Literature DB >> 19084402

A new phenotype of dysferlinopathy with congenital onset.

C Paradas1, L González-Quereda, N De Luna, E Gallardo, I García-Consuegra, H Gómez, A Cabello, I Illa, P Gallano.   

Abstract

We report two patients with a new phenotype of dysferlinopathy presenting as congenital muscular disease. Both patients showed weakness in proximal lower limbs and neck flexor muscles at birth. The presence of normal CK levels during the first years should be noted. Initial MRI showed no abnormalities but short-time-inversion-recovery (STIR) sequences revealed a striking myoedema in gastrocnemius and hamstring muscles at the age of 5. Muscle biopsy showed mild dystrophic features and the absence of dysferlin. Dysferlin gene (DYSF) analysis revealed a p.Ala927LeufsX21 mutation in a homozygous state in both siblings. This new phenotype widens the clinical spectrum of dysferlin myopathies.

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Year:  2008        PMID: 19084402     DOI: 10.1016/j.nmd.2008.09.015

Source DB:  PubMed          Journal:  Neuromuscul Disord        ISSN: 0960-8966            Impact factor:   4.296


  20 in total

1.  Clinical Reasoning: A 30-year-old man with progressive weakness and atrophy.

Authors:  Colin Quinn; Steven A Moore; Tanya M Bardakjian; Chafic Karam
Journal:  Neurology       Date:  2016-11-08       Impact factor: 9.910

Review 2.  Engineered skeletal muscles for disease modeling and drug discovery.

Authors:  Jason Wang; Alastair Khodabukus; Lingjun Rao; Keith Vandusen; Nadia Abutaleb; Nenad Bursac
Journal:  Biomaterials       Date:  2019-08-08       Impact factor: 12.479

3.  A new distal myopathy with mutation in anoctamin 5.

Authors:  Ibrahim Mahjneh; Jyoti Jaiswal; Antti Lamminen; Mirja Somer; Gareth Marlow; Sari Kiuru-Enari; Rumaisa Bashir
Journal:  Neuromuscul Disord       Date:  2010-08-07       Impact factor: 4.296

4.  Dexamethasone induces dysferlin in myoblasts and enhances their myogenic differentiation.

Authors:  Joseph J Belanto; Silvia V Diaz-Perez; Clara E Magyar; Michele M Maxwell; Yasemin Yilmaz; Kasey Topp; Guney Boso; Catriona H Jamieson; Nicholas A Cacalano; Christina A M Jamieson
Journal:  Neuromuscul Disord       Date:  2010-01-18       Impact factor: 4.296

5.  Muscle MRI in muscular dystrophies.

Authors:  Jordi Díaz-Manera; Jaume Llauger; Eduard Gallardo; Isabel Illa
Journal:  Acta Myol       Date:  2015-12

6.  Bone marrow transplantation in dysferlin-deficient mice results in a mild functional improvement.

Authors:  Bàrbara Flix; Xavier Suárez-Calvet; Jordi Díaz-Manera; Eva Santos-Nogueira; Renzo Mancuso; Jordi Barquinero; Miquel Navas; Xavier Navarro; Isabel Illa; Eduard Gallardo
Journal:  Stem Cells Dev       Date:  2013-07-26       Impact factor: 3.272

7.  1α,25(OH)(2)-Vitamin D3 increases dysferlin expression in vitro and in a human clinical trial.

Authors:  Noemi De Luna; Jordi Díaz-Manera; Carmen Paradas; Cristina Iturriaga; Ricardo Rojas-García; Josefa Araque; Mireia Genebriera; Ignasi Gich; Isabel Illa; Eduard Gallardo
Journal:  Mol Ther       Date:  2012-08-21       Impact factor: 11.454

8.  POGLUT1 biallelic mutations cause myopathy with reduced satellite cells, α-dystroglycan hypoglycosylation and a distinctive radiological pattern.

Authors:  E Servián-Morilla; M Cabrera-Serrano; K Johnson; A Pandey; A Ito; E Rivas; T Chamova; N Muelas; T Mongini; S Nafissi; K G Claeys; R P Grewal; M Takeuchi; H Hao; C Bönnemann; O Lopes Abath Neto; L Medne; J Brandsema; A Töpf; A Taneva; J J Vilchez; I Tournev; R S Haltiwanger; H Takeuchi; H Jafar-Nejad; V Straub; Carmen Paradas
Journal:  Acta Neuropathol       Date:  2020-01-03       Impact factor: 17.088

9.  A founder mutation in Anoctamin 5 is a major cause of limb-girdle muscular dystrophy.

Authors:  Debbie Hicks; Anna Sarkozy; Nuria Muelas; Katrin Köehler; Angela Huebner; Gavin Hudson; Patrick F Chinnery; Rita Barresi; Michelle Eagle; Tuomo Polvikoski; Geraldine Bailey; James Miller; Aleksander Radunovic; Paul J Hughes; Richard Roberts; Sabine Krause; Maggie C Walter; Steven H Laval; Volker Straub; Hanns Lochmüller; Kate Bushby
Journal:  Brain       Date:  2011-01       Impact factor: 13.501

10.  New aspects on patients affected by dysferlin deficient muscular dystrophy.

Authors:  Lars Klinge; Ahmed Aboumousa; Michelle Eagle; Judith Hudson; Anna Sarkozy; Gianluca Vita; Richard Charlton; Mark Roberts; Volker Straub; Rita Barresi; Hanns Lochmüller; Kate Bushby
Journal:  J Neurol Neurosurg Psychiatry       Date:  2009-06-14       Impact factor: 10.154

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