Literature DB >> 18196473

Myopathy in Gaucher disease.

Li-Kai Tsai1, Yin-Hsiu Chien, Chih-Chao Yang, Wuh-Liang Hwu.   

Abstract

Gaucher disease is a recessively inherited lysosomal storage disorder, caused by deficiency of glucocerebrosidase activity. Affected individuals usually present with hepatosplenomegaly, anaemia, thrombocytopenia, and skeletal diseases. A wide range of neurological manifestations have also been recognized in Gaucher patients including acute neurological deterioration in infancy, mental retardation, ocular motor apraxia, seizure, and parkinsonism. Although muscle weakness is not an uncommon finding in patients with Gaucher disease, the aetiology of weakness is not well understood. We prospectively investigated seven Gaucher patients and found that four of them (patients 1-4) had mild to moderate degree of proximal-predominant symmetrical muscle weakness in four limbs. By history, three patients (patients 1-3) developed insidious onset of nonprogressive muscle weakness in four limbs with easy muscle fatigue from adolescence. A needle electromyographic study detected some small, brief polyphasic waves in these four patients. Muscle biopsy in one patient (patient 1) showed a few atrophic type II muscle fibres without infiltration of Gaucher cells. Three patients (patients 1-3) continuously received enzyme replacement therapy with imiglucerase and their muscle strength seemed improved after two years. We concluded that Gaucher disease may be associated with myopathy.

Entities:  

Year:  2008        PMID: 18196473     DOI: 10.1007/s10545-007-0795-4

Source DB:  PubMed          Journal:  J Inherit Metab Dis        ISSN: 0141-8955            Impact factor:   4.982


  7 in total

Review 1.  Recent clinical progress in Gaucher disease.

Authors:  Gregory A Grabowski
Journal:  Curr Opin Pediatr       Date:  2005-08       Impact factor: 2.856

2.  Glucosylceramide and glucosylsphingosine modulate calcium mobilization from brain microsomes via different mechanisms.

Authors:  Emyr Lloyd-Evans; Dori Pelled; Christian Riebeling; Jacques Bodennec; Aviv de-Morgan; Helen Waller; Raphael Schiffmann; Anthony H Futerman
Journal:  J Biol Chem       Date:  2003-04-22       Impact factor: 5.157

Review 3.  Musculoskeletal complications associated with lysosomal storage disorders: Gaucher disease and Hurler-Scheie syndrome (mucopolysaccharidosis type I).

Authors:  Gregory M Pastores; Patrick A Meere
Journal:  Curr Opin Rheumatol       Date:  2005-01       Impact factor: 5.006

4.  Enhanced calcium release in the acute neuronopathic form of Gaucher disease.

Authors:  Dori Pelled; Selena Trajkovic-Bodennec; Emyr Lloyd-Evans; Ellen Sidransky; Raphael Schiffmann; Anthony H Futerman
Journal:  Neurobiol Dis       Date:  2005-02       Impact factor: 5.996

Review 5.  Gaucher disease: complexity in a "simple" disorder.

Authors:  Ellen Sidransky
Journal:  Mol Genet Metab       Date:  2004 Sep-Oct       Impact factor: 4.797

6.  A neurological symptom survey of patients with type I Gaucher disease.

Authors:  G M Pastores; N L Barnett; P Bathan; E H Kolodny
Journal:  J Inherit Metab Dis       Date:  2003       Impact factor: 4.982

Review 7.  Calcium regulation and muscle disease.

Authors:  I M P Gommans; M H M Vlak; A de Haan; B G M van Engelen
Journal:  J Muscle Res Cell Motil       Date:  2002       Impact factor: 2.698

  7 in total
  1 in total

Review 1.  Rethinking fatigue in Gaucher disease.

Authors:  Y Chen Zion; E Pappadopulos; M Wajnrajch; H Rosenbaum
Journal:  Orphanet J Rare Dis       Date:  2016-04-29       Impact factor: 4.123

  1 in total

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