Literature DB >> 16002417

Up-regulation of glucocorticoid-regulated genes in a mouse model of Rett syndrome.

Ulrike A Nuber1, Skirmantas Kriaucionis, Tim C Roloff, Jacky Guy, Jim Selfridge, Christine Steinhoff, Ralph Schulz, Bettina Lipkowitz, H Hilger Ropers, Megan C Holmes, Adrian Bird.   

Abstract

Rett syndrome (RTT) is a severe form of mental retardation, which is caused by spontaneous mutations in the X-linked gene MECP2. How the loss of MeCP2 function leads to RTT is currently unknown. Mice lacking the Mecp2 gene initially show normal postnatal development but later acquire neurological phenotypes, including heightened anxiety, that resemble RTT. The MECP2 gene encodes a methyl-CpG-binding protein that can act as a transcriptional repressor. Using cDNA microarrays, we found that Mecp2-null animals differentially express several genes that are induced during the stress response by glucocorticoids. Increased levels of mRNAs for serum glucocorticoid-inducible kinase 1 (Sgk) and FK506-binding protein 51 (Fkbp5) were observed before and after onset of neurological symptoms, but plasma glucocorticoid was not significantly elevated in Mecp2-null mice. MeCP2 is bound to the Fkbp5 and Sgk genes in brain and may function as a modulator of glucocorticoid-inducible gene expression. Given the known deleterious effect of glucocorticoid exposure on brain development, our data raise the possibility that disruption of MeCP2-dependent regulation of stress-responsive genes contributes to the symptoms of RTT.

Entities:  

Mesh:

Substances:

Year:  2005        PMID: 16002417     DOI: 10.1093/hmg/ddi229

Source DB:  PubMed          Journal:  Hum Mol Genet        ISSN: 0964-6906            Impact factor:   6.150


  77 in total

Review 1.  Complexities of Rett syndrome and MeCP2.

Authors:  Rodney C Samaco; Jeffrey L Neul
Journal:  J Neurosci       Date:  2011-06-01       Impact factor: 6.167

2.  Normal mitral cell dendritic development in the setting of Mecp2 mutation.

Authors:  A M Palmer; A L Degano; M J Park; S Ramamurthy; G V Ronnett
Journal:  Neuroscience       Date:  2011-11-28       Impact factor: 3.590

Review 3.  Transient receptor potential channels as novel effectors of brain-derived neurotrophic factor signaling: potential implications for Rett syndrome.

Authors:  Michelle D Amaral; Christopher A Chapleau; Lucas Pozzo-Miller
Journal:  Pharmacol Ther       Date:  2006-11-21       Impact factor: 12.310

4.  Mbd2 contributes to DNA methylation-directed repression of the Xist gene.

Authors:  Helen Barr; Andrea Hermann; Jennifer Berger; Hsin-Hao Tsai; Karen Adie; Anna Prokhortchouk; Brian Hendrich; Adrian Bird
Journal:  Mol Cell Biol       Date:  2007-03-12       Impact factor: 4.272

Review 5.  Breathing dysfunction in Rett syndrome: understanding epigenetic regulation of the respiratory network.

Authors:  Michael Ogier; David M Katz
Journal:  Respir Physiol Neurobiol       Date:  2008-12-10       Impact factor: 1.931

Review 6.  Evolving role of MeCP2 in Rett syndrome and autism.

Authors:  Janine M LaSalle; Dag H Yasui
Journal:  Epigenomics       Date:  2009-10       Impact factor: 4.778

7.  Methyl-CpG Binding Protein 2 Regulates Microglia and Macrophage Gene Expression in Response to Inflammatory Stimuli.

Authors:  James C Cronk; Noël C Derecki; Emily Ji; Yang Xu; Aaron E Lampano; Igor Smirnov; Wendy Baker; Geoffrey T Norris; Ioana Marin; Nathan Coddington; Yochai Wolf; Stephen D Turner; Alan Aderem; Alexander L Klibanov; Tajie H Harris; Steffen Jung; Vladimir Litvak; Jonathan Kipnis
Journal:  Immunity       Date:  2015-04-21       Impact factor: 31.745

8.  Global transcriptional and translational repression in human-embryonic-stem-cell-derived Rett syndrome neurons.

Authors:  Yun Li; Haoyi Wang; Julien Muffat; Albert W Cheng; David A Orlando; Jakob Lovén; Show-Ming Kwok; Danielle A Feldman; Helen S Bateup; Qing Gao; Dirk Hockemeyer; Maisam Mitalipova; Caroline A Lewis; Matthew G Vander Heiden; Mriganka Sur; Richard A Young; Rudolf Jaenisch
Journal:  Cell Stem Cell       Date:  2013-10-03       Impact factor: 24.633

Review 9.  Understanding and determining the etiology of autism.

Authors:  Salvatore A Currenti
Journal:  Cell Mol Neurobiol       Date:  2009-09-23       Impact factor: 5.046

10.  Correcting deregulated Fxyd1 expression ameliorates a behavioral impairment in a mouse model of Rett syndrome.

Authors:  Valerie Matagne; Sarojini Budden; Sergio R Ojeda; Jacob Raber
Journal:  Brain Res       Date:  2012-12-14       Impact factor: 3.252

View more

北京卡尤迪生物科技股份有限公司 © 2022-2023.