Literature DB >> 17931875

Identification of alpha-fetoprotein as an autoantigen in juvenile Batten disease.

Julian A Castaneda1, David A Pearce.   

Abstract

Humoral autoimmunity against glutamic acid decarboxylase has been described in juvenile Batten disease patients and in the Cln3(-/-) mouse model. To obtain a more comprehensive understanding of the repertoire of antigens targeted, we examined the reactivity of Cln3(-/-) mouse sera to brain proteins from fetal, postnatal and adult rats. Among the candidate antigens identified was alpha-fetoprotein (AFP), a protein that has altered expression in several nervous system disorders and hepatic malignancies. Moreover, AFP levels were upregulated in the brains and livers of postnatal day 14 Cln3(-/-) animals. Sera from 31 juvenile Batten disease patients revealed the presence of anti-AFP autoantibodies in juvenile Batten disease male patients (12/13) and female patients (8/18). While these findings provide more evidence that autoimmunity is an active component of juvenile Batten disease, the gender-apparent difference evidenced by patients with regard anti-AFP antibodies may underlie variation in progression and clinical manifestations in this disorder.

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Year:  2007        PMID: 17931875     DOI: 10.1016/j.nbd.2007.08.007

Source DB:  PubMed          Journal:  Neurobiol Dis        ISSN: 0969-9961            Impact factor:   5.996


  15 in total

1.  Abnormally increased surface expression of AMPA receptors in the cerebellum, cortex and striatum of Cln3(-/-) mice.

Authors:  Attila D Kovács; Caitlin Hof; David A Pearce
Journal:  Neurosci Lett       Date:  2015-09-12       Impact factor: 3.046

2.  Antigen presenting cell abnormalities in the Cln3(-/-) mouse model of juvenile neuronal ceroid lipofuscinosis.

Authors:  Samantha L Hersrud; Attila D Kovács; David A Pearce
Journal:  Biochim Biophys Acta       Date:  2016-04-19

3.  Clinical and molecular characterization of non-syndromic retinal dystrophy due to c.175G>A mutation in ceroid lipofuscinosis neuronal 3 (CLN3).

Authors:  Fred K Chen; Xiao Zhang; Jonathan Eintracht; Dan Zhang; Sukanya Arunachalam; Jennifer A Thompson; Enid Chelva; Dominic Mallon; Shang-Chih Chen; Terri McLaren; Tina Lamey; John De Roach; Samuel McLenachan
Journal:  Doc Ophthalmol       Date:  2018-11-16       Impact factor: 2.379

4.  Short-Term Administration of Mycophenolate Is Well-Tolerated in CLN3 Disease (Juvenile Neuronal Ceroid Lipofuscinosis).

Authors:  Erika F Augustine; Christopher A Beck; Heather R Adams; Sara Defendorf; Amy Vierhile; Derek Timm; Jill M Weimer; Jonathan W Mink; Frederick J Marshall
Journal:  JIMD Rep       Date:  2018-06-20

5.  The juvenile Batten disease protein, CLN3, and its role in regulating anterograde and retrograde post-Golgi trafficking.

Authors:  Susan L Cotman; John F Staropoli
Journal:  Clin Lipidol       Date:  2012-02

6.  Immunosuppression alters disease severity in juvenile Batten disease mice.

Authors:  Sabrina S Seehafer; Denia Ramirez-Montealegre; Andrew Ms Wong; Chun-Hung Chan; Julian Castaneda; Michael Horak; Sarah M Ahmadi; Ming J Lim; Jonathan D Cooper; David A Pearce
Journal:  J Neuroimmunol       Date:  2011-01       Impact factor: 3.478

Review 7.  Juvenile neuronal ceroid lipofuscinosis (JNCL) and the eye.

Authors:  Sara Bozorg; Denia Ramirez-Montealegre; Mina Chung; David A Pearce
Journal:  Surv Ophthalmol       Date:  2009 Jul-Aug       Impact factor: 6.048

Review 8.  Therapeutic landscape for Batten disease: current treatments and future prospects.

Authors:  Tyler B Johnson; Jacob T Cain; Katherine A White; Denia Ramirez-Montealegre; David A Pearce; Jill M Weimer
Journal:  Nat Rev Neurol       Date:  2019-03       Impact factor: 42.937

9.  Large-scale phenotyping of an accurate genetic mouse model of JNCL identifies novel early pathology outside the central nervous system.

Authors:  John F Staropoli; Larissa Haliw; Sunita Biswas; Lillian Garrett; Sabine M Hölter; Lore Becker; Sergej Skosyrski; Patricia Da Silva-Buttkus; Julia Calzada-Wack; Frauke Neff; Birgit Rathkolb; Jan Rozman; Anja Schrewe; Thure Adler; Oliver Puk; Minxuan Sun; Jack Favor; Ildikó Racz; Raffi Bekeredjian; Dirk H Busch; Jochen Graw; Martin Klingenspor; Thomas Klopstock; Eckhard Wolf; Wolfgang Wurst; Andreas Zimmer; Edith Lopez; Hayat Harati; Eric Hill; Daniela S Krause; Jolene Guide; Ella Dragileva; Evan Gale; Vanessa C Wheeler; Rose-Mary Boustany; Diane E Brown; Sylvie Breton; Klaus Ruether; Valérie Gailus-Durner; Helmut Fuchs; Martin Hrabě de Angelis; Susan L Cotman
Journal:  PLoS One       Date:  2012-06-06       Impact factor: 3.240

10.  Loss of CLN3, the gene mutated in juvenile neuronal ceroid lipofuscinosis, leads to metabolic impairment and autophagy induction in retinal pigment epithelium.

Authors:  Yu Zhong; Kabhilan Mohan; Jinpeng Liu; Ahmad Al-Attar; Penghui Lin; Robert M Flight; Qiushi Sun; Marc O Warmoes; Rahul R Deshpande; Huijuan Liu; Kyung Sik Jung; Mihail I Mitov; Nianwei Lin; D Allan Butterfield; Shuyan Lu; Jinze Liu; Hunter N B Moseley; Teresa W M Fan; Mark E Kleinman; Qing Jun Wang
Journal:  Biochim Biophys Acta Mol Basis Dis       Date:  2020-06-25       Impact factor: 6.633

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