Literature DB >> 17704945

Ocular findings in children with a microdeletion in chromosome 22q11.2.

Ingele Casteels1, Patricia Casaer, Marc Gewillig, Ann Swillen, Koenraad Devriendt.   

Abstract

A microdeletion in chromosome 22q11.2 is one of the most frequent genetic syndromes. The phenotypic manifestations vary widely, which has led to its initial description as apparently different clinical entities, such as the velocardiofacial syndrome (VCFS) and DiGeorge syndrome. Characteristic features include cleft palate, conotruncal heart malformations, thymus hypoplasia, hypoparathyroidism, a characteristic facial phenotype and learning difficulties. Ocular abnormalities are frequently seen in this patient population. We describe the ophthalmological findings in 36 children between the age of 3 and 14 years with a microdeletion in chromosome 22q11.2. They underwent a full ophthalmological examination with assessment of visual acuity, eye position and motility, stereoscopic vision, biomicroscopic examination, refraction and fundoscopy. If necessary amblyopia treatment was started and follow-up was planned. The presence of a cardiovascular malformation was noted. In conclusion, refractive errors, strabismus, amblyopia and structural ocular abnormalities are frequently encountered in children with a microdeletion in chromosome 22q11.2. Ophthalmological examination at a young age and refractive correction in those children is warranted. On the other hand, ocular findings can give a clue to the diagnosis of del 22q11.2.

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Year:  2007        PMID: 17704945     DOI: 10.1007/s00431-007-0582-0

Source DB:  PubMed          Journal:  Eur J Pediatr        ISSN: 0340-6199            Impact factor:   3.183


  22 in total

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  8 in total

1.  Unmasking of a Recessive SCARF2 Mutation by a 22q11.12 de novo Deletion in a Patient with Van den Ende-Gupta Syndrome.

Authors:  M F Bedeschi; L Colombo; F Mari; K Hofmann; A Rauch; B Gentilin; A Renieri; D Clerici
Journal:  Mol Syndromol       Date:  2011-05-18

2.  A case of 22q11.2 deletion syndrome with Peters anomaly, congenital glaucoma, and heterozygous mutation in CYP1B1.

Authors:  Linda M Reis; Rebecca C Tyler; Roberto Zori; Jennifer Burgess; Jennifer Mueller; Elena V Semina
Journal:  Ophthalmic Genet       Date:  2013-09-11       Impact factor: 1.803

Review 3.  Keratoconus in an adult with 22q11.2 deletion syndrome.

Authors:  Norman Saffra; Benjamin Reinherz
Journal:  BMJ Case Rep       Date:  2015-01-16

4.  Novel retinal observations in a child with DiGeorge (22q11.2 deletion) syndrome.

Authors:  Igor Kozak; Syed A Ali; Wei-Chi Wu
Journal:  Am J Ophthalmol Case Rep       Date:  2022-06-06

5.  Clinical and genetic findings in patients with congenital cataract and heart diseases.

Authors:  Xinru Li; Nuo Si; Zixun Song; Yaqiong Ren; Wei Xiao
Journal:  Orphanet J Rare Dis       Date:  2021-05-31       Impact factor: 4.123

6.  Visual perception and processing in children with 22q11.2 deletion syndrome: associations with social cognition measures of face identity and emotion recognition.

Authors:  Kathryn L McCabe; Stuart Marlin; Gavin Cooper; Robin Morris; Ulrich Schall; Declan G Murphy; Kieran C Murphy; Linda E Campbell
Journal:  J Neurodev Disord       Date:  2016-08-17       Impact factor: 4.025

7.  Ocular findings in 22q11.2 deletion syndrome: A systematic literature review and results of a Dutch multicenter study.

Authors:  Emma N M M von Scheibler; Emy S van der Valk Bouman; Myrthe A Nuijts; Noël J C Bauer; Tos T J M Berendschot; Pit Vermeltfoort; Levinus A Bok; Agnies M van Eeghen; Michiel L Houben; Thérèse A M J van Amelsvoort; Erik Boot; Michelle B van Egmond-Ebbeling
Journal:  Am J Med Genet A       Date:  2021-11-12       Impact factor: 2.578

8.  Arvcf Dependent Adherens Junction Stability is Required to Prevent Age-Related Cortical Cataracts.

Authors:  Jessica B Martin; Kenneth Herman; Nathalie S Houssin; Wade Rich; Matthew A Reilly; Timothy F Plageman
Journal:  Front Cell Dev Biol       Date:  2022-07-06
  8 in total

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