoshiaki Kinoshita; Masakazu Kurita; Shien Seike; Nobuyuki Takakura; Masataka Takahashi; Takao Tachibana; Kumiko Chuman; Shuji Nagata; Mitsunaga Narushima; Yasunari Niimi; Shunsuke Nosaka; Taiki Nozaki; Kazuki Hashimoto; Ayato Hayashi; Satoshi Hirakawa; Atsuko Fujikawa; Yumiko Hori; Kentaro Matsuoka; Hideki Mori; Yuki Yamamoto; Shunsuke Yuzuriha; Naoaki Rikihisa; Shoji Watanabe; Shinichi Watanabe; Tatsuo Kuroda; Shunsuke Sugawara; Kosuke Ishikawa; Satoru Sasaki
Journal:  Jpn J Radiol       Date:  2020-04       Impact factor: 2.374

7.  Japanese Clinical Practice Guidelines for Vascular Anomalies 2017.

Authors:  Hidefumi Mimura; Sadanori Akita; Akihiro Fujino; Masatoshi Jinnin; Mine Ozaki; Keigo Osuga; Hiroki Nakaoka; Eiichi Morii; Akira Kuramochi; Yoko Aoki; Yasunori Arai; Noriko Aramaki; Masanori Inoue; Yuki Iwashina; Tadashi Iwanaka; Shigeru Ueno; Akihiro Umezawa; Michio Ozeki; Junko Ochi; Yoshiaki Kinoshita; Masakazu Kurita; Shien Seike; Nobuyuki Takakura; Masataka Takahashi; Takao Tachibana; Kumiko Chuman; Shuji Nagata; Mitsunaga Narushima; Yasunari Niimi; Shunsuke Nosaka; Taiki Nozaki; Kazuki Hashimoto; Ayato Hayashi; Satoshi Hirakawa; Atsuko Fujikawa; Yumiko Hori; Kentaro Matsuoka; Hideki Mori; Yuki Yamamoto; Shunsuke Yuzuriha; Naoaki Rikihisa; Shoji Watanabe; Shinichi Watanabe; Tatsuo Kuroda; Shunsuke Sugawara; Kosuke Ishikawa; Satoru Sasaki
Journal:  J Dermatol       Date:  2020-03-22       Impact factor: 4.005

8.  Gorham-Stout disease: radiological, histological, and clinical features of 12 cases and review of literature.

Authors:  Yi Liu; Ding-Rong Zhong; Pei-Ran Zhou; Fang Lv; Dou-Dou Ma; Wei-Bo Xia; Yan Jiang; Ou Wang; Xiao-Ping Xing; Mei Li
Journal:  Clin Rheumatol       Date:  2014-09-18       Impact factor: 2.980

9.  Spinal Gorham-Stout syndrome: radiological changes and spinal deformities.

Authors:  Chang-Zhi Du; Song Li; Liang Xu; Qing-Shuang Zhou; Ze-Zhang Zhu; Xu Sun; Yong Qiu
Journal:  Quant Imaging Med Surg       Date:  2019-04

10.  An unusual cause of recurrent chylothorax: gorham syndrome.

Authors:  Rahşan Ozcan; Ahmet Alptekin; Senol Emre; Sebuh Kuruoğlu; Muharrem Inan; Gonca Topuzlu Tekant
Journal:  APSP J Case Rep       Date:  2014-05-21
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