Literature DB >> 16612636

Dysfunction of transmission in the inner retina: incidence and clinical causes of negative electroretinogram.

Agnes B Renner1, Ulrich Kellner, Elke Cropp, Michael H Foerster.   

Abstract

BACKGROUND: Only limited data exist on the incidence of negative electroretinograms (ERG) in clinical practice. The purpose of this study is therefore to determine the incidence and clinical causes of a negative ERG in a tertiary care centre focused on inherited and acquired retinal degenerations.
METHODS: All ERGs recorded (in accordance with ISCEV standards) in our electrophysiological laboratory from 1992 to 2004 were retrospectively reviewed. The negative ERGs (criterion: ERG with b:a wave ratio<or=1 in the scotopic standard combined response in at least one eye) were analysed in the context of further clinical results. The photopic ON- and OFF-responses were recorded with long duration (200 ms) stimuli.
RESULTS: A total of 1999 ERGs from 1644 patients were performed during the study period. 47/1644 patients (2.9%) presented with a negative ERG and were included in the study. Clinical diagnoses included inherited retinal dystrophies [X-linked congenital retinoschisis (XRS) (n=17), congenital stationary night blindness (CSNB) (n=6), retinitis pigmentosa (RP) (n=6), cone (-rod) dystrophy (n=5), choroideremia (n=1), Müller cell sheen dystrophy (MCSD) (n=1)] and acquired retinopathies (melanoma-associated retinopathy (MAR) (n=1), vigabatrin retinotoxicity (n=1)). In nine patients a definitive diagnosis could not be established. Unilateral negative ERGs were seen in 10/37 patients where ERG was bilaterally recorded. The fellow eye presented with a b:a wave ratio >1 (8 eyes) or ERG responses were not detectable (2 eyes). Photopic ON- and OFF-responses were recorded in 38 eyes of 29 patients and 32/38 eyes presented with a negative ERG. The ON-response was reduced in 25/32 eyes, whereas the OFF-response was reduced in only 11/32 eyes.
CONCLUSIONS: The incidence of a negative ERG can differ between the laboratories depending on the causes for ERG recording and was in our laboratory 2.9% in a consecutive series of patients with inherited or acquired retinal degenerations. A disorder characteristically associated with negative ERG (e.g. XRS, CSNB, MAR) was diagnosed in 53% of these patients, whereas in 47% the negative ERG indicated an unexpected post-receptoral dysfunction, e.g. in cone (-rod) dystrophy or RP. The ON-bipolar pathway was affected in most cases.

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Year:  2006        PMID: 16612636     DOI: 10.1007/s00417-006-0319-1

Source DB:  PubMed          Journal:  Graefes Arch Clin Exp Ophthalmol        ISSN: 0721-832X            Impact factor:   3.117


  22 in total

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  17 in total

1.  Sorting out co-occurrence of rare monogenic retinopathies: Stargardt disease co-existing with congenital stationary night blindness.

Authors:  Nancy Huynh; Brett G Jeffrey; Amy Turriff; Paul A Sieving; Catherine A Cukras
Journal:  Ophthalmic Genet       Date:  2014-01-07       Impact factor: 1.803

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Review 3.  [Electrophysiology in ophthalmology].

Authors:  T Meigen
Journal:  Ophthalmologe       Date:  2015-06       Impact factor: 1.059

4.  Retinal dystrophies with bull's-eye maculopathy along with negative ERGs.

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Journal:  Doc Ophthalmol       Date:  2019-04-03       Impact factor: 2.379

Review 5.  X-linked juvenile retinoschisis: clinical diagnosis, genetic analysis, and molecular mechanisms.

Authors:  Robert S Molday; Ulrich Kellner; Bernhard H F Weber
Journal:  Prog Retin Eye Res       Date:  2012-01-03       Impact factor: 21.198

6.  Negative electroretinograms in the pediatric and adult population.

Authors:  Johnstone M Kim; John F Payne; Jiong Yan; Claire S Barnes
Journal:  Doc Ophthalmol       Date:  2012-01-13       Impact factor: 2.379

7.  Phenotypic characterization of complete CSNB in the inbred research beagle: how common is CSNB in research and companion dogs?

Authors:  Annie Oh; Ellis R Loew; Melanie L Foster; Michael G Davidson; Robert V English; Kristen J Gervais; Ian P Herring; Freya M Mowat
Journal:  Doc Ophthalmol       Date:  2018-07-26       Impact factor: 2.379

8.  ERG variability in X-linked congenital retinoschisis patients with mutations in the RS1 gene and the diagnostic importance of fundus autofluorescence and OCT.

Authors:  Agnes B Renner; Ulrich Kellner; Britta Fiebig; Elke Cropp; Michael H Foerster; Bernhard H F Weber
Journal:  Doc Ophthalmol       Date:  2007-11-07       Impact factor: 2.379

9.  Sodium iodate selectively injuries the posterior pole of the retina in a dose-dependent manner: morphological and electrophysiological study.

Authors:  Anna Machalińska; Wojciech Lubiński; Patrycja Kłos; Miłosz Kawa; Bartłomiej Baumert; Krzysztof Penkala; Ryszard Grzegrzółka; Danuta Karczewicz; Barbara Wiszniewska; Bogusław Machaliński
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10.  A negative electroretinogram (ERG) in a case of probable multiple system atrophy (MSA).

Authors:  Claire S Barnes; Jiong Yan; George R Wilmot
Journal:  Doc Ophthalmol       Date:  2008-11-21       Impact factor: 2.379

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