Literature DB >> 17400532

Molecular study of six families originating from the Middle-East and presenting with autosomal recessive osteopetrosis.

Noëlle Souraty1, Peter Noun, Claudia Djambas-Khayat, Eliane Chouery, Alessandra Pangrazio, Anna Villa, Gérard Lefranc, Annalisa Frattini, André Mégarbané.   

Abstract

Autosomal recessive osteopetrosis is a severe hereditary bone disease whose cellular basis is in the osteoclast, but with heterogeneous molecular defects. We hereby report the clinical and the molecular study of seven patients affected by the recessive form of osteopetrosis (ARO) from six families originating from the Middle-East: four from Lebanon and two from Syria. Parental consanguinity was found in five families. The mean age of diagnosis was 3 months. Failure to thrive, prominent forehead, exophthalmia, optic atrophy, hepatosplenomegaly, neurological manifestations, anaemia, thrombocytopenia, hypocalcaemia, elevated hepatic enzymes and acid phosphatase, and an early fatal outcome were common. Macrocephaly, strabismus, and brain malformations were relatively less common. Mutations were identified in two genes: TCIRG1 and OSTM1. Phenotype-genotype correlation is discussed.

Entities:  

Mesh:

Substances:

Year:  2007        PMID: 17400532     DOI: 10.1016/j.ejmg.2007.01.005

Source DB:  PubMed          Journal:  Eur J Med Genet        ISSN: 1769-7212            Impact factor:   2.708


  7 in total

1.  Novel mutation of TCIRG1 and clinical pictures of two infantile malignant osteopetrosis patients.

Authors:  Ping Yuan; Zhihui Yue; Liangzhong Sun; Weijun Huang; Bin Hu; Zhiyun Yang; Yuelin Hu; Hua Xiao; Hui Shi; Qing Zhou; Yiming Wang
Journal:  J Bone Miner Metab       Date:  2010-11-02       Impact factor: 2.626

Review 2.  Neonatal hydrocephalus: an atypical presentation of malignant infantile osteopetrosis.

Authors:  Angela Lee; Samuel Cortez; Peter Yang; Diane Aum; Prapti Singh; Catherine Gooch; Matthew Smyth
Journal:  Childs Nerv Syst       Date:  2021-09-14       Impact factor: 1.475

Review 3.  Advances in osteoclast biology resulting from the study of osteopetrotic mutations.

Authors:  T Segovia-Silvestre; A V Neutzsky-Wulff; M G Sorensen; C Christiansen; J Bollerslev; M A Karsdal; K Henriksen
Journal:  Hum Genet       Date:  2008-11-06       Impact factor: 4.132

Review 4.  Osteopetrosis: genetics, treatment and new insights into osteoclast function.

Authors:  Cristina Sobacchi; Ansgar Schulz; Fraser P Coxon; Anna Villa; Miep H Helfrich
Journal:  Nat Rev Endocrinol       Date:  2013-07-23       Impact factor: 43.330

5.  Prognostic potential of precise molecular diagnosis of Autosomal Recessive Osteopetrosis with respect to the outcome of bone marrow transplantation.

Authors:  Anna Villa; Alessandra Pangrazio; Elena Caldana; Matteo Guerrini; Paolo Vezzoni; Annalisa Frattini; Cristina Sobacchi
Journal:  Cytotechnology       Date:  2008-09-30       Impact factor: 2.058

6.  Haploidentical haematopoietic stem cell transplantation for malignant infantile osteopetrosis and intermediate osteopetrosis: a retrospective analysis of a single centre.

Authors:  Guanghua Zhu; Ang Wei; Bin Wang; Jun Yang; Yan Yan; Kai Wang; Chenguang Jia; Yanhui Luo; Sidan Li; Xuan Zhou; Tianyou Wang; Huyong Zheng; Maoquan Qin
Journal:  Orphanet J Rare Dis       Date:  2021-07-15       Impact factor: 4.123

Review 7.  Ostm1 from Mouse to Human: Insights into Osteoclast Maturation.

Authors:  Jean Vacher; Michael Bruccoleri; Monica Pata
Journal:  Int J Mol Sci       Date:  2020-08-05       Impact factor: 5.923

  7 in total

北京卡尤迪生物科技股份有限公司 © 2022-2023.