Literature DB >> 17514432

A novel starch for the treatment of glycogen storage diseases.

K Bhattacharya1, R C Orton, X Qi, H Mundy, D W Morley, M P Champion, S Eaton, R F Tester, P J Lee.   

Abstract

OBJECTIVE: To determine whether a new starch offers better short-term metabolic control than uncooked cornstarch in patients with glycogen storage diseases (GSDs). STUDY
DESIGN: A short-term double-blind cross-over pilot study comparing uncooked physically modified cornstarch (WMHM20) with uncooked cornstarch in patients with GSD types Ia, Ib and III. Twenty-one patients (ages 3-47, 9 female) were given 2 g/kg cornstarch or WMHM20 mixed in water. Blood glucose, lactate and insulin, and breath hydrogen and (13)CO2 enrichment were measured, at baseline and after each load. The hourly biochemical evaluations terminated when blood glucose was < or = 3.0 mmol/L, when the study period had lasted 10 h or when the patient wished to end the test. The alternative starch was administered under similar trial conditions a median of 10 days later.
RESULTS: The median starch load duration was 9 h for WMHM20 versus 7 h for cornstarch. Glucose decreased more slowly (p = 0.05) and lactate was suppressed faster (p = 0.17) for WMHM20 compared with cornstarch. Peak hydrogen excretion was increased (p = 0.05) when cornstarch was taken.
CONCLUSION: These data indicate longer duration of euglycaemia and better short-term metabolic control in the majority of GSD patients with WMHM20 compared to cornstarch.

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Year:  2007        PMID: 17514432     DOI: 10.1007/s10545-007-0479-0

Source DB:  PubMed          Journal:  J Inherit Metab Dis        ISSN: 0141-8955            Impact factor:   4.982


  27 in total

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2.  Hypoglycaemia complicating feeding regimens for glycogen-storage disease.

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4.  Effect of continuous glucose therapy begun in infancy on the long-term clinical course of patients with type I glycogen storage disease.

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5.  Effect of continuous glucose therapy with uncooked cornstarch on the long-term clinical course of type 1a glycogen storage disease.

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8.  Chronic inflammatory bowel disease in glycogen storage disease type 1B.

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9.  Breath hydrogen as a diagnostic method for hypolactasia.

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3.  Dietary Management of the Glycogen Storage Diseases: Evolution of Treatment and Ongoing Controversies.

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7.  Safety and Efficacy of Chronic Extended Release Cornstarch Therapy for Glycogen Storage Disease Type I.

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