Literature DB >> 18855117

Detection of treatable neonatal liver disease by expanded newborn screening.

R J Mackay1, D Bratkovic, R Couper, G P Davidson, R Fahy, J M Fletcher, E Ranieri.   

Abstract

Two neonates were identified at age 48 h by expanded newborn screening, with abnormal methionine and tyrosine concentrations, which were confirmed on repeat samples. Evidence of previously unsuspected liver disease was found at recall, and there was radiological and biochemical evidence of severe liver disease with hepatic synthetic failure. After inborn errors of metabolism (IEMs) were excluded, both were considered to have neonatal haemochromatosis, on the basis of raised ferritin, iron saturation, and very high α-fetoprotein and confirmed by a mildly hyperferritinaemic sibling in the first case, and raised ferritin and iron saturation in the second. However, it was not feasible to obtain tissue confirmation as the requirement for early therapy precluded biopsy. The babies were treated with antioxidants and iron-chelating agents, and the coagulopathy and hypoalbuminaemia were corrected. Both made a complete recovery and remain well after follow-up. Newborn screening programmes could consider advising clinicians, when tyrosine and methionine values are elevated, that once IEMs are excluded liver disease from other causes must be sought. Neonatal haemochromatosis is an example of one such disease that is potentially treatable.

Entities:  

Mesh:

Substances:

Year:  2008        PMID: 18855117     DOI: 10.1007/s10545-008-0842-9

Source DB:  PubMed          Journal:  J Inherit Metab Dis        ISSN: 0141-8955            Impact factor:   4.982


  4 in total

Review 1.  Neonatal hemochromatosis: the importance of early recognition of liver failure.

Authors:  P Vohra; C Haller; S Emre; M Magid; I Holzman; M Q Ye; E Iofel; B L Shneider
Journal:  J Pediatr       Date:  2000-04       Impact factor: 4.406

Review 2.  Fetal and infantile hemochromatosis.

Authors:  Peter F Whitington
Journal:  Hepatology       Date:  2006-04       Impact factor: 17.425

3.  High-dose immunoglobulin during pregnancy for recurrent neonatal haemochromatosis.

Authors:  Peter F Whitington; Judith U Hibbard
Journal:  Lancet       Date:  2004 Nov 6-12       Impact factor: 79.321

4.  Progress in treatment and outcome for children with neonatal haemochromatosis.

Authors:  D M Flynn; N Mohan; P McKiernan; S Beath; J Buckels; D Mayer; D A Kelly
Journal:  Arch Dis Child Fetal Neonatal Ed       Date:  2003-03       Impact factor: 5.747

  4 in total

北京卡尤迪生物科技股份有限公司 © 2022-2023.