| Literature DB >> 16138673 |
Edward Dabrowski1, Sarah A Smathers, Curt S Ralstrom, Michael A Nigro, Jimmie P Leleszi.
Abstract
Lesch-Nyhan syndrome (LNS) is an X-linked recessive disorder resulting from a deficiency of the metabolic enzyme hypozanthine-guanine phosphoribosyltransferase (HPRT). This syndrome presents with abnormal metabolic and neurological manifestations including hyperuricemia, mental retardation*, spastic cerebral palsy (CP), dystonia, and self-mutilation. The mechanism behind the severe self-mutilating behavior exhibited by patients with LNS is unknown and remains one of the greatest obstacles in providing care to these patients. This report describes a 10-year-old male child with confirmed LNS who was treated for self-mutilation of his hands, tongue, and lips with repeated botulinum toxin A (BTX-A) injections into the bilateral masseters. Our findings suggest that treatment with BTX-A affects both the central and peripheral nervous systems, resulting in reduced self-abusive behavior in this patient.Entities:
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Year: 2005 PMID: 16138673
Source DB: PubMed Journal: Dev Med Child Neurol ISSN: 0012-1622 Impact factor: 5.449