Literature DB >> 17634063

Mutational analysis of EFHC1 gene in Italian families with juvenile myoclonic epilepsy.

Ferdinanda Annesi1, Antonio Gambardella1, Roberto Michelucci1, Amedeo Bianchi1, Carla Marini1, Maria Paola Canevini1, Giuseppe Capovilla1, Maurizio Elia1, Daniela Buti1, Rosanna Chifari1, Pasquale Striano1, Francesca E Rocca1, Barbara Castellotti1, Francesco Cali1, Angelo Labate1, Emilio LePiane1, Dante Besana1, Vito Sofia1, Giulietta Tabiadon1, Gaetano Tortorella1, Piernanda Vigliano1, Aglaia Vignoli1, Francesca Beccaria1, Grazia Annesi1, Salvatore Striano1, Umberto Aguglia1, Renzo Guerrini1, Aldo Quattrone1.   

Abstract

OBJECTIVES: Mutations in the EFHC1 gene have been reported in six juvenile myoclonic epilepsy (JME) families from Mexico and Belize. In this study, we screened 27 unrelated JME Italian families for mutations in the EFHC1 gene.
MATERIALS AND METHODS: Twenty-seven families (86 affected individuals, 52 women) with at least two affected members with JME were selected. DNA was isolated from peripheral blood lymphocytes by standard methods and each exon of the EFHC1 gene was amplified and sequenced using intronic primers.
RESULTS: Two heterozygous mutations were identified in three unrelated families. One (R353 W) was a novel missense mutation, while the F229 L mutation was previously described (say which on of the two occurred in two families). Both mutations cosegregated with the disease. In a fourth family, the variant 545G-->A (resulting in the amino acid substitution R182 H) cosegregated with JME.
CONCLUSIONS: The results of our study extend the distribution of EFHC1 mutations to the white population and confirm the high level of genetic heterogeneity associated with JME.

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Year:  2007        PMID: 17634063     DOI: 10.1111/j.1528-1167.2007.01173.x

Source DB:  PubMed          Journal:  Epilepsia        ISSN: 0013-9580            Impact factor:   5.864


  15 in total

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