Literature DB >> 18599533

Mechanisms by which atrial fibrillation-associated mutations in the S1 domain of KCNQ1 slow deactivation of IKs channels.

Lioara Restier1, Lan Cheng, Michael C Sanguinetti.   

Abstract

The slow delayed rectifier K(+) current (I(Ks)) is a major determinant of action potential repolarization in the heart. I(Ks) channels are formed by coassembly of pore-forming KCNQ1 alpha-subunits and ancillary KCNE1 beta-subunits. Two gain of function mutations in KCNQ1 subunits (S140G and V141M) have been associated with atrial fibrillation (AF). Previous heterologous expression studies found that both mutations caused I(Ks) to be instantaneously activated, presumably by preventing channel closure. The purpose of this study was to refine our understanding of the channel gating defects caused by these two mutations located in the S1 domain of KCNQ1. Site-directed mutagenesis was used to replace S140 or V141 with several other natural amino acids. Wild-type and mutant channels were heterologously expressed in Xenopus oocytes and channel function was assessed with the two-microelectrode voltage clamp technique. Long intervals between voltage clamp pulses revealed that S140G and V141M KCNQ1-KCNE1 channels are not constitutively active as previously reported, but instead exhibit extremely slow deactivation. The slow component of I(Ks) deactivation was decreased 62-fold by S140G and 140-fold by the V141M mutation. In addition, the half-point for activation of these mutant I(Ks) channels was approximately 50 mV more negative than wild-type channels. Other substitutions of S140 or V141 in KCNQ1 caused variable shifts in the voltage dependence of activation, but slowed I(Ks) deactivation to a much lesser extent than the AF-associated mutations. Based on a published structural model of KCNQ1, S140 and V141 are located near E160 in S2 and R237 in S4, two charged residues that could form a salt bridge when the channel is in the open state. In support of this model, mutational exchange of E160 and R237 residues produced a constitutively open channel. Together our findings suggest that altered charge-pair interactions within the voltage sensor module of KCNQ1 subunits may account for slowed I(Ks) deactivation induced by S140 or V141.

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Year:  2008        PMID: 18599533      PMCID: PMC2652179          DOI: 10.1113/jphysiol.2008.157511

Source DB:  PubMed          Journal:  J Physiol        ISSN: 0022-3751            Impact factor:   5.182


  33 in total

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Journal:  Proc Natl Acad Sci U S A       Date:  2003-02-26       Impact factor: 11.205

3.  Parental atrial fibrillation as a risk factor for atrial fibrillation in offspring.

Authors:  Caroline S Fox; Helen Parise; Ralph B D'Agostino; Donald M Lloyd-Jones; Ramachandran S Vasan; Thomas J Wang; Daniel Levy; Philip A Wolf; Emelia J Benjamin
Journal:  JAMA       Date:  2004-06-16       Impact factor: 56.272

4.  Negative charges in the transmembrane domains of the HERG K channel are involved in the activation- and deactivation-gating processes.

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Journal:  J Gen Physiol       Date:  2003-06       Impact factor: 4.086

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Authors:  William R Silverman; John P A Bannister; Diane M Papazian
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6.  Identification of a KCNE2 gain-of-function mutation in patients with familial atrial fibrillation.

Authors:  Yiqing Yang; Min Xia; Qingfeng Jin; Saïd Bendahhou; Jingyi Shi; Yiping Chen; Bo Liang; Jie Lin; Yi Liu; Ban Liu; Qinshu Zhou; Dongwei Zhang; Rong Wang; Ning Ma; Xiaoyan Su; Kaiya Niu; Yan Pei; Wenyuan Xu; Zhaopeng Chen; Haiying Wan; Jianmin Cui; Jacques Barhanin; Yihan Chen
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8.  MinK subdomains that mediate modulation of and association with KvLQT1.

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Journal:  J Gen Physiol       Date:  2008-06       Impact factor: 4.086

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  40 in total

1.  Pitx2 prevents susceptibility to atrial arrhythmias by inhibiting left-sided pacemaker specification.

Authors:  Jun Wang; Elzbieta Klysik; Subeena Sood; Randy L Johnson; Xander H T Wehrens; James F Martin
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Review 2.  Voltage-Dependent Gating: Novel Insights from KCNQ1 Channels.

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Journal:  Biophys J       Date:  2016-01-05       Impact factor: 4.033

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Journal:  Biophys J       Date:  2011-02-16       Impact factor: 4.033

4.  Single-channel basis for the slow activation of the repolarizing cardiac potassium current, I(Ks).

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Journal:  Proc Natl Acad Sci U S A       Date:  2013-02-19       Impact factor: 11.205

Review 5.  KCNQ1 channel modulation by KCNE proteins via the voltage-sensing domain.

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Journal:  J Physiol       Date:  2015-02-16       Impact factor: 5.182

Review 6.  Genetics of atrial fibrillation: from families to genomes.

Authors:  Ingrid E Christophersen; Patrick T Ellinor
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Review 7.  Cardiac Delayed Rectifier Potassium Channels in Health and Disease.

Authors:  Lei Chen; Kevin J Sampson; Robert S Kass
Journal:  Card Electrophysiol Clin       Date:  2016-04-01

Review 8.  Monogenic atrial fibrillation as pathophysiological paradigms.

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Journal:  Cardiovasc Res       Date:  2010-11-30       Impact factor: 10.787

9.  Molecular remodeling of ion channels, exchangers and pumps in atrial and ventricular myocytes in ischemic cardiomyopathy.

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10.  Distinct subdomains of the KCNQ1 S6 segment determine channel modulation by different KCNE subunits.

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Journal:  J Gen Physiol       Date:  2009-08-17       Impact factor: 4.086

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