Literature DB >> 17314706

Noninvasive ventilation in children with spinal muscular atrophy types 1 and 2.

Albino Petrone1, Martino Pavone, Maria B Chiarini Testa, Francesca Petreschi, Enrico Bertini, Renato Cutrera.   

Abstract

OBJECTIVE: Our aim was to assess the efficacy of noninvasive ventilation (NIV) for the treatment of thoracoabdominal asynchrony during sleep in children with spinal muscular atrophy (SMA) types 1 and 2.
DESIGN: Nine subjects underwent assessment for sleep apnea/hypopnea index (AHI), mean oxyhemoglobin saturation (SpO2), oxygen desaturation index, transcutaneous carbon dioxide tension (tcpCO2), and mean phase angle during sleep as a measure of thoracoabdominal coordination. A second sleep study was performed with use of NIV.
RESULTS: The nine patients (7 mos of age, range 2-33) had a baseline AHI of 2.1 events per hour (range 0.5-55.8), oxygen desaturation index of 3.7 events per hour (range 1.6-46.1), mean tcpCO2 of 46 mm Hg (range 37-60), and phase angle of 127 degrees (range 72.7-151.7). Comparing baseline and NIV sleep studies, we found significant improvement in oxygen desaturation index (P < 0.010), mean tcpCO2 (P < 0.001), and phase angle (P < 0.001). For five patients, phase-angle improvement became significant when using high-span bilevel positive airway pressure (PAP).
CONCLUSIONS: NIV improved sleep breathing parameters and thoracoabdominal coordination during sleep in SMA types 1 and 2. Phase-angle improvement correlated with bilevel PAP pressures. Phase angle may be useful for the evaluation and monitoring of therapeutic interventions such as NIV.

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Year:  2007        PMID: 17314706     DOI: 10.1097/PHM.0b013e31802ef774

Source DB:  PubMed          Journal:  Am J Phys Med Rehabil        ISSN: 0894-9115            Impact factor:   2.159


  6 in total

1.  Sleep, sleep disordered breathing, and nocturnal hypoventilation in children with neuromuscular diseases.

Authors:  Raanan Arens; Hiren Muzumdar
Journal:  Paediatr Respir Rev       Date:  2010-03       Impact factor: 2.726

2.  Sleep quality of mother-caregivers of Duchenne muscular dystrophy patients.

Authors:  Karen T Nozoe; Daniel N Polesel; Gustavo A Moreira; Gabriel N Pires; Ricardo T Akamine; Sergio Tufik; Monica L Andersen
Journal:  Sleep Breath       Date:  2015-05-24       Impact factor: 2.816

3.  Spontaneous Breathing Pattern as Respiratory Functional Outcome in Children with Spinal Muscular Atrophy (SMA).

Authors:  A LoMauro; A Aliverti; C Mastella; M T Arnoldi; P Banfi; G Baranello
Journal:  PLoS One       Date:  2016-11-07       Impact factor: 3.240

4.  Long-term Non-Invasive Ventilation in Infants: A Systematic Review and Meta-Analysis.

Authors:  Prabhjot K Bedi; Maria Luisa Castro-Codesal; Robin Featherstone; Mohammed M AlBalawi; Bashar Alkhaledi; Anita L Kozyrskyj; Carlos Flores-Mir; Joanna E MacLean
Journal:  Front Pediatr       Date:  2018-02-12       Impact factor: 3.418

5.  Respiratory support attitudes among pediatric intensive care staff for spinal muscular atrophy patients in Saudi Arabia.

Authors:  Mohamad-Hani A Temsah; Fahad M Al-Sohime; Fahad A Bashiri; Ayman A Al-Eyadhy; Gamal M Hasan; Ali A Alhaboob
Journal:  Neurosciences (Riyadh)       Date:  2018-01       Impact factor: 0.906

Review 6.  Respiratory Involvement in Patients with Neuromuscular Diseases: A Narrative Review.

Authors:  Athanasios Voulgaris; Maria Antoniadou; Michalis Agrafiotis; Paschalis Steiropoulos
Journal:  Pulm Med       Date:  2019-12-26
  6 in total

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