Literature DB >> 19253345

Longitudinal changes of mtDNA A3243G mutation load and level of functioning in MELAS.

Mahsa Mehrazin1, Sara Shanske, Petra Kaufmann, Ying Wei, Jorida Coku, Kristin Engelstad, Ali Naini, Darryl C De Vivo, Salvatore DiMauro.   

Abstract

Mitochondrial encephalopathy, lactic acidosis, and stroke-like episodes (MELAS), one of the most common mitochondrial multisystemic diseases, is most commonly associated with an A-to-G transition at nucleotide position 3243 (A3243G) in mitochondrial DNA. We studied 34 individuals harboring the A3243G mutation for up to 7 years; 17 had the full MELAS phenotype and 17 who were classified as "carrier relatives" because they were either asymptomatic or had some symptoms suggestive of mitochondrial disease but no seizures or strokes. Using the sensitive real-time polymerase chain reaction to quantify the A3243G mutation, we confirmed that the percent mutation decreases progressively in DNA isolated from blood: the average percent decrease was 0.5% per year for fully symptomatic patients and 0.2% per year for oligosymptomatic carrier relatives. We also correlated mutant loads with functional status estimated by the Karnofksky score: even though the mutation load decreases, the level of functioning worsens in fully symptomatic patients, whereas the level of functioning of carrier relatives remains largely unchanged. This study suggests that A3243G mutant load in DNA isolated from blood is neither useful for prognosis nor for functional assessment.

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Year:  2009        PMID: 19253345      PMCID: PMC2663596          DOI: 10.1002/ajmg.a.32703

Source DB:  PubMed          Journal:  Am J Med Genet A        ISSN: 1552-4825            Impact factor:   2.802


  31 in total

1.  Detection of MELAS A3243G point mutation in muscle, blood and hair follicles.

Authors:  C M Sue; A Quigley; S Katsabanis; R Kapsa; D S Crimmins; E Byrne; J G Morris
Journal:  J Neurol Sci       Date:  1998-11-26       Impact factor: 3.181

2.  Rapid and sensitive real-time polymerase chain reaction method for detection and quantification of 3243A>G mitochondrial point mutation.

Authors:  Rinki Singh; Sian Ellard; Andrew Hattersley; Lorna W Harries
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4.  Molecular pathology of MELAS and MERRF. The relationship between mutation load and clinical phenotypes.

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5.  Epidemiology of A3243G, the mutation for mitochondrial encephalomyopathy, lactic acidosis, and strokelike episodes: prevalence of the mutation in an adult population.

Authors:  K Majamaa; J S Moilanen; S Uimonen; A M Remes; P I Salmela; M Kärppä; K A Majamaa-Voltti; H Rusanen; M Sorri; K J Peuhkurinen; I E Hassinen
Journal:  Am J Hum Genet       Date:  1998-08       Impact factor: 11.025

6.  Variable distribution of mutant mitochondrial DNAs (tRNA(Leu[3243])) in tissues of symptomatic relatives with MELAS: the role of mitotic segregation.

Authors:  C Macmillan; B Lach; E A Shoubridge
Journal:  Neurology       Date:  1993-08       Impact factor: 9.910

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10.  Correlation between clinical and molecular features in two MELAS families.

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6.  Increased Prevalence of Hypertension in Young Adults with High Heteroplasmy Levels of the MELAS m.3243A>G Mutation.

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7.  Purifying Selection against Pathogenic Mitochondrial DNA in Human T Cells.

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8.  Neuroimaging characteristics in mitochondrial encephalopathies associated with the m.3243A>G MTTL1 mutation.

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