Literature DB >> 17377524

Joubert syndrome (and related disorders) (OMIM 213300).

Melissa A Parisi1, Dan Doherty, Phillip F Chance, Ian A Glass.   

Abstract

Joubert syndrome (JS) and related disorders are characterized by the 'molar tooth sign' (cerebellar vermis hypoplasia and brainstem anomalies) on MRI, hypotonia, developmental delay, ataxia, irregular breathing pattern and abnormal eye movements. Combinations of additional features such as polydactyly, ocular coloboma, retinal dystrophy, renal disease, hepatic fibrosis, encephalocele, and other brain malformations define clinical sub-types. Recent identification of the NPHP1, AHI1, and CEP290 genes has started to reveal the molecular basis of JS, which may implicate the primary cilium in these disorders. Additional genes remain to be identified.

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Year:  2007        PMID: 17377524     DOI: 10.1038/sj.ejhg.5201648

Source DB:  PubMed          Journal:  Eur J Hum Genet        ISSN: 1018-4813            Impact factor:   4.246


  87 in total

Review 1.  Ciliary diffusion barrier: the gatekeeper for the primary cilium compartment.

Authors:  Qicong Hu; W James Nelson
Journal:  Cytoskeleton (Hoboken)       Date:  2011-06-10

2.  Craniovertebral junction abnormality in a case of Joubert syndrome.

Authors:  Timothy W Vogel; Brian J Dlouhy; Arnold H Menezes
Journal:  Childs Nerv Syst       Date:  2012-01-10       Impact factor: 1.475

Review 3.  Joubert Syndrome and related disorders.

Authors:  Francesco Brancati; Bruno Dallapiccola; Enza Maria Valente
Journal:  Orphanet J Rare Dis       Date:  2010-07-08       Impact factor: 4.123

Review 4.  Cilia in cell signaling and human disorders.

Authors:  Neil A Duldulao; Jade Li; Zhaoxia Sun
Journal:  Protein Cell       Date:  2010-08-28       Impact factor: 14.870

5.  Modelling a ciliopathy: Ahi1 knockdown in model systems reveals an essential role in brain, retinal, and renal development.

Authors:  Roslyn J Simms; Ann Marie Hynes; Lorraine Eley; David Inglis; Bill Chaudhry; Helen R Dawe; John A Sayer
Journal:  Cell Mol Life Sci       Date:  2011-09-29       Impact factor: 9.261

6.  Joubert syndrome associated with severe central sleep apnea.

Authors:  Lisa Wolfe; Hüseyin Lakadamyali; Gökhan M Mutlu
Journal:  J Clin Sleep Med       Date:  2010-08-15       Impact factor: 4.062

7.  Co-occurrence of Joubert syndrome and Jeune asphyxiating thoracic dystrophy.

Authors:  A M Lehman; P Eydoux; D Doherty; I A Glass; D Chitayat; B Y H Chung; S Langlois; S L Yong; R B Lowry; F Hildebrandt; P Trnka
Journal:  Am J Med Genet A       Date:  2010-06       Impact factor: 2.802

8.  Nephronophthisis 13: implications of its association with Caroli disease and altered intracellular localization of WDR19 in the kidney.

Authors:  Jiwon M Lee; Yo Han Ahn; Hee Gyung Kang; I I Soo Ha; Kyoungbun Lee; Kyung Chul Moon; Joo Hoon Lee; Young Seo Park; Yong Mee Cho; Jun-Seok Bae; Nayoung K D Kim; Woong-Yang Park; Hae I I Cheong
Journal:  Pediatr Nephrol       Date:  2015-03-01       Impact factor: 3.714

9.  Diagnostic utility of whole exome sequencing in patients showing cerebellar and/or vermis atrophy in childhood.

Authors:  Chihiro Ohba; Hitoshi Osaka; Mizue Iai; Sumimasa Yamashita; Yume Suzuki; Noriko Aida; Nobuyuki Shimozawa; Ayumi Takamura; Hiroshi Doi; Atsuko Tomita-Katsumoto; Kiyomi Nishiyama; Yoshinori Tsurusaki; Mitsuko Nakashima; Noriko Miyake; Yoshikatsu Eto; Fumiaki Tanaka; Naomichi Matsumoto; Hirotomo Saitsu
Journal:  Neurogenetics       Date:  2013-10-04       Impact factor: 2.660

10.  CC2D2A is mutated in Joubert syndrome and interacts with the ciliopathy-associated basal body protein CEP290.

Authors:  Nicholas T Gorden; Heleen H Arts; Melissa A Parisi; Karlien L M Coene; Stef J F Letteboer; Sylvia E C van Beersum; Dorus A Mans; Abigail Hikida; Melissa Eckert; Dana Knutzen; Abdulrahman F Alswaid; Hamit Ozyurek; Sel Dibooglu; Edgar A Otto; Yangfan Liu; Erica E Davis; Carolyn M Hutter; Theo K Bammler; Frederico M Farin; Michael Dorschner; Meral Topçu; Elaine H Zackai; Phillip Rosenthal; Kelly N Owens; Nicholas Katsanis; John B Vincent; Friedhelm Hildebrandt; Edwin W Rubel; David W Raible; Nine V A M Knoers; Phillip F Chance; Ronald Roepman; Cecilia B Moens; Ian A Glass; Dan Doherty
Journal:  Am J Hum Genet       Date:  2008-10-23       Impact factor: 11.025

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