Literature DB >> 18363170

Novel RDH5 mutation in family with mother having fundus albipunctatus and three children with retinitis pigmentosa.

Chunxia Wang1, Nobuo Nakanishi, Kentaro Ohishi, Akiko Hikoya, Kenro Koide, Miho Sato, Makoto Nakamura, Yoshihiro Hotta, Shinsei Minoshima.   

Abstract

PURPOSE: To identify mutations in the RDH5 gene in a family with a mother having fundus albipunctatus (FA) and 3 children with retinitis pigmentosa (RP).
METHODS: Ophthalmological examinations were performed to diagnose FA and RP. Mutational analysis of RDH5 was performed. RESULTS/
CONCLUSIONS: The mother was diagnosed with FA, and 3 children were diagnosed with RP. The proband's mother, brother, and sister had a novel mutation c.689_690CT > GG in RDH5. The proband and mother had a previously reported mutation c.928delCinsGAAG. Consequently, the mother's FA was caused by compound heterozygous mutations. Further studies will be needed to determine the gene responsible for children's RP.

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Year:  2008        PMID: 18363170     DOI: 10.1080/13816810701663535

Source DB:  PubMed          Journal:  Ophthalmic Genet        ISSN: 1381-6810            Impact factor:   1.803


  7 in total

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Journal:  Curr Mol Med       Date:  2010-12       Impact factor: 2.222

2.  A novel mutation in RDH5 gene causes retinitis pigmentosa in consanguineous Pakistani family.

Authors:  Neelam Sultan; Irfan Ali; Shazia Anwer Bukhari; Shahid Mahmood Baig; Muhammad Asif; Muhammad Qasim; Muhammad Imran Naseer; Mahmood Rasool
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3.  Novel mutations in RDH5 cause fundus albipunctatus in two consanguineous Pakistani families.

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Journal:  Mol Vis       Date:  2012-06-13       Impact factor: 2.367

Review 4.  Fundus albipunctatus: review of the literature and report of a novel RDH5 gene mutation affecting the invariant tyrosine (p.Tyr175Phe).

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6.  Novel variants in the RDH5 Gene in a Chinese Han family with fundus albipunctatus.

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7.  A Novel Pathogenic Variant in the RDH5 Gene in a Patient with Fundus Albipunctatus and Severe Macular Atrophy.

Authors:  Hyelin You; David Sierpina
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  7 in total

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