Literature DB >> 17034540

Childhood epidermolysis bullosa acquisita with autoantibodies against the noncollagenous 1 and 2 domains of type VII collagen: case report and review of the literature.

M Mayuzumi1, M Akiyama, W Nishie, S Ukae, M Abe, D Sawamura, T Hashimoto, H Shimizu.   

Abstract

Epidermolysis bullosa acquisita (EBA) is an acquired subepidermal bullous disease characterized by IgG autoantibodies to type VII collagen, a major component of anchoring fibrils. Most patients with EBA are adult and develop autoantibodies to the noncollagenous (NC) 1 domain of type VII collagen. We describe a 4-year-old Japanese boy presenting pruritic vesicles and tense blisters over his whole body. Immunofluorescence studies revealed linear IgG/C3 deposits along the dermal-epidermal junction of the patient's skin, and circulating IgG autoantibodies mapping to the dermal side of 1 M NaCl-split skin. By immunoblotting analysis using dermal extracts as a substrate, the patient's IgG antibodies labelled a 290-kDa protein corresponding to type VII collagen. Immunoblotting studies using recombinant proteins demonstrated that the patient's circulating autoantibodies recognized not only the NC1 but also the NC2 domain of type VII procollagen. Review of the previously reported cases and the present case suggested that patients with EBA with autoantibodies to regions other than the NC1 domain are all children younger than 10 years of age with clinical features of an inflammatory phenotype.

Entities:  

Mesh:

Substances:

Year:  2006        PMID: 17034540     DOI: 10.1111/j.1365-2133.2006.07443.x

Source DB:  PubMed          Journal:  Br J Dermatol        ISSN: 0007-0963            Impact factor:   9.302


  7 in total

Review 1.  Epidermolysis bullosa acquisita.

Authors:  Rishu Gupta; David T Woodley; Mei Chen
Journal:  Clin Dermatol       Date:  2012 Jan-Feb       Impact factor: 3.541

Review 2.  Epidermolysis bullosa acquisita: autoimmunity to anchoring fibril collagen.

Authors:  Mei Chen; Gene H Kim; Lori Prakash; David T Woodley
Journal:  Autoimmunity       Date:  2011-09-28       Impact factor: 2.815

Review 3.  Bullous Diseases in Children: A Review of Clinical Features and Treatment Options.

Authors:  Brittney Schultz; Kristen Hook
Journal:  Paediatr Drugs       Date:  2019-10       Impact factor: 3.022

Review 4.  Epidermolysis bullosa acquisita: current diagnosis and therapy.

Authors:  Christine R Mehren; Robert Gniadecki
Journal:  Dermatol Reports       Date:  2011-11-28

Review 5.  Multiple milia formation in blistering diseases.

Authors:  Aikaterini Patsatsi; Cybill Dianne C Uy; Dedee F Murrell
Journal:  Int J Womens Dermatol       Date:  2020-04-01

Review 6.  Immunopathology and molecular diagnosis of autoimmune bullous diseases.

Authors:  Sidonia Mihai; Cassian Sitaru
Journal:  J Cell Mol Med       Date:  2007 May-Jun       Impact factor: 5.310

7.  Childhood Epidermolysis Bullosa Acquisita: Confirmation of Diagnosis by Skin Deficient in Type VII Collagen, Enzyme-linked Immunosorbent Assay, and Immunoblotting.

Authors:  Nupur Goyal; Raghavendra Rao; C Balachandran; Sathish Pai; Balbir S Bhogal; Enno Schmidt; Detlef Zillikens
Journal:  Indian J Dermatol       Date:  2016 May-Jun       Impact factor: 1.494

  7 in total

北京卡尤迪生物科技股份有限公司 © 2022-2023.