| Literature DB >> 18835491 |
Claudia C Ferreiro-Barros1, Célia H Tengan, Mário H Barros, Lluis Palenzuela, Chisaka Kanki, Catarina Quinzii, Johanna Lou, Nader El Gharaby, Aly Shokr, Darryl C De Vivo, Salvatore DiMauro, Michio Hirano.
Abstract
Mitochondrial diseases are clinically and genetically heterogeneous disorders due to primary mutations in mitochondrial DNA (mtDNA) or nuclear DNA (nDNA). We studied a male infant with severe congenital encephalopathy, peripheral neuropathy, and myopathy. The patient's lactic acidosis and biochemical defects of respiratory chain complexes I, III, and IV in muscle indicated that he had a mitochondrial disorder while parental consanguinity suggested autosomal recessive inheritance. Cultured fibroblasts from the patient showed a generalized defect of mitochondrial protein synthesis. Fusion of cells from the patient with 143B206 rho(0) cells devoid of mtDNA restored cytochrome c oxidase activity confirming the nDNA origin of the disease. Our studies indicate that the patient has a novel autosomal recessive defect of mitochondrial protein synthesis.Entities:
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Year: 2008 PMID: 18835491 PMCID: PMC2605845 DOI: 10.1016/j.jns.2008.08.028
Source DB: PubMed Journal: J Neurol Sci ISSN: 0022-510X Impact factor: 3.181