Literature DB >> 18538102

Nail-patella syndrome and renal involvement. Description of three cases and literature review.

A Granata1, G Nori, R Ravazzolo, M Marini, S Castellino, E Sicurezza, C E Fiore, R Mignani.   

Abstract

Nail-patella syndrome (NPS) is a rare, autosomal dominant disorder reported in approximatively 1/50,000 individuals. It is characterized by hypoplastic or absent patellae, dystrophic nails, dysplasia of the elbows and iliac horns. Less frequently renal and ocular damages occur. The abnormal gene in NPS is located at the distal end of the long arm of Chromosome 9. Mutations in the human LMX1B gene have been demonstrated to be responsible for NPS. It encodes a LIM-homeodomain transcription factor which plays an important role in limb development in vertebrates. Extensive mutation analysis of different NPS families by different groups failed to demonstrate any genotype-phenotype correlation. Renal involvement occurs in 30-60% of patients and presents with proteinuria and/or microscopic hematuria, edema, hypertension. Progression to nephrotic syndrome occurs in less than 20% of patients, and renal failure in about 10% of NPS patients requiring dialysis and/or transplantation. We report three cases of NPS with different degrees of renal involvement and present a review of the literature on this rare hereditary condition.

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Year:  2008        PMID: 18538102     DOI: 10.5414/cnp69377

Source DB:  PubMed          Journal:  Clin Nephrol        ISSN: 0301-0430            Impact factor:   0.975


  4 in total

1.  A case of ectopic cilia in nail-patella syndrome.

Authors:  Matthew R Edmunds; Athina Kipioti; Peter S Colloby; Tristan T Q Reuser
Journal:  Int Ophthalmol       Date:  2012-03-23       Impact factor: 2.031

2.  Nail-Patella Syndrome: clinical and molecular data in 55 families raising the hypothesis of a genetic heterogeneity.

Authors:  Jamal Ghoumid; Florence Petit; Muriel Holder-Espinasse; Anne-Sophie Jourdain; José Guerra; Anne Dieux-Coeslier; Martin Figeac; Nicole Porchet; Sylvie Manouvrier-Hanu; Fabienne Escande
Journal:  Eur J Hum Genet       Date:  2015-04-22       Impact factor: 4.246

3.  Radiographic findings in the nail-patella syndrome.

Authors:  James A West; Thomas H Louis
Journal:  Proc (Bayl Univ Med Cent)       Date:  2015-07

4.  Treatment of patellar instability in a case of hereditary onycho-osteodysplasia (nail-patella syndrome) with medial patellofemoral ligament reconstruction: A case report.

Authors:  Yubao Gong; Chen Yang; Yang Liu; Jianguo Liu; Xin Qi
Journal:  Exp Ther Med       Date:  2016-03-23       Impact factor: 2.447

  4 in total

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