Literature DB >> 18240370

[Prenatal diagnosis of Gaucher disease].

D P Germain1, K Benistan.   

Abstract

Gaucher disease (GD, OMIM #230800, 230900, 231000) is a lysosomal surcharge disorder caused by a deficiency in glucocerebrosidase, a lysosomal enzyme also referred to as acid beta-glucosidase or, in rare cases, by a deficiency in the activator protein saposin C. Partial deficiency of acid beta-glucosidase is associated with the presence of glucosylceramide, also known as glucocerebroside (Gb1), deposits in the reticuloendothelial cells of the liver, spleen and bone marrow, in non-neuronopathic type 1, GD. Profound deficiency of acid beta-glucosidase caused by disabling mutations is additionally associated with neurological manifestations in the less common type 2 and type 3 Gaucher diseases. Type 2 GD culminates in early death as a result of devastating neurological disease. Congenital ichtyosis with a collodion baby phenotype is also part of the spectrum of clinical presentations of type 2 GD. Recombinant glucocerebrosidase (imiglucerase) is an effective mean of treating type 1 GD and should be initiated early on in life. Although imiglucerase has recently been approved for the treatment of type 3 GD, enzyme replacement therapy cannot reverse the neurological manifestations in type 2 or type 3 GD. Following genetic counseling and informed consent, direct enzymatic assay of acid beta-glucosidase and molecular testing of the GBA mutations on chorionic villi samples (CVS) can be offered to families in which type 2 or type 3 GD has been diagnosed. Improvement in substrate deprivation therapy or gene therapy may provide a cure for patients with these disorders in the future.

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Year:  2007        PMID: 18240370     DOI: 10.1016/s0248-8663(07)78881-1

Source DB:  PubMed          Journal:  Rev Med Interne        ISSN: 0248-8663            Impact factor:   0.728


  2 in total

1.  Prenatal Diagnosis of Gaucher Disease.

Authors:  Y Singh; D Arora; Sps Kochar
Journal:  Med J Armed Forces India       Date:  2011-07-21

2.  Gaucher's Disease in Albanian Children: Casuistics and Treatment.

Authors:  Behar Shehi; Gëzim Boçari; Gentian Vyshka; Rezar Xhepa; Dritan Alushani
Journal:  Iran J Pediatr       Date:  2011-03       Impact factor: 0.364

  2 in total

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