Literature DB >> 16922724

Spectrum of pathogenic mutations and associated polymorphisms in a cohort of 44 unrelated patients with long QT syndrome.

G Millat1, P Chevalier, L Restier-Miron, A Da Costa, P Bouvagnet, B Kugener, L Fayol, C Gonzàlez Armengod, B Oddou, V Chanavat, E Froidefond, R Perraudin, R Rousson, C Rodriguez-Lafrasse.   

Abstract

Long QT syndrome (LQTS) is a rare and clinically heterogeneous inherited disorder characterized by a long QT interval on the electrocardiogram, increased risk of syncope and sudden death caused by arrhythmias. This syndrome is mostly caused by mutations in genes encoding various cardiac ion channels. The clinical heterogeneity is usually attributed to variable penetrance. One of the reasons for this variability in expression could be the coexistence of common single nucleotide polymorphisms (SNPs) on LQTS-causing genes and/or unknown genes. Some synonymous and nonsynonymous exonic SNPs identified in LQTS-causing genes may have an effect on the cardiac repolarization process and modulate the clinical expression of a latent LQTS pathogenic mutation. We report the molecular pattern of 44 unrelated patients with LQTS using denaturing high-performance liquid chromatography analysis of the KCNQ1, KCNH2, SCN5A, KCNE1 and KCNE2 genes. Forty-five disease-causing mutations (including 24 novel ones) were identified in this cohort. Most of our patients (84%) showed complex molecular pattern with one mutation (and even two for four patients) associated with several SNPs located in several LQTS genes.

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Year:  2006        PMID: 16922724     DOI: 10.1111/j.1399-0004.2006.00671.x

Source DB:  PubMed          Journal:  Clin Genet        ISSN: 0009-9163            Impact factor:   4.438


  38 in total

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2.  Evaluation of a new high-throughput next-generation sequencing method based on a custom AmpliSeq™ library and ion torrent PGM™ sequencing for the rapid detection of genetic variations in long QT syndrome.

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6.  Nonsense mutations in hERG cause a decrease in mutant mRNA transcripts by nonsense-mediated mRNA decay in human long-QT syndrome.

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7.  Novel SCN5A mutation in amiodarone-responsive multifocal ventricular ectopy-associated cardiomyopathy.

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8.  Exome analysis of a family with Wolff-Parkinson-White syndrome identifies a novel disease locus.

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9.  A new C-terminal hERG mutation A915fs+47X associated with symptomatic LQT2 and auditory-trigger syncope.

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Journal:  Heart Rhythm       Date:  2008-08-31       Impact factor: 6.343

10.  In silico investigations on functional and haplotype tag SNPs associated with congenital long QT syndromes (LQTSs).

Authors:  C Sudandiradoss; Rao Sethumadhavan
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