Literature DB >> 19167105

Dilated cardiomyopathy with profound segmental wall motion abnormalities and ventricular arrhythmia caused by the R541C mutation in the LMNA gene.

Michał Saj, Agnieszka Jankowska, Michał Lewandowski, Hanna Szwed, Małgorzata Szperl, Rafał Płoski, Zofia T Bilińska.   

Abstract

In laminopathies cardiac involvement is common with dilated cardiomyopathy associated with atrio-ventricular block and malignant ventricular arrhythmia found in vast majority of patients. However, the specific disease course can be very different even among members of the same family which makes genotype-phenotype correlations difficult. Here we describe a 19-year-old patient with the LMNA R541C mutation and compare the course of his disease with two previously reported cases of the same molecular defect. We found that our patient shared important features with the previously described other subjects: significant LV segmental contractility defects (dyskinesis of the inferior wall and akinesis of LV apex), the presence of LBBB without atrio-ventricular block on 12-lead standard ECG and ICD requirement. The important differences between our subject and previously reported cases were early presentation (first symptoms at the age of 11 years) and early, progressive LV dilatation. We conclude that the LMNA R541C mutation should be considered not only in patients with malignant ventricular arrhythmia and LV local wall motion abnormalities, but also in classic dilated cardiomyopathy with profound segmental LV contractility defects.
Copyright © 2008 Elsevier Ireland Ltd. All rights reserved.

Entities:  

Mesh:

Substances:

Year:  2009        PMID: 19167105     DOI: 10.1016/j.ijcard.2008.12.083

Source DB:  PubMed          Journal:  Int J Cardiol        ISSN: 0167-5273            Impact factor:   4.164


  4 in total

1.  Case series: LMNA-related dilated cardiomyopathy presents with reginal wall akinesis and transmural late gadolinium enhancement.

Authors:  Shuai Wang; Daoquan Peng
Journal:  ESC Heart Fail       Date:  2020-07-14

Review 2.  Genotype-phenotype correlation of LMNA variants involving the Arg541 residue: a case report with multimodality imaging and literature review.

Authors:  Andrea Di Marco; María Ruiz-Cueto; Joel Salazar-Mendiguchía; Eduard Claver; Gerard Roura; Paolo Domenico Dallaglio; Ignasi Anguera
Journal:  ESC Heart Fail       Date:  2020-07-15

3.  Phosphorylation of Lamin A/C at serine 22 modulates Nav 1.5 function.

Authors:  Michael A Olaopa; Tomohiko Ai; Bo Chao; Xiangshu Xiao; Matteo Vatta; Beth A Habecker
Journal:  Physiol Rep       Date:  2021-11

4.  LMNA mutations in Polish patients with dilated cardiomyopathy: prevalence, clinical characteristics, and in vitro studies.

Authors:  Michal Saj; Zofia T Bilinska; Agnieszka Tarnowska; Agnieszka Sioma; Pierrette Bolongo; Malgorzata Sobieszczanska-Malek; Ewa Michalak; Dorota Golen; Lukasz Mazurkiewicz; Lukasz Malek; Ewa Walczak; Anna Fidzianska; Jacek Grzybowski; Andrzej Przybylski; Tomasz Zielinski; Jerzy Korewicki; Frederique Tesson; Rafal Ploski
Journal:  BMC Med Genet       Date:  2013-05-23       Impact factor: 2.103

  4 in total

北京卡尤迪生物科技股份有限公司 © 2022-2023.