Literature DB >> 19087156

R632W mutation in PLA2G6 segregates with dystonia-parkinsonism in a consanguineous Iranian family.

F Sina1, S Shojaee, E Elahi, C Paisán-Ruiz.   

Abstract

BACKGROUND: PLA2G6 mutations are known to be responsible for infantile neuroaxonal dystrophy (INAD) and neurodegeneration with brain iron accumulation (NBIA). In addition, novel mutations in PLA2G6 have recently been associated with dystonia-parkinsonism in two unrelated consanguineous families.
METHODS: Direct sequencing analysis of the PLA2G6 gene.
RESULTS: Here, we report the segregation of R632W with disease in an Iranian consanguineous dystonia-parkinsonism pedigree. The identical mutation was previously observed in a patient affected with NBIA.
CONCLUSION: We conclude that different and even identical PLA2G6 mutations may cause neurodegenerative diseases with heterogeneous clinical manifestations, including INAD, NBIA and dystonia-parkinsonism.

Entities:  

Mesh:

Substances:

Year:  2009        PMID: 19087156     DOI: 10.1111/j.1468-1331.2008.02356.x

Source DB:  PubMed          Journal:  Eur J Neurol        ISSN: 1351-5101            Impact factor:   6.089


  33 in total

1.  Mutation screening of PLA2G6 in Japanese patients with early onset dystonia-parkinsonism.

Authors:  Chikara Yamashita; Manabu Funayama; Yuanzhe Li; Hiroyo Yoshino; Hitoshi Yamada; Yusuke Seino; Hiroyuki Tomiyama; Nobutaka Hattori
Journal:  J Neural Transm (Vienna)       Date:  2016-12-09       Impact factor: 3.575

Review 2.  Defective Lysosomal Lipid Catabolism as a Common Pathogenic Mechanism for Dementia.

Authors:  Jun Yup Lee; Oana C Marian; Anthony S Don
Journal:  Neuromolecular Med       Date:  2021-02-07       Impact factor: 3.843

Review 3.  Calcium-independent phospholipases A2 and their roles in biological processes and diseases.

Authors:  Sasanka Ramanadham; Tomader Ali; Jason W Ashley; Robert N Bone; William D Hancock; Xiaoyong Lei
Journal:  J Lipid Res       Date:  2015-05-28       Impact factor: 5.922

Review 4.  Current perspective of mitochondrial biology in Parkinson's disease.

Authors:  Navneet Ammal Kaidery; Bobby Thomas
Journal:  Neurochem Int       Date:  2018-03-14       Impact factor: 3.921

5.  Catalytic function of PLA2G6 is impaired by mutations associated with infantile neuroaxonal dystrophy but not dystonia-parkinsonism.

Authors:  Laura A Engel; Zheng Jing; Daniel E O'Brien; Mengyang Sun; Paul T Kotzbauer
Journal:  PLoS One       Date:  2010-09-23       Impact factor: 3.240

Review 6.  Genetics in Parkinson disease: Mendelian versus non-Mendelian inheritance.

Authors:  Dena G Hernandez; Xylena Reed; Andrew B Singleton
Journal:  J Neurochem       Date:  2016-04-18       Impact factor: 5.372

7.  Pla2g6 Deficiency in Zebrafish Leads to Dopaminergic Cell Death, Axonal Degeneration, Increased β-Synuclein Expression, and Defects in Brain Functions and Pathways.

Authors:  Elena Sánchez; Luis J Azcona; Coro Paisán-Ruiz
Journal:  Mol Neurobiol       Date:  2018-01-17       Impact factor: 5.590

8.  Early-onset L-dopa-responsive parkinsonism with pyramidal signs due to ATP13A2, PLA2G6, FBXO7 and spatacsin mutations.

Authors:  Coro Paisán-Ruiz; Rocio Guevara; Monica Federoff; Hasmet Hanagasi; Fardaz Sina; Elahe Elahi; Susanne A Schneider; Petra Schwingenschuh; Nin Bajaj; Murat Emre; Andrew B Singleton; John Hardy; Kailash P Bhatia; Sebastian Brandner; Andrew J Lees; Henry Houlden
Journal:  Mov Disord       Date:  2010-09-15       Impact factor: 10.338

9.  Pluripotent Stem Cell Derived Neurons as In Vitro Models for Studying Autosomal Recessive Parkinson's Disease (ARPD): PLA2G6 and Other Gene Loci.

Authors:  Renjitha Gopurappilly
Journal:  Adv Exp Med Biol       Date:  2021       Impact factor: 2.622

Review 10.  A Practical Approach to Early-Onset Parkinsonism.

Authors:  Giulietta M Riboldi; Emanuele Frattini; Edoardo Monfrini; Steven J Frucht; Alessio Di Fonzo
Journal:  J Parkinsons Dis       Date:  2022       Impact factor: 5.568

View more

北京卡尤迪生物科技股份有限公司 © 2022-2023.