Literature DB >> 18854696

Ocular manifestation of storage diseases.

Jyotirmay Biswas1, Krishnendu Nandi, Sudharshan Sridharan, Prabhat Ranjan.   

Abstract

PURPOSE OF REVIEW: This is an attempt to provide a brief overview of ocular manifestation of storage diseases (lysosomal storage diseases). RECENT
FINDINGS: Lysosomal storage disorder is a heterogeneous group of rare disorders characterized by abnormal accumulation of incompletely degraded substances in various tissues and organs. Patients with these kinds of inherited disorder often present with ocular manifestation along with various systemic features. Systemic manifestations including neurological impairment, skeletal deformities, intellectual and cardiac abnormalities, and gastrointestinal problems are quite common. Ocular complication may cause severe reduction in vision and can affect any part of the eye. Corneal opacification of varying severity is frequently seen. Patients can also present with cataract, vitreous degeneration, retinopathy, optic nerve swelling and atrophy, ocular hypertension, and glaucoma.
SUMMARY: The majority of these patients have poor vision due to various ocular complications that are often very difficult to monitor and treat.

Entities:  

Mesh:

Year:  2008        PMID: 18854696     DOI: 10.1097/ICU.0b013e32831215c3

Source DB:  PubMed          Journal:  Curr Opin Ophthalmol        ISSN: 1040-8738            Impact factor:   3.761


  7 in total

Review 1.  The physiological and pathophysiological roles of the autophagy lysosomal system in the conventional aqueous humor outflow pathway: More than cellular clean up.

Authors:  Myoung Sup Shim; Paloma B Liton
Journal:  Prog Retin Eye Res       Date:  2022-04-01       Impact factor: 19.704

2.  Autophagic dysregulation in glaucomatous trabecular meshwork cells.

Authors:  Kristine Porter; Joshua Hirt; W Daniel Stamer; Paloma B Liton
Journal:  Biochim Biophys Acta       Date:  2014-12-04

Review 3.  Vision loss in juvenile neuronal ceroid lipofuscinosis (CLN3 disease).

Authors:  Madhu M Ouseph; Mark E Kleinman; Qing Jun Wang
Journal:  Ann N Y Acad Sci       Date:  2016-01-08       Impact factor: 5.691

Review 4.  The autophagic lysosomal system in outflow pathway physiology and pathophysiology.

Authors:  Paloma B Liton
Journal:  Exp Eye Res       Date:  2015-07-27       Impact factor: 3.467

5.  Corneal alterations during combined therapy with cyclodextrin/allopregnanolone and miglustat in a knock-out mouse model of NPC1 disease.

Authors:  Marine Hovakimyan; Jana Petersen; Fabian Maass; Maria Reichard; Martin Witt; Jan Lukas; Oliver Stachs; Rudolf Guthoff; Arndt Rolfs; Andreas Wree
Journal:  PLoS One       Date:  2011-12-06       Impact factor: 3.240

6.  Spectrum of ocular manifestations in CLN2-associated batten (Jansky-Bielschowsky) disease correlate with advancing age and deteriorating neurological function.

Authors:  Anton Orlin; Dolan Sondhi; Matthew T Witmer; Matthew M Wessel; Jason G Mezey; Stephen M Kaminsky; Neil R Hackett; Kaleb Yohay; Barry Kosofsky; Mark M Souweidane; Michael G Kaplitt; Donald J D'Amico; Ronald G Crystal; Szilárd Kiss
Journal:  PLoS One       Date:  2013-08-28       Impact factor: 3.240

7.  Lysosomal basification and decreased autophagic flux in oxidatively stressed trabecular meshwork cells: implications for glaucoma pathogenesis.

Authors:  Kristine Porter; Jeyabalan Nallathambi; Yizhi Lin; Paloma B Liton
Journal:  Autophagy       Date:  2013-01-29       Impact factor: 16.016

  7 in total

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