Literature DB >> 19068257

Gomez-Lopez-Hernandez syndrome: two new cases and review of the literature.

Alberto Fernández-Jaén1, Daniel Martín Fernández-Mayoralas, Beatriz Calleja-Pérez, Nuria Muñoz-Jareño, Noelia Moreno.   

Abstract

Gomez-Lopez-Hernandez syndrome, or cerebellotrigeminal-dermal dysplasia, is a rare neurocutaneous syndrome of trigeminal anesthesia, scalp alopecia and cerebellar anomalies. Other features include craniosynostosis, short stature, hypertelorism, down-slanting palpebral fissures, corneal opacities, mediofacial hypoplasia, and turri-brachycephaly. There have been 19 cases documented to date and we report on two additional male patients, 1 and 6 years of age, with typical features, mild mental retardation and dyspraxia. In both cases, MRI findings included rhombencephalosynapsis, a constant neuroimaging feature in this syndrome, comprising fusion of the cerebellar hemispheres with agenesis of the cerebellar vermis. Based on literature and our experience, we propose the presence of trigeminal anesthesia and/or partial alopecia of the scalp to complete the diagnosis of the syndrome.

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Year:  2009        PMID: 19068257     DOI: 10.1016/j.pediatrneurol.2008.10.001

Source DB:  PubMed          Journal:  Pediatr Neurol        ISSN: 0887-8994            Impact factor:   3.372


  4 in total

1.  Gómez-López-Hernández syndrome: reappraisal of the diagnostic criteria.

Authors:  Biayna Sukhudyan; Varsine Jaladyan; Gayane Melikyan; Jan Ulrich Schlump; Eugen Boltshauser; Andrea Poretti
Journal:  Eur J Pediatr       Date:  2010-07-23       Impact factor: 3.183

2.  Rhombencephalosynapsis: a hindbrain malformation associated with incomplete separation of midbrain and forebrain, hydrocephalus and a broad spectrum of severity.

Authors:  Gisele E Ishak; Jennifer C Dempsey; Dennis W W Shaw; Hannah Tully; Margaret P Adam; Pedro A Sanchez-Lara; Ian Glass; Tessa C Rue; Kathleen J Millen; William B Dobyns; Dan Doherty
Journal:  Brain       Date:  2012-03-26       Impact factor: 13.501

3.  Co-occurrence of Gomez-Lopez-Hernandez syndrome and Autism Spectrum Disorder: Case report with review of literature.

Authors:  Bakur Kotetishvili; Malkhaz Makashvili; Michael Okujava; Alexandre Kotetishvili; Tamar Kopadze
Journal:  Intractable Rare Dis Res       Date:  2018-08

4.  Purkinje cell compartmentation in the cerebellum of the lysosomal Acid phosphatase 2 mutant mouse (nax - naked-ataxia mutant mouse).

Authors:  Karen Bailey; Maryam Rahimi Balaei; Ashraf Mannan; Marc R Del Bigio; Hassan Marzban
Journal:  PLoS One       Date:  2014-04-10       Impact factor: 3.240

  4 in total

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