Literature DB >> 15937636

Molecular basis of oculocutaneous albinism type 1 in Lebanese patients.

Laila Zahed1, Hala Zahreddine2, Baha' Noureddine3, Nelly Rebeiz4, Nadine Shakar5, Pierre Zalloua5, Fadi Haddad4.   

Abstract

Oculocutaneous albinism type 1 (OCA1) results from mutations in the tyrosinase gene, which lead to partial or complete loss of activity of the corresponding enzyme. A large number of mutations have been identified worldwide, providing insight into the pathogenesis of the disorder. We performed ophthalmic and dermatological exams on 30 Lebanese subjects with oculocutaneous albinism, then screened for mutations in the tyrosinase gene in an effort to establish the molecular basis of the disorder in our population and correlate it with phenotypic findings. The five exons of the gene together with the exon-intron boundaries and part of the promoter region were sequenced. Mutations were found in a total of 14 patients (47%) while no mutation was identified in the sequenced regions in 53% of patients. Fourteen different mutations were identified of which eight were novel while six had been previously reported. Mutations were mainly seen in patients with clinical findings, suggestive of OCA1A (64% of patients with OCA1A versus 25% of patients with OCA1B); therefore, the absence of mutations in some of the other patients may indicate the involvement of other genes.

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Year:  2005        PMID: 15937636     DOI: 10.1007/s10038-005-0257-5

Source DB:  PubMed          Journal:  J Hum Genet        ISSN: 1434-5161            Impact factor:   3.172


  7 in total

1.  Acceptance of prenatal diagnosis for genetic disorders in Lebanon.

Authors:  L Zahed; M Nabulsi; M Bou-Ghanim; I Usta
Journal:  Prenat Diagn       Date:  1999-12       Impact factor: 3.050

2.  Acceptance of first-trimester prenatal diagnosis for the haemoglobinopathies in Lebanon.

Authors:  L Zahed; J Bou-Dames
Journal:  Prenat Diagn       Date:  1997-05       Impact factor: 3.050

3.  Novel and recurrent mutations in the tyrosinase gene and the P gene in the German albino population.

Authors:  L A Passmore; B Kaesmann-Kellner; B H Weber
Journal:  Hum Genet       Date:  1999-09       Impact factor: 4.132

4.  Tyrosinase gene analysis in Japanese patients with oculocutaneous albinism.

Authors:  Maki Goto; Kazuko C Sato-Matsumura; Daisuke Sawamura; Koichi Yokota; Hideki Nakamura; Hiroshi Shimizu
Journal:  J Dermatol Sci       Date:  2004-09       Impact factor: 4.563

5.  Detection of 53 novel DNA variations within the tyrosinase gene and accumulation of mutations in 17 patients with albinism.

Authors:  Sven Opitz; Barbara Käsmann-Kellner; Markus Kaufmann; Eberhard Schwinger; Christine Zühlke
Journal:  Hum Mutat       Date:  2004-06       Impact factor: 4.878

6.  Tyrosinase gene mutations in oculocutaneous albinism 1 (OCA1): definition of the phenotype.

Authors:  Richard A King; Jacy Pietsch; James P Fryer; Sarah Savage; Marcia J Brott; Isabelle Russell-Eggitt; C Gail Summers; William S Oetting
Journal:  Hum Genet       Date:  2003-09-10       Impact factor: 4.132

7.  Parental consanguinity and congenital heart malformations in a developing country.

Authors:  Mona M Nabulsi; Hala Tamim; Maha Sabbagh; Mounir Y Obeid; Khaled A Yunis; Fadi F Bitar
Journal:  Am J Med Genet A       Date:  2003-02-01       Impact factor: 2.802

  7 in total
  7 in total

1.  Molecular and clinical characterization of albinism in a large cohort of Italian patients.

Authors:  Annagiusi Gargiulo; Francesco Testa; Settimio Rossi; Valentina Di Iorio; Simona Fecarotta; Teresa de Berardinis; Antonello Iovine; Adriano Magli; Sabrina Signorini; Elisa Fazzi; Maria Silvana Galantuomo; Maurizio Fossarello; Sandro Montefusco; Alfredo Ciccodicola; Alberto Neri; Claudio Macaluso; Francesca Simonelli; Enrico Maria Surace
Journal:  Invest Ophthalmol Vis Sci       Date:  2011-03-14       Impact factor: 4.799

Review 2.  DNA variations in oculocutaneous albinism: an updated mutation list and current outstanding issues in molecular diagnostics.

Authors:  Dimitre R Simeonov; Xinjing Wang; Chen Wang; Yuri Sergeev; Monika Dolinska; Matthew Bower; Roxanne Fischer; David Winer; Genia Dubrovsky; Joan Z Balog; Marjan Huizing; Rachel Hart; Wadih M Zein; William A Gahl; Brian P Brooks; David R Adams
Journal:  Hum Mutat       Date:  2013-04-30       Impact factor: 4.878

3.  Molecular genetic studies and delineation of the oculocutaneous albinism phenotype in the Pakistani population.

Authors:  Thomas J Jaworek; Tasleem Kausar; Shannon M Bell; Nabeela Tariq; Muhammad Imran Maqsood; Asma Sohail; Muhmmmad Ali; Furhan Iqbal; Shafqat Rasool; Saima Riazuddin; Rehan S Shaikh; Zubair M Ahmed
Journal:  Orphanet J Rare Dis       Date:  2012-06-26       Impact factor: 4.123

4.  Spectrum of candidate gene mutations associated with Indian familial oculocutaneous and ocular albinism.

Authors:  Kathirvel Renugadevi; Asim Kumar Sil; Vijayalakshmi Perumalsamy; Periasamy Sundaresan
Journal:  Mol Vis       Date:  2010-08-09       Impact factor: 2.367

5.  Screening of TYR, OCA2, GPR143, and MC1R in patients with congenital nystagmus, macular hypoplasia, and fundus hypopigmentation indicating albinism.

Authors:  Markus N Preising; Hedwig Forster; Miriam Gonser; Birgit Lorenz
Journal:  Mol Vis       Date:  2011-04-15       Impact factor: 2.367

6.  Assessment of coding region variants in Kuwaiti population: implications for medical genetics and population genomics.

Authors:  Sumi Elsa John; Dinu Antony; Muthukrishnan Eaaswarkhanth; Prashantha Hebbar; Arshad Mohamed Channanath; Daisy Thomas; Sriraman Devarajan; Jaakko Tuomilehto; Fahd Al-Mulla; Osama Alsmadi; Thangavel Alphonse Thanaraj
Journal:  Sci Rep       Date:  2018-11-08       Impact factor: 4.379

7.  Mutational Analysis of the TYR and OCA2 Genes in Four Chinese Families with Oculocutaneous Albinism.

Authors:  Yun Wang; Zhi Wang; Mengping Chen; Ning Fan; Jie Yang; Lu Liu; Ying Wang; Xuyang Liu
Journal:  PLoS One       Date:  2015-04-28       Impact factor: 3.240

  7 in total

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