Literature DB >> 17943323

A milder variant of Pierson syndrome.

Mikhail Kagan1, Arthur H Cohen, Verena Matejas, Christopher Vlangos, Martin Zenker.   

Abstract

Congenital nephrotic syndrome (CNS) comprises a heterogeneous group of conditions having in common the disruption of normal glomerular permselectivity, and it carries a poor prognosis, with most patients progressing to end-stage renal disease. Recently, mutations in the LAMB2 gene encoding laminin beta2 were described as the cause of Pierson syndrome, which is characterized by CNS and a complex ocular maldevelopment with microcoria as the most prominent clinical features. Most affected children exhibit early onset of chronic renal failure, neurodevelopmental deficits, and blindness. We report on a patient with CNS, high-grade myopia, and minor structural eye anomalies, including remnants of pupillary membranes, but no microcoria. The patient had not developed renal failure by the age of 16 months, and he showed no neurodevelopmental deficits. He was identified to be homozygous for a novel LAMB2 missense mutation. This observation, together with two recent reports on milder variants of Pierson syndrome, corroborates the concept that the clinical expression of Pierson syndrome is more variable than initially described, and that milder phenotypes may be related to hypomorphic LAMB2 alleles.

Entities:  

Mesh:

Substances:

Year:  2007        PMID: 17943323     DOI: 10.1007/s00467-007-0624-x

Source DB:  PubMed          Journal:  Pediatr Nephrol        ISSN: 0931-041X            Impact factor:   3.714


  15 in total

Review 1.  Laminins: structure and genetic regulation.

Authors:  P Tunggal; N Smyth; M Paulsson; M C Ott
Journal:  Microsc Res Tech       Date:  2000-11-01       Impact factor: 2.769

2.  A syndrome comprising childhood-onset glomerular kidney disease and ocular abnormalities with progressive loss of vision is caused by mutated LAMB2.

Authors:  Verena Matejas; Lihadh Al-Gazali; Iradj Amirlak; Martin Zenker
Journal:  Nephrol Dial Transplant       Date:  2006-08-18       Impact factor: 5.992

3.  Role of laminin terminal globular domains in basement membrane assembly.

Authors:  Karen K McKee; David Harrison; Stephanie Capizzi; Peter D Yurchenco
Journal:  J Biol Chem       Date:  2007-05-21       Impact factor: 5.157

4.  [LAMB2 gene mutation as a cause of congenital nephrotic syndrome with distinct eye abnormalities and hypotonia].

Authors:  Aleksandra Zurowska; Iga Załuska-Leśniewska; Martin Zenker
Journal:  Przegl Lek       Date:  2006

5.  Pierson syndrome: a novel cause of congenital nephrotic syndrome.

Authors:  Rene' VanDeVoorde; David Witte; Jillene Kogan; Jens Goebel
Journal:  Pediatrics       Date:  2006-07-24       Impact factor: 7.124

Review 6.  Nephrotic syndrome in the 1st year of life.

Authors:  R Habib
Journal:  Pediatr Nephrol       Date:  1993-08       Impact factor: 3.714

Review 7.  Congenital nephrosis, mesangial sclerosis, and distinct eye abnormalities with microcoria: an autosomal recessive syndrome.

Authors:  Martin Zenker; Tim Tralau; Thomas Lennert; Susanne Pitz; Karlheinz Mark; Henry Madlon; Jörg Dötsch; André Reis; Horst Müntefering; Luitgard M Neumann
Journal:  Am J Med Genet A       Date:  2004-10-01       Impact factor: 2.802

8.  Human laminin beta2 deficiency causes congenital nephrosis with mesangial sclerosis and distinct eye abnormalities.

Authors:  Martin Zenker; Thomas Aigner; Olaf Wendler; Tim Tralau; Horst Müntefering; Regina Fenski; Susanne Pitz; Valérie Schumacher; Brigitte Royer-Pokora; Elke Wühl; Pierre Cochat; Raymonde Bouvier; Cornelia Kraus; Karlheinz Mark; Henry Madlon; Jörg Dötsch; Wolfgang Rascher; Iwona Maruniak-Chudek; Thomas Lennert; Luitgard M Neumann; André Reis
Journal:  Hum Mol Genet       Date:  2004-09-14       Impact factor: 6.150

9.  The renal glomerulus of mice lacking s-laminin/laminin beta 2: nephrosis despite molecular compensation by laminin beta 1.

Authors:  P G Noakes; J H Miner; M Gautam; J M Cunningham; J R Sanes; J P Merlie
Journal:  Nat Genet       Date:  1995-08       Impact factor: 38.330

Review 10.  Kidney in Galloway-Mowat syndrome: clinical spectrum with description of pathology.

