Literature DB >> 19094978

Coenzyme Q10 deficiency associated with a mitochondrial DNA depletion syndrome: a case report.

Raquel Montero1, Jose A Sánchez-Alcázar, Paz Briones, Aleix Navarro-Sastre, Ester Gallardo, Belén Bornstein, Dolores Herrero-Martín, Henry Rivera, Miguel A Martin, Ramón Marti, Angels García-Cazorla, Julio Montoya, Plácido Navas, Rafael Artuch.   

Abstract

OBJECTIVES: To report on a case with a mitochondrial DNA (mtDNA) depletion syndrome. DESIGN AND METHODS: Laboratory studies were done in muscle biopsy and fibroblasts to evaluate coenzyme Q(10) (CoQ(10)) status and quantify mitochondrial DNA.
RESULTS: Decreased CoQ(10) values and a 78% of mtDNA depletion were detected in muscle. Mutational studies failed to reveal any pathogenic mutation in nuclear genes related with mtDNA maintenance.
CONCLUSIONS: mtDNA depletion syndrome was associated with CoQ(10) deficiency in our patient.

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Year:  2008        PMID: 19094978     DOI: 10.1016/j.clinbiochem.2008.10.027

Source DB:  PubMed          Journal:  Clin Biochem        ISSN: 0009-9120            Impact factor:   3.281


  11 in total

1.  Pathomechanisms in coenzyme q10-deficient human fibroblasts.

Authors:  Luis C López; Marta Luna-Sánchez; Laura García-Corzo; Catarina M Quinzii; Michio Hirano
Journal:  Mol Syndromol       Date:  2014-07

2.  Biochemical diagnosis of coenzyme q10 deficiency.

Authors:  Delia Yubero; Raquel Montero; Rafael Artuch; John M Land; Simon J R Heales; Iain P Hargreaves
Journal:  Mol Syndromol       Date:  2014-07

Review 3.  Coenzyme Q10 deficiencies in neuromuscular diseases.

Authors:  Rafael Artuch; Leonardo Salviati; Sandra Jackson; Michio Hirano; Plácido Navas
Journal:  Adv Exp Med Biol       Date:  2009       Impact factor: 2.622

Review 4.  Update on clinical aspects and treatment of selected vitamin-responsive disorders II (riboflavin and CoQ 10).

Authors:  Rita Horvath
Journal:  J Inherit Metab Dis       Date:  2012-01-10       Impact factor: 4.982

5.  Acute liver failure with subsequent cirrhosis as the primary manifestation of TRMU mutations.

Authors:  Ulrike Schara; Jürgen-Christoph von Kleist-Retzow; Elke Lainka; Patrick Gerner; Angela Pyle; Paul M Smith; Hanns Lochmüller; Birgit Czermin; Angela Abicht; Elke Holinski-Feder; Rita Horvath
Journal:  J Inherit Metab Dis       Date:  2010-12-10       Impact factor: 4.982

Review 6.  Primary and secondary CoQ(10) deficiencies in humans.

Authors:  Catarina M Quinzii; Michio Hirano
Journal:  Biofactors       Date:  2011-10-11       Impact factor: 6.113

7.  Characterization of CoQ₁₀ biosynthesis in fibroblasts of patients with primary and secondary CoQ₁₀ deficiency.

Authors:  Nuria Buján; Angela Arias; Raquel Montero; Judit García-Villoria; Willy Lissens; Sara Seneca; Carmen Espinós; Plácido Navas; Linda De Meirleir; Rafael Artuch; Paz Briones; Antonia Ribes
Journal:  J Inherit Metab Dis       Date:  2013-06-18       Impact factor: 4.982

Review 8.  Biochemical Assessment of Coenzyme Q10 Deficiency.

Authors:  Juan Carlos Rodríguez-Aguilera; Ana Belén Cortés; Daniel J M Fernández-Ayala; Plácido Navas
Journal:  J Clin Med       Date:  2017-03-05       Impact factor: 4.241

Review 9.  Metabolic Targets of Coenzyme Q10 in Mitochondria.

Authors:  Agustín Hidalgo-Gutiérrez; Pilar González-García; María Elena Díaz-Casado; Eliana Barriocanal-Casado; Sergio López-Herrador; Catarina M Quinzii; Luis C López
Journal:  Antioxidants (Basel)       Date:  2021-03-26

10.  Survival transcriptome in the coenzyme Q10 deficiency syndrome is acquired by epigenetic modifications: a modelling study for human coenzyme Q10 deficiencies.

Authors:  Daniel J M Fernández-Ayala; Ignacio Guerra; Sandra Jiménez-Gancedo; Maria V Cascajo; Angela Gavilán; Salvatore Dimauro; Michio Hirano; Paz Briones; Rafael Artuch; Rafael De Cabo; Leonardo Salviati; Plácido Navas
Journal:  BMJ Open       Date:  2013-03-25       Impact factor: 2.692

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