Literature DB >> 17020904

Temporal lobe epilepsy and GEFS+ phenotypes associated with SCN1B mutations.

Ingrid E Scheffer1, Louise A Harkin, Bronwyn E Grinton, Leanne M Dibbens, Samantha J Turner, Marta A Zielinski, Ruwei Xu, Graeme Jackson, Judith Adams, Mary Connellan, Steven Petrou, R Mark Wellard, Regula S Briellmann, Robyn H Wallace, John C Mulley, Samuel F Berkovic.   

Abstract

SCN1B, the gene encoding the sodium channel beta 1 subunit, was the first gene identified for generalized epilepsy with febrile seizures plus (GEFS+). Only three families have been published with SCN1B mutations. Here, we present four new families with SCN1B mutations and characterize the associated phenotypes. Analysis of SCN1B was performed on 402 individuals with various epilepsy syndromes. Four probands with missense mutations were identified. Detailed electroclinical phenotyping was performed on all available affected family members including quantitative MR imaging in those with temporal lobe epilepsy (TLE). Two new families with the original C121W SCN1B mutation were identified; novel mutations R85C and R85H were each found in one family. The following phenotypes occurred in the six families with SCN1B missense mutations: 22 febrile seizures, 20 febrile seizures plus, five TLE, three other GEFS+ phenotypes, two unclassified and ten unaffected individuals. All individuals with confirmed TLE had the C121W mutation; two underwent temporal lobectomy (one with hippocampal sclerosis and one without) and both are seizure free. We confirm the role of SCN1B in GEFS+ and show that the GEFS+ spectrum may include TLE alone. TLE with an SCN1B mutation is not a contraindication to epilepsy surgery.

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Year:  2006        PMID: 17020904     DOI: 10.1093/brain/awl272

Source DB:  PubMed          Journal:  Brain        ISSN: 0006-8950            Impact factor:   13.501


  74 in total

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Review 2.  Axon initial segment dysfunction in epilepsy.

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Review 3.  Sodium channel β subunits: emerging targets in channelopathies.

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Journal:  Annu Rev Physiol       Date:  2015       Impact factor: 19.318

4.  The sodium channel accessory subunit Navβ1 regulates neuronal excitability through modulation of repolarizing voltage-gated K⁺ channels.

Authors:  Céline Marionneau; Yarimar Carrasquillo; Aaron J Norris; R Reid Townsend; Lori L Isom; Andrew J Link; Jeanne M Nerbonne
Journal:  J Neurosci       Date:  2012-04-25       Impact factor: 6.167

5.  The genetics of temporal lobe epilepsy and implications for treatment.

Authors:  Bassel W Abou-Khalil
Journal:  Epilepsy Curr       Date:  2007 Jul-Aug       Impact factor: 7.500

6.  Regulation of persistent Na current by interactions between beta subunits of voltage-gated Na channels.

Authors:  Teresa K Aman; Tina M Grieco-Calub; Chunling Chen; Raffaella Rusconi; Emily A Slat; Lori L Isom; Indira M Raman
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7.  Voltage-gated Na+ channels: potential for beta subunits as therapeutic targets.

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8.  Generalised epilepsy with febrile seizures plus (GEFS(+)): molecular analysis in a restricted area.

Authors:  Agata Polizzi; Gemma Incorpora; Piero Pavone; Martino Ruggieri; Grazia Annesi; Antonio Gambardella; Lorenzo Pavone; Aldo Quattrone
Journal:  Childs Nerv Syst       Date:  2011-10-20       Impact factor: 1.475

9.  β1-C121W Is Down But Not Out: Epilepsy-Associated Scn1b-C121W Results in a Deleterious Gain-of-Function.

Authors:  Larisa C Kruger; Heather A O'Malley; Jacob M Hull; Amanda Kleeman; Gustavo A Patino; Lori L Isom
Journal:  J Neurosci       Date:  2016-06-08       Impact factor: 6.167

10.  SCN1A, SCN1B, and GABRG2 gene mutation analysis in Chinese families with generalized epilepsy with febrile seizures plus.

Authors:  Huihui Sun; Yuehua Zhang; Jianmin Liang; Xiaoyan Liu; Xiuwei Ma; Husheng Wu; Keming Xu; Jiong Qin; Yu Qi; Xiru Wu
Journal:  J Hum Genet       Date:  2008-06-20       Impact factor: 3.172

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