Literature DB >> 18718593

Update of Japanese common LDLR gene mutations and their phenotypes: Mild type mutation L547V might predominate in the Japanese population.

Yasuko Miyake1, Taku Yamamura, Naohiko Sakai, Toshiyuki Miyata, Yoshihiro Kokubo, Akira Yamamoto.   

Abstract

We investigated the LDLR gene mutations in 205 unrelated Japanese FH (familial hypercholesterolemia) heterozygotes to see if there is a prevalence of common mutations in the Japanese population. A total of 53 different small mutations (<25bp) and 10 kinds of large deletions (>25bp) were identified. Among them there were eight relatively frequent mutations: C317S, c.1845+2T>C, K790X, L547V, P664L, D412H, c.2312-3C>A and V776M. The patients with these mutations comprised 32% of the total FH heterozygotes investigated. Comparison of clinical phenotypes of the eight frequent mutations disclosed that a missense mutation, L547V, manifested a milder phenotype than the other mutations. The mild clinical phenotype was shown to be based on the high level of receptor activity remaining on the patient's cell surfaces. When we examined the presence of common mutations in a general population, the L547V mutation was detected with unexpectedly higher frequency than the other mutations, suggesting an underestimation of the frequency of this mutation in FH heterozygote patients. In conclusion, although there is a broad spectrum of LDLR gene mutations in the Japanese population, eight common mutations were observed. Among them, a mild phenotype mutation, L547V, might predominate in the Japanese population.

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Year:  2008        PMID: 18718593     DOI: 10.1016/j.atherosclerosis.2008.07.005

Source DB:  PubMed          Journal:  Atherosclerosis        ISSN: 0021-9150            Impact factor:   5.162


  12 in total

1.  Low prevalence of mutations in known loci for autosomal dominant hypercholesterolemia in a multiethnic patient cohort.

Authors:  Zahid Ahmad; Beverley Adams-Huet; Chiyuan Chen; Abhimanyu Garg
Journal:  Circ Cardiovasc Genet       Date:  2012-10-11

2.  Evaluation of reported pathogenic variants and their frequencies in a Japanese population based on a whole-genome reference panel of 2049 individuals.

Authors:  Yumi Yamaguchi-Kabata; Jun Yasuda; Osamu Tanabe; Yoichi Suzuki; Hiroshi Kawame; Nobuo Fuse; Masao Nagasaki; Yosuke Kawai; Kaname Kojima; Fumiki Katsuoka; Sakae Saito; Inaho Danjoh; Ikuko N Motoike; Riu Yamashita; Seizo Koshiba; Daisuke Saigusa; Gen Tamiya; Shigeo Kure; Nobuo Yaegashi; Yoshio Kawaguchi; Fuji Nagami; Shinichi Kuriyama; Junichi Sugawara; Naoko Minegishi; Atsushi Hozawa; Soichi Ogishima; Hideyasu Kiyomoto; Takako Takai-Igarashi; Kengo Kinoshita; Masayuki Yamamoto
Journal:  J Hum Genet       Date:  2017-12-01       Impact factor: 3.172

3.  Structure-Function Relationships of LDL Receptor Missense Mutations Using Homology Modeling.

Authors:  Sureerut Porntadavity; Nutjaree Jeenduang
Journal:  Protein J       Date:  2019-08       Impact factor: 2.371

4.  Premature coronary heart disease and autosomal dominant hypercholesterolemia: Increased risk in women with LDLR mutations.

Authors:  Zahid Ahmad; Xilong Li; Jedrek Wosik; Preethi Mani; Joye Petr; George McLeod; Shatha Murad; Li Song; Beverley Adams-Huet; Abhimanyu Garg
Journal:  J Clin Lipidol       Date:  2015-09-25       Impact factor: 4.766

5.  Analysis of sequence variations in low-density lipoprotein receptor gene among Malaysian patients with familial hypercholesterolemia.

Authors:  Alyaa Al-Khateeb; Mohd K Zahri; Mohd S Mohamed; Teguh H Sasongko; Suhairi Ibrahim; Zurkurnai Yusof; Bin A Zilfalil
Journal:  BMC Med Genet       Date:  2011-03-19       Impact factor: 2.103

6.  Genetic testing of Korean familial hypercholesterolemia using whole-exome sequencing.

Authors:  Soo Min Han; Byungjin Hwang; Tae-gun Park; Do-Il Kim; Moo-Yong Rhee; Byoung-Kwon Lee; Young Keun Ahn; Byung Ryul Cho; Jeongtaek Woo; Seung-Ho Hur; Jin-Ok Jeong; Sungha Park; Yangsoo Jang; Min Goo Lee; Duhee Bang; Ji Hyun Lee; Sang-Hak Lee
Journal:  PLoS One       Date:  2015-05-11       Impact factor: 3.240

Review 7.  Validation of LDLr Activity as a Tool to Improve Genetic Diagnosis of Familial Hypercholesterolemia: A Retrospective on Functional Characterization of LDLr Variants.

Authors:  Asier Benito-Vicente; Kepa B Uribe; Shifa Jebari; Unai Galicia-Garcia; Helena Ostolaza; Cesar Martin
Journal:  Int J Mol Sci       Date:  2018-06-05       Impact factor: 5.923

8.  p.(Asp47Asn) and p.(Thr62Met): non deleterious LDL receptor missense variants functionally characterized in vitro.

Authors:  A Benito-Vicente; H Siddiqi; K B Uribe; S Jebari; U Galicia-Garcia; A Larrea-Sebal; M Stef; H Ostolaza; L Palacios; C Martin
Journal:  Sci Rep       Date:  2018-11-09       Impact factor: 4.379

Review 9.  Familial hypercholesterolemia in Southeast and East Asia.

Authors:  Candace L Jackson; Magdi Zordok; Iftikhar J Kullo
Journal:  Am J Prev Cardiol       Date:  2021-02-12

10.  Detection of Familial Hypercholesterolemia Using Next Generation Sequencing in Two Population-Based Cohorts.

Authors:  Hee Nam Kim; Sun-Seog Kweon; Min-Ho Shin
Journal:  Chonnam Med J       Date:  2018-01-25
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