Authors:  A H Cohen; M C Turner
Journal:  Kidney Int       Date:  1994-05       Impact factor: 10.612

View more
  15 in total

1.  Genotype-phenotype correlations in non-Finnish congenital nephrotic syndrome.

Authors:  Eduardo Machuca; Geneviève Benoit; Fabien Nevo; Marie-Josèphe Tête; Olivier Gribouval; Audrey Pawtowski; Per Brandström; Chantal Loirat; Patrick Niaudet; Marie-Claire Gubler; Corinne Antignac
Journal:  J Am Soc Nephrol       Date:  2010-05-27       Impact factor: 10.121

2.  Extracellular Matrix in Kidney Fibrosis: More Than Just a Scaffold.

Authors:  Roman David Bülow; Peter Boor
Journal:  J Histochem Cytochem       Date:  2019-05-22       Impact factor: 2.479

3.  A novel mutation of LAMB2 in a multigenerational mennonite family reveals a new phenotypic variant of Pierson syndrome.

Authors:  Brian G Mohney; Jose S Pulido; Noralane M Lindor; Marie C Hogan; Mark B Consugar; Justin Peters; V Shane Pankratz; Samih H Nasr; Stephen J Smith; James Gloor; Vickie Kubly; Dorothy Spencer; Rebecca Nielson; Erik G Puffenberger; Kevin A Strauss; D Holmes Morton; Lama Eldahdah; Peter C Harris
Journal:  Ophthalmology       Date:  2011-01-13       Impact factor: 12.079

4.  Pierson syndrome in an adolescent girl with nephrotic range proteinuria but a normal GFR.

Authors:  Anja Lehnhardt; Albert Lama; Kerstin Amann; Verena Matejas; Martin Zenker; Markus J Kemper
Journal:  Pediatr Nephrol       Date:  2012-01-08       Impact factor: 3.714

5.  Variable phenotype of Pierson syndrome.

Authors:  Hyun Jin Choi; Beom Hee Lee; Ju Hyung Kang; Hyoen Joo Jeong; Kyung Chul Moon; Il Soo Ha; Young Suk Yu; Verena Matejas; Martin Zenker; Yong Choi; Hae Il Cheong
Journal:  Pediatr Nephrol       Date:  2008-06       Impact factor: 3.714

Review 6.  The glomerular basement membrane as a barrier to albumin.

Authors:  Jung Hee Suh; Jeffrey H Miner
Journal:  Nat Rev Nephrol       Date:  2013-06-18       Impact factor: 28.314

7.  Analysis of genes encoding laminin beta2 and related proteins in patients with Galloway-Mowat syndrome.

Authors:  Andreas Dietrich; Verena Matejas; Martin Bitzan; Seema Hashmi; Cathy Kiraly-Borri; Shuan-Pei Lin; Eva Mildenberger; Bernd Hoppe; Lars Palm; Takashi Shiihara; Jens-Oliver Steiss; Jeng-Daw Tsai; Udo Vester; Stefanie Weber; Elke Wühl; Kristina Zepf; Martin Zenker
Journal:  Pediatr Nephrol       Date:  2008-07-02       Impact factor: 3.714

Review 8.  Genetics of nephrotic syndrome: new insights into molecules acting at the glomerular filtration barrier.

Authors:  Martin Zenker; Eduardo Machuca; Corinne Antignac
Journal:  J Mol Med (Berl)       Date:  2009-08-01       Impact factor: 4.599

9.  Molecular mechanisms determining severity in patients with Pierson syndrome.

Authors:  Shogo Minamikawa; Saori Miwa; Tetsuji Inagaki; Kei Nishiyama; Hiroshi Kaito; Takeshi Ninchoji; Tomohiko Yamamura; China Nagano; Nana Sakakibara; Shingo Ishimori; Shigeo Hara; Norishige Yoshikawa; Daishi Hirano; Ryoko Harada; Riku Hamada; Natsuki Matsunoshita; Michio Nagata; Yuko Shima; Koichi Nakanishi; Hiroaki Nagase; Hiroki Takeda; Naoya Morisada; Kazumoto Iijima; Kandai Nozu
Journal:  J Hum Genet       Date:  2020-01-21       Impact factor: 3.172

Review 10.  Mutations in the human laminin beta2 (LAMB2) gene and the associated phenotypic spectrum.

Authors:  Verena Matejas; Bernward Hinkes; Faisal Alkandari; Lihadh Al-Gazali; Ellen Annexstad; Mehmet B Aytac; Margaret Barrow; Kveta Bláhová; Detlef Bockenhauer; Hae Il Cheong; Iwona Maruniak-Chudek; Pierre Cochat; Jörg Dötsch; Priya Gajjar; Raoul C Hennekam; Françoise Janssen; Mikhail Kagan; Ariana Kariminejad; Markus J Kemper; Jens Koenig; Jillene Kogan; Hester Y Kroes; Eberhard Kuwertz-Bröking; Amy F Lewanda; Ana Medeira; Jutta Muscheites; Patrick Niaudet; Michel Pierson; Anand Saggar; Laurie Seaver; Mohnish Suri; Alexey Tsygin; Elke Wühl; Aleksandra Zurowska; Steffen Uebe; Friedhelm Hildebrandt; Corinne Antignac; Martin Zenker
Journal:  Hum Mutat       Date:  2010-09       Impact factor: 4.878

View more

北京卡尤迪生物科技股份有限公司 © 2022-2023.