Literature DB >> 16935612

A second decorin frame shift mutation in a family with congenital stromal corneal dystrophy.

Eyvind Rødahl1, Rita Van Ginderdeuren, Per M Knappskog, Cecilie Bredrup, Helge Boman.   

Abstract

PURPOSE: To identify the genetic defect in a Belgian family with congenital stromal corneal dystrophy.
DESIGN: Case report and result of deoxyribonucleic acid (DNA) analyses.
METHODS: DNA sequencing of polymerase chain reaction (PCR) products generated from amplification of exons and adjacent introns of the decorin gene.
RESULTS: The family consisted of a mother and her son, both suffering from congenital stromal corneal dystrophy. In both individuals, a single base pair deletion (c.941delC) in the coding sequence of the decorin gene was demonstrated, predicting a C-terminal truncation of the decorin protein (p.Pro314fsX14).
CONCLUSION: This is the second family with congenital stromal corneal dystrophy of the cornea in which a frame shift mutation in the decorin gene has been detected. Both in this family and in a previously reported Norwegian family, a decorin protein missing the 33 C-terminal amino acids is predicted. This observation strongly supports a role for decorin in the pathogenesis of this disorder.

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Year:  2006        PMID: 16935612     DOI: 10.1016/j.ajo.2006.03.064

Source DB:  PubMed          Journal:  Am J Ophthalmol        ISSN: 0002-9394            Impact factor:   5.258


  21 in total

1.  Linkage of posterior amorphous corneal dystrophy to chromosome 12q21.33 and exclusion of coding region mutations in KERA, LUM, DCN, and EPYC.

Authors:  Anthony J Aldave; George O D Rosenwasser; Vivek S Yellore; Jeanette C Papp; Eric M Sobel; Michele N Pham; Michael C Chen; Sugandha Dandekar; Ram Sripracha; Sylvia A Rayner; Joseph W Sassani; Michael B Gorin
Journal:  Invest Ophthalmol Vis Sci       Date:  2010-03-31       Impact factor: 4.799

2.  Genetic evidence for the coordinated regulation of collagen fibrillogenesis in the cornea by decorin and biglycan.

Authors:  Guiyun Zhang; Shoujun Chen; Silvia Goldoni; Bennett W Calder; Holly C Simpson; Rick T Owens; David J McQuillan; Marian F Young; Renato V Iozzo; David E Birk
Journal:  J Biol Chem       Date:  2009-01-09       Impact factor: 5.157

Review 3.  Regulation of corneal stroma extracellular matrix assembly.

Authors:  Shoujun Chen; Michael J Mienaltowski; David E Birk
Journal:  Exp Eye Res       Date:  2015-04       Impact factor: 3.467

Review 4.  The molecular basis of corneal transparency.

Authors:  John R Hassell; David E Birk
Journal:  Exp Eye Res       Date:  2010-07-03       Impact factor: 3.467

5.  Interclass small leucine-rich repeat proteoglycan interactions regulate collagen fibrillogenesis and corneal stromal assembly.

Authors:  Shoujun Chen; Marian F Young; Shukti Chakravarti; David E Birk
Journal:  Matrix Biol       Date:  2014-01-18       Impact factor: 11.583

Review 6.  Decorin interacting network: A comprehensive analysis of decorin-binding partners and their versatile functions.

Authors:  Maria A Gubbiotti; Sylvain D Vallet; Sylvie Ricard-Blum; Renato V Iozzo
Journal:  Matrix Biol       Date:  2016-09-30       Impact factor: 11.583

Review 7.  The regulatory roles of small leucine-rich proteoglycans in extracellular matrix assembly.

Authors:  Shoujun Chen; David E Birk
Journal:  FEBS J       Date:  2013-02-14       Impact factor: 5.542

8.  Intracellularly-retained decorin lacking the C-terminal ear repeat causes ER stress: a cell-based etiological mechanism for congenital stromal corneal dystrophy.

Authors:  Shoujun Chen; Mei Sun; Renato V Iozzo; Winston W-Y Kao; David E Birk
Journal:  Am J Pathol       Date:  2013-05-15       Impact factor: 4.307

9.  Expression analysis of human pterygium shows a predominance of conjunctival and limbal markers and genes associated with cell migration.

Authors:  C J Jaworski; M Aryankalayil-John; M M Campos; R N Fariss; J Rowsey; N Agarwalla; T W Reid; N Dushku; C A Cox; D Carper; G Wistow
Journal:  Mol Vis       Date:  2009-11-20       Impact factor: 2.367

Review 10.  Corneal dystrophies.

Authors:  Gordon K Klintworth
Journal:  Orphanet J Rare Dis       Date:  2009-02-23       Impact factor: 4.123

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