Literature DB >> 17651168

Familial keratosis follicularis spinulosa decalvans associated with woolly hair.

Francesco Lacarrubba1, Federica Dall'Oglio, Alfredo Rossi, Robert A Schwartz, Giuseppe Micali.   

Abstract

Keratosis follicularis spinulosa decalvans (KFSD) is a rare inherited disorder of keratinization clinically characterized by diffuse follicular hyperkeratosis, progressive scarring alopecia of scalp, eyebrows and eyelashes, corneal dystrophy and photophobia. Woolly hair is a hereditary condition, transmitted as an autosomal dominant or recessive trait, usually seen in Caucasians at birth or shortly after, in which there are curly, thick, often heavily pigmented hairs. We report two cases, a son and his mother, in whom KFSD occurred in association with woolly hair. In addition, various dental anomalies, including agenesis, inclusions and teeth malformations, were present in the child. Interestingly, both patients simultaneously developed an inflammatory tinea capitis caused by Microsporum canis. To our knowledge, the association of KFSD with woolly hair has not been described. The dental anomalies found in the child are intriguing, as they have never been reported previously in patients with KFSD. Finally, the concomitant onset of inflammatory tinea capitis in both patients may be explained by the enhanced susceptibility to fungal infection in keratinizing disorders.

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Year:  2007        PMID: 17651168     DOI: 10.1111/j.1365-4632.2007.03162.x

Source DB:  PubMed          Journal:  Int J Dermatol        ISSN: 0011-9059            Impact factor:   2.736


  5 in total

1.  Keratosis Follicularis Spinulosa Decalvans: A Report of Three Cases.

Authors:  Dipali D Malvankar; S Sacchidanand
Journal:  Int J Trichology       Date:  2015 Jul-Sep

2.  Keratosis Follicularis Spinulosa Decalvans with Associated Mental Retardation: Response to Isotretinoin.

Authors:  Sarita Sanke; Vibhu Mendiratta; Archana Singh; Ram Chander
Journal:  Int J Trichology       Date:  2017 Jul-Sep

3.  Diagnosis of Woolly Hair Using Trichoscopy.

Authors:  Mahesh Mathur; Prakash Acharya; Alina Karki; Nisha Kc; Jyoti Shah
Journal:  Case Rep Dermatol Med       Date:  2019-01-03

4.  The Role of Trichoscopy in Keratosis Follicularis Spinulosa Decalvans: Case Report and Review of the Literature.

Authors:  Aurora Alessandrini; Giancarlo Brattoli; Bianca Maria Piraccini; Ambra Di Altobrando; Michela Starace
Journal:  Skin Appendage Disord       Date:  2020-10-12

5.  A rare case of woolly hair with unusual associations.

Authors:  Biju Vasudevan; Rajesh Verma; Vijendran Pragasam; Ambresh Badad
Journal:  Indian Dermatol Online J       Date:  2013-07
  5 in total

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