Literature DB >> 16190963

Characteristics of hyperthermia and its complications in patients with Prader Willi syndrome.

Erdal Ince1, Ergin Ciftçi, Mustafa Tekin, Tanil Kendirli, Ercan Tutar, Nazan Dalgiç, Selim Oncel, Ulker Dogru.   

Abstract

BACKGROUND: Thermoregulation problems, resulting in hypo- or hyperthermia, have been infrequently reported in children with Prader Willi syndrome (PWS), yet their clinical details remained unknown.
METHODS: The clinical characteristics of three infants with PWS are reported.
RESULTS: Etiologies of high fever could not be identified in three children with PWS. One of these children was also admitted to the intensive care unit with extremely high body temperature in a life-threatening condition, similar to septic shock, without a plausible explanation.
CONCLUSION: Hyperthermia may be a part of the clinical spectrum in young infants with PWS and should be carefully monitored, since it may cause life-threatening complications.

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Year:  2005        PMID: 16190963     DOI: 10.1111/j.1442-200x.2005.02124.x

Source DB:  PubMed          Journal:  Pediatr Int        ISSN: 1328-8067            Impact factor:   1.524


  6 in total

1.  Thermal dysregulation in Prader-Willi syndrome: a potentially fatal complication in adolescence, not just in infancy.

Authors:  Steven McVea; Andrew James Thompson; Noina Abid; Julie Richardson
Journal:  BMJ Case Rep       Date:  2016-06-29

2.  Whole genome microarray analysis of gene expression in an imprinting center deletion mouse model of Prader-Willi syndrome.

Authors:  Douglas C Bittel; Nataliya Kibiryeva; Steven G McNulty; Daniel J Driscoll; Merlin G Butler; Robert A White
Journal:  Am J Med Genet A       Date:  2007-03-01       Impact factor: 2.802

3.  Paradoxical leanness in the imprinting-centre deletion mouse model for Prader-Willi syndrome.

Authors:  David M Golding; Daniel J Rees; Jennifer R Davies; Dinko Relkovic; Hannah V Furby; Irina A Guschina; Anna L Hopkins; Jeffrey S Davies; James L Resnick; Anthony R Isles; Timothy Wells
Journal:  J Endocrinol       Date:  2016-10-31       Impact factor: 4.286

Review 4.  Chromosomal abnormalities related to fever of unknown origin in a Chinese pediatric cohort and literature review.

Authors:  Bijun Sun; Mi Yang; Jia Hou; Wenjie Wang; Wenjing Ying; Xiaoying Hui; Qinhua Zhou; Haili Yao; Jinqiao Sun; Xiaochuan Wang
Journal:  Orphanet J Rare Dis       Date:  2022-07-27       Impact factor: 4.303

5.  Deletion of the Snord116/SNORD116 Alters Sleep in Mice and Patients with Prader-Willi Syndrome.

Authors:  Glenda Lassi; Lorenzo Priano; Silvia Maggi; Celina Garcia-Garcia; Edoardo Balzani; Nadia El-Assawy; Marco Pagani; Federico Tinarelli; Daniela Giardino; Alessandro Mauro; Jo Peters; Alessandro Gozzi; Graziano Grugni; Valter Tucci
Journal:  Sleep       Date:  2016-03-01       Impact factor: 5.849

Review 6.  The RDoC approach for translational psychiatry: Could a genetic disorder with psychiatric symptoms help fill the matrix? the example of Prader-Willi syndrome.

Authors:  Juliette Salles; Emmanuelle Lacassagne; Grégoire Benvegnu; Sophie Çabal Berthoumieu; Nicolas Franchitto; Maithé Tauber
Journal:  Transl Psychiatry       Date:  2020-08-08       Impact factor: 6.222

  6 in total

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